نتایج جستجو برای: alport syndrorme

تعداد نتایج: 843  

2014
Jeffrey H. Miner

Malone et al. performed next-generation sequencing on 70 families with focal segmental glomerulosclerosis (FSGS) and discovered that 10% had variants in surprising 'old' genes, COL4A3 and COL4A4, which are involved in Alport syndrome and thin basement membrane nephropathy. These data show that a subset of renal manifestations associated with COL4A3 or COL4A4 variants cannot be distinguished fro...

2013
Clifford E Kashtan

Correspondence: Clifford E Kashtan Department of Pediatrics, Division of Nephrology, 2450 Riverside Avenue, East Building, 6th Floor, MB679 University of Minnesota Medical School, Minneapolis, MN, USA Email [email protected] Abstract: Alport syndrome, an important inherited cause of end-stage renal disease, has long been considered an untreatable disorder. That view is changing as a result of tr...

Journal: :The Journal of clinical investigation 1996
H H Lemmink W N Nillesen T Mochizuki C H Schröder H G Brunner B A van Oost L A Monnens H J Smeets

Benign familial hematuria (BFH) is characterized by autosomal dominant inheritance, thinning of the glomerular basement membrane (GBM) and normal renal function. It is frequent in patients with persistent microscopic hematuria, but cannot be clinically differentiated from the initial stages of Alport syndrome, a severe GBM disorder which progresses to renal failure. We present here linkage of b...

2012
Pilar Antón-Martín Cristina Aparicio López Soraya Ramiro-León Sonia Santillán Garzón Fernando Santos-Simarro Belén Gil-Fournier

BACKGROUND Alport syndrome is a primary basement membrane disorder arising from mutations in genes encoding the type IV collagen protein family. It is a genetically heterogeneous disease with different mutations and forms of inheritance that presents with renal affection, hearing loss and eye defects. Several new mutations related to X-linked forms have been previously determined. METHODS We ...

Journal: :Kidney International 1996

Journal: :Arquivos brasileiros de oftalmologia 2016
Juliana Maria da Silva Rosa Marcelo Vicente de Andrade Sobrinho César Lipener

Alport Syndrome is a hereditary disease that is caused by a gene mutation and affects the production of collagen in basement membranes; this condition causes hemorrhagic nephritis associated with deafness and ocular changes. The X-linked form of this disease is the most common and mainly affects males. Typical ocular findings are dot-and-fleck retinopathy, anterior lenticonus, and posterior pol...

2012
Tomoaki Koga Yukari Kai Ryosuke Fukuda Saori Morino-Koga Mary Ann Suico Kosuke Koyama Takashi Sato Tsuyoshi Shuto Hirofumi Kai

Alport syndrome is a hereditary glomerulopathy with proteinuria and nephritis caused by defects in genes encoding type IV collagen in the glomerular basement membrane. All male and most female patients develop end-stage renal disease. Effective treatment to stop or decelerate the progression of proteinuria and nephritis is still under investigation. Here we showed that combination treatment of ...

Journal: :Clinical journal of the American Society of Nephrology : CJASN 2010
Rachel Tan Deb Colville Yan Yan Wang Lin Rigby Judy Savige

BACKGROUND AND OBJECTIVES Previous studies of X-linked Alport syndrome demonstrated that "severe" COL4A5 mutations (large deletions and rearrangements, nonsense and frame-shift mutations, and glycine substitutions in the carboxy-terminal residues) were associated with early-onset renal failure, hearing loss, and lenticonus in affected male patients. This study examined whether severe mutations ...

Journal: :Journal of the American Society of Nephrology : JASN 2003
Jean Philippe Jais Bertrand Knebelmann Iannis Giatras Mario De Marchi Gianfranco Rizzoni Alessandra Renieri Manfred Weber Oliver Gross Kai-Olaf Netzer Frances Flinter Yves Pirson Karin Dahan Jörgen Wieslander Ulf Persson Karl Tryggvason Paula Martin Jens Michael Hertz Cornelis Schröder Marek Sanak Maria Fernanda Carvalho Juan Saus Corinne Antignac Hubert Smeets Marie Claire Gubler

Alport syndrome (AS) is a type IV collagen hereditary disease characterized by progressive hematuric nephritis, hearing loss, and ocular changes. Mutations in the COL4A5 collagen gene are responsible for the more common X-linked dominant form of the disease characterized by much less severe disease in girls and women. A "European Community Alport Syndrome Concerted Action" (ECASCA) group was es...

2015
Judy Savige Shivanand Sheth Anita Leys Anjali Nicholson Heather G. Mack

Alport syndrome is an inherited disease characterized by progressive renal failure, hearing loss, and ocular abnormalities. Mutations in the COL4A5 (X-linked), or COL4A3 and COL4A4 (autosomal recessive) genes result in absenceof the collagen IVa3a4a5network fromthebasementmembranesof the cornea, lens capsule, and retinaand are associatedwith corneal opacities, anterior lenticonus, fleck retinop...

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