نتایج جستجو برای: alport syndrorme

تعداد نتایج: 843  

Journal: :Pediatric Nephrology 2011

2010
LAURA MASSELLA MARTIN GREGORY

chain altered distribution in a much higher proportion of patients with X-linked AS [5]. It is our experience that skin biopsy, examined with conventional, and if needed, with confocal microscopy, is able to virtually detect (almost) all cases of X-linked AS [5], thus allowing to avoid or to postpone more invasive and/or expensive diagnostic procedure like renal biopsy and genetic investigation...

Journal: :Journal of the American Society of Nephrology 2000

Journal: :Journal of the American Society of Nephrology : JASN 2009
Laurence Heidet Marie-Claire Gubler

Alport syndrome is a hereditary, progressive, hematuric nephropathy characterized by glomerular basement membrane abnormalities with frequent hearing defects and ocular anomalies. The disease is associated with mutations in genes encoding the alpha3, alpha4, or alpha5 chains of type IV collagen, COL4A3, or COL4A4 in the autosomal forms of the disease, COL4A5 in the more frequent X-linked variet...

Journal: :Journal of the American Academy of Audiology 1995
D C Wester C L Atkin M C Gregory

This review of the literature on Alport syndrome (AS) places emphasis on genetic and clinical issues related to the sensorineural hearing loss in type III and type IV X-linked AS. The review covers prevalence, medical issues, genetic issues, audiologic findings, vestibular findings, the pathophysiology of hearing loss in type III AS, age- and phenotype-specific normative data and concludes with...

Journal: :PloS one 2016
Gábor Kovács Tibor Kalmár Emőke Endreffy Zoltán Ondrik Béla Iványi Csaba Rikker Ibolya Haszon Sándor Túri Mária Sinkó Csaba Bereczki Zoltán Maróti

Alport syndrome (AS) is an inherited type IV collagen nephropathies characterized by microscopic hematuria during early childhood, the development of proteinuria and progression to end-stage renal disease. Since choosing the right therapy, even before the onset of proteinuria, can delay the onset of end-stage renal failure and improve life expectancy, the earliest possible differential diagnosi...

Journal: :The Journal of clinical investigation 2015
Ivan G Gomez Deidre A MacKenna Bryce G Johnson Vivek Kaimal Allie M Roach Shuyu Ren Naoki Nakagawa Cuiyan Xin Rick Newitt Shweta Pandya Tai-He Xia Xueqing Liu Dorin-Bogdan Borza Monica Grafals Stuart J Shankland Jonathan Himmelfarb Didier Portilla Shiguang Liu B Nelson Chau Jeremy S Duffield

MicroRNA-21 (miR-21) contributes to the pathogenesis of fibrogenic diseases in multiple organs, including the kidneys, potentially by silencing metabolic pathways that are critical for cellular ATP generation, ROS production, and inflammatory signaling. Here, we developed highly specific oligonucleotides that distribute to the kidney and inhibit miR-21 function when administered subcutaneously ...

Journal: :The Journal of clinical investigation 2010
Mari Tanaka Misako Asada Atsuko Y Higashi Jin Nakamura Akiko Oguchi Mayumi Tomita Sachiko Yamada Nariaki Asada Masayuki Takase Tomohiko Okuda Hiroshi Kawachi Aris N Economides Elizabeth Robertson Satoru Takahashi Takeshi Sakurai Roel Goldschmeding Eri Muso Atsushi Fukatsu Toru Kita Motoko Yanagita

The glomerular basement membrane (GBM) is a key component of the filtering unit in the kidney. Mutations involving any of the collagen IV genes (COL4A3, COL4A4, and COL4A5) affect GBM assembly and cause Alport syndrome, a progressive hereditary kidney disease with no definitive therapy. Previously, we have demonstrated that the bone morphogenetic protein (BMP) antagonist uterine sensitization-a...

Journal: :Journal of the American Society of Nephrology : JASN 2009
Valerie LeBleu Hikaru Sugimoto Thomas M Mundel Behzad Gerami-Naini Elizabeth Finan Caroline A Miller Vincent H Gattone Lingge Lu Charles F Shield Judah Folkman Raghu Kalluri

Patients with Alport syndrome progressively lose renal function as a result of defective type IV collagen in their glomerular basement membrane. In mice lacking the alpha3 chain of type IV collagen (Col4A3 knockout mice), a model for Alport syndrome, transplantation of wild-type bone marrow repairs the renal disease. It is unknown whether cell-based therapies that do not require transplantation...

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