نتایج جستجو برای: shprintzen syndrome

تعداد نتایج: 621913  

2017
Shadab SALEHPOUR Feyzollah HASHEMI-GORJI Ziba SOLTANI Soudeh GHAFOURI-FARD Mohammad MIRYOUNESI

Goldberg-Shprintzen syndrome (OMIM 609460) (GOSHS) is an autosomal recessive multiple congenital anomaly syndrome distinguished by intellectual disability, microcephaly, and dysmorphic facial characteristics. Most affected individuals also have Hirschsprung disease and/or gyral abnormalities of the brain. This syndrome has been associated with KIAA1279 gene mutations at 10q22.1. Here we report ...

Journal: :Human molecular genetics 1997
C Roberts S C Daw S Halford P J Scambler

Deletions within human chromosome 22q11 cause a wide variety of birth defects including the DiGeorge syndrome and velo-cardio-facial (Shprintzen) syndrome. Despite the positional cloning of several genes from the critical region, it is still not possible to state whether the phenotype is secondary to haploinsufficiency of one or more than one gene. In embryological studies phenocopies of these ...

Journal: :Human molecular genetics 2013
Loïc Drévillon André Megarbane Bénédicte Demeer Corine Matar Paule Benit Audrey Briand-Suleau Virginie Bodereau Jamal Ghoumid Mayssa Nasser Xavier Decrouy Martine Doco-Fenzy Pierre Rustin Dominique Gaillard Michel Goossens Irina Giurgea

Goldberg-Shprintzen syndrome (GOSHS, MIM #609460) is an autosomal recessive disorder of intellectual disability, specific facial gestalt and Hirschsprung's disease (HSCR). In 2005, homozygosity mapping in a large consanguineous family identified KIAA1279 as the disease-causing gene. KIAA1279 encodes KIF-binding protein (KBP), whose function is incompletely understood. Studies have identified ei...

Journal: :Journal of medical genetics 1997
S Worthington A Colley K Fagan K Dai A H Lipson

We report three cases of velocardiofacial syndrome (VCFS) with anal anomalies who have deletions of the 22q11 region and a further case where the proband has VCFS clinically and her father has an anal anomaly. It is important to consider VCFS in the differential diagnosis of children with anal anomalies and to look for other features of the syndrome, such as asymmetrical crying facies, submucou...

Journal: :Journal of medical genetics 1991
A H Lipson D Yuille M Angel P G Thompson J G Vandervoord E J Beckenham

We report the dysmorphological, genetic, and speech therapy aspects of 38 cases of velocardiofacial syndrome presenting to a craniofacial clinic and a specialised children's hospital, to indicate a relatively low incidence of clefting, good response to pharyngoplasty, considerable variability of the syndrome, and two further familial cases. We emphasise the low index of suspicion by paediatrici...

2002
Yoshiyuki Yonehara Takashi Nakatsuka Shigeru Ichioka Nozomu Sasaki Toshiki Kobayashi

CATCH 22 syndrome is characterized by cardiac defects, abnormal facial features, thymic hypoplasia, cleft palate, and hypocalcemia. It is associated with a deletion within chromosome 22q11. This syndrome is not a simple disease. It includes DiGeorge syndrome, conotruncal anomaly face syndrome, and velocardiofacial syndrome. In DiGeorge’s original report, he focused on thymic hypoplasia and hypo...

2015
Matthew A. Benton

Epistemologists focus primarily on cases of knowledge, belief, or credence where the evidence which one possesses, or on which one is relying, plays a fundamental role in the epistemic or normative status of one’s doxastic state. Thus one’s belief might be rational, or justified, or amount to knowledge (if true and other conditions are met); or in a partial belief framework, one’s credence migh...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید