نتایج جستجو برای: dok7 gene

تعداد نتایج: 1141397  

Journal: :Brain : a journal of neurology 2007
Juliane S Müller Agnes Herczegfalvi Juan J Vilchez Jaume Colomer Linda L Bachinski Violeta Mihaylova Manuela Santos Ulrike Schara Marcus Deschauer Michael Shevell Chantal Poulin Ana Dias Ana Soudo Marja Hietala Tuula Aärimaa Ralf Krahe Veronika Karcagi Angela Huebner David Beeson Angela Abicht Hanns Lochmüller

Dok ('downstream-of-kinase') family of cytoplasmic proteins play a role in signalling downstream of receptor and non-receptor phosphotyrosine kinases. Recently, a skeletal muscle receptor tyrosine kinase (MuSK)-interacting cytoplasmic protein termed Dok-7 has been identified. Subsequently, we and others identified mutations in DOK7 as a cause of congenital myasthenic syndromes (CMS), providing ...

2017
Gang Chen Hefen Yu Lucy Satherley Catherine Zabkiewicz Jeyna Resaul Huishan Zhao Hu Mu Xiuyi Zhi Junqi He Lin Ye Wen G. Jiang

The downstream of tyrosine kinase 7 (DOK7) is an adaptor protein mediating signalling transduction between receptors and intracellular downstream molecules. Reduced expression of DOK7 has been observed in breast cancer. The present study aimed to investigate the role played by DOK7 in lung cancer. The expression of DOK7 at both mRNA and protein levels was evaluated in human lung cancer. A reduc...

2016
Amanda Buyan Antreas C. Kalli Mark S. P. Sansom

Dok7 is a peripheral membrane protein that is associated with the MuSK receptor tyrosine kinase. Formation of the Dok7/MuSK/membrane complex is required for the activation of MuSK. This is a key step in the complex exchange of signals between neuron and muscle, which lead to neuromuscular junction formation, dysfunction of which is associated with congenital myasthenic syndromes. The Dok7 struc...

Journal: :genetics in the 3rd millennium 0
arash pooladi mehrdad noruzinia javad tavakkoly bazzaz

breast cancer is the most important and prevalent cancer in women that can be managed if detected in the early stages. recently, there has been much focus on the use of epigenetic changes such as dna methylation in early detection of cancer. as recent research has put forth dok7 cpg island methylation as an epimarker, in the present study, using a quantification method, a cohort of iranian spor...

2013
Holger Heyn F. Javier Carmona Antonio Gomez Humberto J. Ferreira Jordana T. Bell Sergi Sayols Kirsten Ward Olafur A. Stefansson Sebastian Moran Juan Sandoval Jorunn E. Eyfjord Tim D. Spector Manel Esteller

Using whole blood from 15 twin pairs discordant for breast cancer and high-resolution (450K) DNA methylation analysis, we identified 403 differentially methylated CpG sites including known and novel potential breast cancer genes. Confirming the results in an independent validation cohort of 21 twin pairs determined the docking protein DOK7 as a candidate for blood-based cancer diagnosis. DNA h...

Journal: :Brain : a journal of neurology 2007
Jacqueline Palace Daniel Lashley John Newsom-Davis Judy Cossins Susan Maxwell Robin Kennett Sandeep Jayawant Yuji Yamanashi David Beeson

Mutations in DOK7 have recently been shown to underlie a recessive congenital myasthenic syndrome (CMS) associated with small simplified neuromuscular junctions ('synaptopathy') but normal acetylcholine receptor and acetylcholinesterase function. We identified DOK7 mutations in 27 patients from 24 kinships. Mutation 1124_1127dupTGCC was common, present in 20 out of 24 kinships. All patients wer...

Journal: :Indian pediatrics 2015
S Khadilkar A Bhutada B Nallamilli M Hegde

BACKGROUND Congenital Myasthenic Syndromes (CMS) are heterogeneous genetic diseases. CASE CHARACTERISTICS Two siblings presented with progressive limb girdle weakness without significant fluctuations or ocular muscle weakness. Repetitive nerve stimulation showed a decremental response and there was no response to pyridostigmine therapy. OUTCOME A trial of salbutamol produced a remarkable, c...

2017
Jorge A. Bevilacqua Marian Lara Jorge Díaz Mario Campero Jessica Vázquez Ricardo A. Maselli

Congenital myasthenic syndromes (CMS) are neuromuscular transmission disorders caused by mutations in genes encoding neuromuscular junction proteins. A 61-year-old female and her older sister showed bilateral ptosis, facial and proximal limb weakness, and scoliosis since childhood. Another female sibling had milder signs, while other family members were asymptomatic. Facial nerve repetitive sti...

2017
Yoshiteru Azuma Ana Töpf Teresinha Evangelista Paulo José Lorenzoni Andreas Roos Pedro Viana Hidehito Inagaki Hiroki Kurahashi Hanns Lochmüller

OBJECTIVE To identify the genetic cause in a patient affected by ptosis and exercise-induced muscle weakness and diagnosed with congenital myasthenic syndromes (CMS) using whole-genome sequencing (WGS). METHODS Candidate gene screening and WGS analysis were performed in the case. Allele-specific PCR was subsequently performed to confirm the copy number variation (CNV) that was suspected from ...

2017
Sadanori Miyoshi Tohru Tezuka Sumimasa Arimura Taro Tomono Takashi Okada Yuji Yamanashi

Amyotrophic lateral sclerosis (ALS) is a progressive, multifactorial motor neurodegenerative disease with severe muscle atrophy. The glutamate release inhibitor riluzole is the only medication approved by the FDA, and prolongs patient life span by a few months, testifying to a strong need for new treatment strategies. In ALS, motor neuron degeneration first becomes evident at the motor nerve te...

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