نتایج جستجو برای: alport syndrorme

تعداد نتایج: 843  

Journal: :iranian journal of public health 0
d.d. farhud; t.rezaie jami; m.r. khosh-sorour; m. islami; b.broumand

alport syndrome is a progressive hereditary nephritis leading to renal failure. nearly all of the documents declare that alport syndrome is inherited as x-linked dominant trait and reports of autosomal inheritance form is very rare. this paper presents an iranian large alport family with autosomal recessive inheritance. in our patients alport disease was confirmed with electron microscopic stud...

Journal: :Clinical journal of the American Society of Nephrology : CJASN 2016
Naohiro Kamiyoshi Kandai Nozu Xue Jun Fu Naoya Morisada Yoshimi Nozu Ming Juan Ye Aya Imafuku Kenichiro Miura Tomohiko Yamamura Shogo Minamikawa Akemi Shono Takeshi Ninchoji Ichiro Morioka Koichi Nakanishi Norishige Yoshikawa Hiroshi Kaito Kazumoto Iijima

BACKGROUND AND OBJECTIVES Alport syndrome comprises a group of inherited heterogeneous disorders involving CKD, hearing loss, and ocular abnormalities. Autosomal dominant Alport syndrome caused by heterozygous mutations in collagen 4A3 and/or collagen 4A4 accounts for <5% of patients. However, the clinical, genetic, and pathologic backgrounds of patients with autosomal dominant Alport syndrome ...

Journal: :Advances in peritoneal dialysis. Conference on Peritoneal Dialysis 2010
Denise E Sampimon Anniek Vlijm Dirk G Struijk Raymond T Krediet

Alport syndrome and encapsulating peritoneal sclerosis (EPS) are both rare diseases. Their joint occurrence is highly unlikely. Two patients at our center with Alport syndrome developed EPS. We therefore hypothesized that Alport syndrome might predispose to the development of EPS and that this predisposition might be reflected in a fast peritoneal transport rate at baseline. We compared the mas...

2012
Brooke M. Steenhard Roberto Vanacore David Friedman Adrian Zelenchuk Larysa Stroganova Kathryn Isom Patricia L. St. John Billy G. Hudson Dale R. Abrahamson

Alport disease in humans, which usually results in proteinuria and kidney failure, is caused by mutations to the COL4A3, COL4A4, or COL4A5 genes, and absence of collagen α3α4α5(IV) networks found in mature kidney glomerular basement membrane (GBM). The Alport mouse harbors a deletion of the Col4a3 gene, which also results in the lack of GBM collagen α3α4α5(IV). This animal model shares many fea...

Journal: :Nephrology, dialysis, transplantation : official publication of the European Dialysis and Transplant Association - European Renal Association 2014
Andrew Mallett Wen Tang Philip A Clayton Sarah Stevenson Stephen P McDonald Carmel M Hawley Sunil V Badve Neil Boudville Fiona G Brown Scott B Campbell David W Johnson

BACKGROUND Alport syndrome is a rare inheritable renal disease. Clinical outcomes for patients progressing to end-stage kidney disease (ESKD) are not well described. METHODS This study aimed to investigate the characteristics and clinical outcomes of patients from Australia and New Zealand commencing renal replacement therapy (RRT) for ESKD due to Alport syndrome between 1965 and 1995 (early ...

Journal: :Clinical journal of the American Society of Nephrology : CJASN 2012
Johanna Temme Anneke Kramer Kitty J Jager Katharina Lange Frederick Peters Gerhard-Anton Müller Reinhard Kramar James G Heaf Patrik Finne Runolfur Palsson Anna V Reisæter Andries J Hoitsma Wendy Metcalfe Maurizio Postorino Oscar Zurriaga Julio P Santos Pietro Ravani Faical Jarraya Enrico Verrina Friedo W Dekker Oliver Gross

BACKGROUND AND OBJECTIVES Patients with the hereditary disease Alport syndrome commonly require renal replacement therapy (RRT) in the second or third decade of life. This study compared age at onset of RRT, renal allograft, and patient survival in men with Alport syndrome receiving various forms of RRT (peritoneal dialysis, hemodialysis, or transplantation) with those of men with other renal d...

Journal: :JCI insight 2018
Wen Ding Keyvan Yousefi Stefania Goncalves Bradley J Goldstein Alfonso L Sabater Amy Kloosterboer Portia Ritter Guerline Lambert Armando J Mendez Lina A Shehadeh

Alport syndrome is a rare hereditary renal disorder with no etiologic therapy. We found that osteopontin (OPN) is highly expressed in the renal tubules of the Alport mouse and plays a causative pathological role. OPN genetic deletion ameliorated albuminuria, hypertension, tubulointerstitial proliferation, renal apoptosis, and hearing and visual deficits in the Alport mouse. In Alport renal tubu...

Journal: :The Tohoku journal of experimental medicine 2016
Nao Uchida Naonori Kumagai Kandai Nozu Xue Jun Fu Kazumoto Iijima Yoshiaki Kondo Shigeo Kure

Alport syndrome is a progressive renal disease caused by mutations in COL4A3, COL4A4, and COL4A5 genes that encode collagen type IV alpha 3, alpha 4, and alpha 5 chains, respectively. Because of abnormal collagen chain, glomerular basement membrane becomes fragile and most of the patients progress to end-stage renal disease in early adulthood. COL4A5 mutation causes X-linked form of Alport synd...

Journal: :Journal of the American Society of Nephrology : JASN 2005
Clifford Kashtan

P osttransplant anti–glomerular basement membrane (GBM) nephritis is a rare but devastating complication of Alport syndrome. Although anti-GBM nephritis follows transplantation in only about 3 to 5% of Alport patients, about 75% of affected allografts are lost, and the risk of recurrence in subsequent allografts is very high. Posttransplant anti-GBM nephritis and anti-GBM nephritis in native ki...

Journal: :Nephrology, dialysis, transplantation : official publication of the European Dialysis and Transplant Association - European Renal Association 2009
Clifford E Kashtan

Insights gained during the last 30 years of research in Alport syndrome have influenced the way potential related kidney donors for Alport patients with end-stage renal disease (ESRD) are assessed. Awareness of Alport syndrome among clinicians and families has increased greatly, so the disease is more likely to be suspected in patients with haematuria and in kindreds with renal disease. Widespr...

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