نتایج جستجو برای: aspartoacylase enzyme

تعداد نتایج: 241038  

2017
Marisa I Mendes Desirée EC Smith Ana Pop Pascal Lennertz Matilde R Fernandez Ojeda Warsha A Kanhai Silvy JM van Dooren Yair Anikster Ivo Barić Caroline Boelen Jaime Campistol Lonneke de Boer Ariana Kariminejad Hulya Kayserili Agathe Roubertie Krijn T Verbruggen Christine Vianey‐Saban Monique Williams Gajja S Salomons

We describe 14 patients with 12 novel missense mutations in ASPA, the gene causing Canavan disease (CD). We developed a method to study the effect of these 12 variants on the function of aspartoacylase-the hydrolysis of N-acetyl-l-aspartic acid (NAA) to aspartate and acetate. The wild-type ASPA open reading frame (ORF) and the ORFs containing each of the variants were transfected into HEK293 ce...

2000
M. Quast J. Wei E. L. Ezell P. L. Rady G. A. Campbell K. Matalon J. Ceci S. K. Tyring M. Nehls S. Szucs R. Matalon

Introduction Canavan disease (CD) is an autosomal recessive leukodystrophy associated with spongy degeneration of the white matter of the brain, leading to mental retardation, megalencephaly and early death {I). Brain histology in CD shows characteristic spongy degeneration of the white matter and astrocytic swelling, while neurons are spared. Aspartoacylase (ASPA) deficiency is the basic defec...

Journal: :Journal of Cerebral Blood Flow & Metabolism 2012

Journal: :Journal of neurological disorders 2014
Seemin Seher Ahmed Guangping Gao

The blood brain barrier (BBB) refers to the complex anatomical barrier in the brain composed of endothelial cells, astroglia, pericytes, perivascular macrophages and basal lamina. Its selectivity controls the entry of substances into the Central Nervous System (CNS) [1]. BBB disruption affects neurodegeneration [2] and in some cases can be harnessed to deliver intravenous therapeutics to the CN...

2015
Mahmoudreza ASHRAFI Alireza TAVASOLI Pegah KATIBEH Omid ARYANI Mohammad VAFAEE-SHAHI

Objective Canavan disease (CD) is a type of vacuolating leukodystrophy with autosomal recessive inheritance. Aspartoacylase deficiency results in decrease of myelin biosynthesis, dysmyelination and brain edema. Although CD is a very common in Ashkenazi Jews patients, several cases have been reported from non-Jewish population. This report is based on a homozygous C.202G>A mutation in the ASPA g...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید