نتایج جستجو برای: friedreich

تعداد نتایج: 2912  

Journal: :Human molecular genetics 2005
René Thierbach Tim J Schulz Frank Isken Anja Voigt Brun Mietzner Gunnar Drewes Jürgen-Christoph von Kleist-Retzow Rudolf J Wiesner Mark A Magnuson Hélène Puccio Andreas F H Pfeiffer Pablo Steinberg Michael Ristow

We have disrupted expression of the mitochondrial Friedreich ataxia protein frataxin specifically in murine hepatocytes to generate mice with impaired mitochondrial function and decreased oxidative phosphorylation. These animals have a reduced life span and develop multiple hepatic tumors. Livers also show increased oxidative stress, impaired respiration and reduced ATP levels paralleled by red...

Journal: :Journal of Neuropathology & Experimental Neurology 2017

2000
SANDRA LEISTNER LUCIANE C. LIMA

Friedreich ataxia (FRDA), the most common autosomal recessive ataxia, is caused in 94% of cases by homozygous expansions of an unstable GAA repeat localised in intron 1 of the X25 gene. We have investigated this mutation in five Brazilian patients: four with typical FRDA findings and one patient with atypical manifestations, who was considered to have some other form of cerebellar ataxia with r...

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