نتایج جستجو برای: dravet syndrome

تعداد نتایج: 621933  

Journal: :Epilepsy & Behavior 2015
Luis Miguel Aras Julián Isla Ana Mingorance-Le Meur

Dravet syndrome is a rare form of epilepsy largely refractory to current antiepileptic medications. The only precedents of randomized placebo-controlled trials in Dravet syndrome are the two small trials that led to the approval of stiripentol. With the arrival of new clinical trials for Dravet syndrome, we sought to determine the characteristics of the patient population with Dravet syndrome i...

2016
Yishan Sun Sergiu P Paşca Thomas Portmann Carleton Goold Kathleen A Worringer Wendy Guan Karen C Chan Hui Gai Daniel Vogt Ying-Jiun J Chen Rong Mao Karrie Chan John Lr Rubenstein Daniel V Madison Joachim Hallmayer Wendy M Froehlich-Santino Jonathan A Bernstein Ricardo E Dolmetsch

Dravet Syndrome is an intractable form of childhood epilepsy associated with deleterious mutations in SCN1A, the gene encoding neuronal sodium channel Nav1.1. Earlier studies using human induced pluripotent stem cells (iPSCs) have produced mixed results regarding the importance of Nav1.1 in human inhibitory versus excitatory neurons. We studied a Nav1.1 mutation (p.S1328P) identified in a pair ...

2013
Nienke E. Verbeek Nicoline A. T. van der Maas Floor E. Jansen Marjan J. A. van Kempen Dick Lindhout Eva H. Brilstra

OBJECTIVES To determine the prevalence of Dravet syndrome, an epileptic encephalopathy caused by SCN1A-mutations, often with seizure onset after vaccination, among infants reported with seizures following vaccination. To determine differences in characteristics of reported seizures after vaccination in children with and without SCN1A-related Dravet syndrome. METHODS Data were reviewed of 1,26...

2012
Anna Ka-Yee Kwong Cheuk-Wing Fung Siu-Yuen Chan Virginia Chun-Nei Wong

BACKGROUND Dravet syndrome is a severe form of epilepsy. Majority of patients have a mutation in SCN1A gene, which encodes a voltage-gated sodium channel. A recent study has demonstrated that 16% of SCN1A-negative patients have a mutation in PCDH19, the gene encoding protocadherin-19. Mutations in other genes account for only a very small proportion of families. TSPYL4 is a novel candidate gene...

2011
Claudia B. Catarino Joan Y.W. Liu Ioannis Liagkouras Vaneesha S. Gibbons Robyn W. Labrum Rachael Ellis Cathy Woodward Mary B. Davis Shelagh J. Smith J. Helen Cross Richard E. Appleton Simone C. Yendle Jacinta M. McMahon Susannah T. Bellows Thomas S. Jacques Sameer M. Zuberi Matthias J. Koepp Lillian Martinian Ingrid E. Scheffer Maria Thom Sanjay M. Sisodiya

Dravet syndrome is an epilepsy syndrome of infantile onset, frequently caused by SCN1A mutations or deletions. Its prevalence, long-term evolution in adults and neuropathology are not well known. We identified a series of 22 adult patients, including three adult post-mortem cases with Dravet syndrome. For all patients, we reviewed the clinical history, seizure types and frequency, antiepileptic...

2017
William M. Stern Josemir W. Sander John C. Rothwell Sanjay M. Sisodiya

OBJECTIVE Dravet syndrome is a rare neurodevelopmental disorder characterized by seizures and other neurologic problems. SCN1A mutations account for ∼80% of cases. Animal studies have implicated mutation-related dysregulated cortical inhibitory networks in its pathophysiology. We investigated such networks in people with the condition. METHODS Transcranial magnetic stimulation using single an...

2014
Kimford J. Meador

An adult woman with Dravet syndrome (documented SCN1A mutation) experienced a marked reduction in seizures when treated with the selective serotonin reuptake inhibitor (SSRI) fluoxetine. The seizure reduction may be partly to reductions associated with aging in Dravet patients, but it appears to be due at least in part to the fluoxetine. A prior preliminary study reported that fenfluramine redu...

2017
Maria P. Gontika Christopher Konialis Constantine Pangalos Antigone Papavasiliou

In the light of modern molecular technologies, the understanding of the complexity of the numerous genotype-phenotype correlations regarding Dravet syndrome is mandatory. Motivated by 2 patients, whose whole-exome sequencing revealed novel mutations that exemplify the phenotypic and genetic heterogeneities associated with typical and atypical Dravet syndrome presentations, the authors discuss t...

2013
David S. Auerbach Julie Jones Brittany C. Clawson James Offord Guy M. Lenk Ikuo Ogiwara Kazuhiro Yamakawa Miriam H. Meisler Jack M. Parent Lori L. Isom

OBJECTIVE Dravet syndrome is a severe form of intractable pediatric epilepsy with a high incidence of SUDEP: Sudden Unexpected Death in epilepsy. Cardiac arrhythmias are a proposed cause for some cases of SUDEP, yet the susceptibility and potential mechanism of arrhythmogenesis in Dravet syndrome remain unknown. The majority of Dravet syndrome patients have de novo mutations in SCN1A, resulting...

Journal: :iranian journal of child neurology 0
seyed hassan tonekaboni 1. professor of pediatric neurology, pediatric neurology research center, shahid beheshi university of medical science, tehran, iran 2. professor of pediatric neurology, school of medicine, hahid beheshi university of medical science, tehran, iran ahmad ebrahimi phd of medical genetic, parseh medical genetics center, tehran, iran mohammadkazem bakhshandeh bali pediatric neurology research center, shahid beheshti university of medical sciences, tehran, iran massoud houshmand phd of medical clinical genetic, national institute of genetic engineering and biotechnology, tehran, iran mehdi moghaddasi neurologist, department of neurology, rasool-e-akram hospital, tehran university of medical sciences, tehran, iran mohammad mahdi taghdiri associate professor of pediatric neurology, shahid beheshti university of medical science, tehran, iran

how to cite this article: tonekaboni sh, ebrahimi a, bakhshandeh bali mk, houshmand m, moghaddasi m, taghdiri mm, nasehi mm. sodium channel gene mutations in children with gefs + and dravet syndrome: a cross sectional study. iran j child neurol. 2013 winter; 7 (1):25-29.   objective dravet syndrome or severe myoclonic epilepsy of infancy (smei) is a baleful epileptic encephalopathy that begins ...

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