نتایج جستجو برای: aspartoacylase enzyme

تعداد نتایج: 241038  

Journal: :iranian journal of child neurology 0
mahmoodreza ashrafi 1. pediatric neurology division, growth and development research center, children’s medical center, pediatric center of excellence, tehran university of medical science, tehran, iran alireza tavasoli 1. pediatric neurology division, growth and development research center, children’s medical center, pediatric center of excellence, tehran university of medical science, tehran, iran pegah katibeh 1. pediatric neurology division, growth and development research center, children’s medical center, pediatric center of excellence, tehran university of medical science, tehran, iran omid aryani 2. department of medical genetic, national institute for genetic engineering and biotechnology, tehran, iran mohammad vafaee-shahi 1. pediatric neurology division, growth and development research center, children’s medical center, pediatric center of excellence, tehran university of medical science, tehran, iran

how to cite this article: ashrafi mr, tavasoli ar, katibeh p, aryani o, vafaee-shahi m. a novel mutation in aspartoacylase gene; canavan disease. iran j child neurol. autumn 2015; 9(4): 54-57. abstract objective canavan disease (cd) is a type of vacuolating leukodystrophy with autosomal recessive inheritance. aspartoacylase deficiency results in decrease of myelin biosynthesis, dysmyelination a...

2001
Kishore Bhakoo Timothy Craig Peter Styles

Introduction NAA (N-acetyl-aspartate) is the second most abundant molecule in the CNS (after glutamate), its MRS signal is commonly used as a putative marker of viable neurones, and yet little is known about its function. Furthermore, recent data from cell culture has raised the possibility of an additional cellular contribution of NAA from nonneuronal origins, principally in isolated mature ol...

Journal: :Journal of medical genetics 2002
T R Olsen L Tranebjaerg E A Kvittingen L Hagenfeldt C Møller O Nilssen

Canavan disease (CD) (OMIM 271900) is an autosomal recessive leucodystrophy characterised by swelling and spongy degeneration of the white matter of the brain. The biochemical marker for the disorder is increased level of N-acetylaspartic acid (NAA) in cerebrospinal fluid and urine owing to aspartoacylase (ASPA) deficiency. 2 The disease is caused by mutations in the gene encoding the enzyme as...

2002
T R Olsen L Tranebjærg E A Kvittingen L Hagenfeldt C Møller Ø Nilssen

Canavan disease (CD) (OMIM 271900) is an autosomal recessive leucodystrophy characterised by swelling and spongy degeneration of the white matter of the brain. The biochemical marker for the disorder is increased level of N-acetylaspartic acid (NAA) in cerebrospinal fluid and urine owing to aspartoacylase (ASPA) deficiency. 2 The disease is caused by mutations in the gene encoding the enzyme as...

2015
Mahmoudreza ASHRAFI Alireza TAVASOLI Omid ARYANI Mohammad VAFAEE-SHAHI

Introduction Canavan disease (CD) is a type of vacuolating leukodystrophy with autosomal recessive inheritance (1). This neurodegenerative disorder is caused by a defect in the aspartoacylase (ASPA) gene encoding the critical enzyme aspartoacylase, which has the role of hydrolyzing N-acetyl-L-aspartic acid (NAA) and providing the acetyl group to oligodendrocytes for myelin synthesis (2, 3). Asp...

Journal: :Proceedings of the National Academy of Sciences 2006

2015
Seemin Seher Ahmed Seher Ahmed

Canavan’s Disease is a fatal Central Nervous System disorder caused by genetic defects in the enzyme – aspartoacylase and currently has no effective treatment options. We report additional phenotypes in a stringent preclinical aspartoacylase knockout mouse model. Using this model, we developed a gene therapy strategy with intravenous injections of the aspartoacylase gene packaged in recombinant...

Journal: :Human gene therapy 2002
Christopher Janson Scott McPhee Larissa Bilaniuk John Haselgrove Mark Testaiuti Andrew Freese Dah-Jyuu Wang David Shera Peter Hurh Joan Rupin Elizabeth Saslow Olga Goldfarb Michael Goldberg Ghassem Larijani William Sharrar Larisa Liouterman Angelique Camp Edwin Kolodny Jude Samulski Paola Leone

This clinical protocol describes virus-based gene transfer for Canavan disease, a childhood leukodystrophy. Canavan disease, also known as Van Bogaert-Bertrand disease, is a monogeneic, autosomal recessive disease in which the gene coding for the enzyme aspartoacylase (ASPA) is defective. The lack of functional enzyme leads to an increase in the central nervous system of the substrate molecule,...

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