نتایج جستجو برای: alport syndrorme

تعداد نتایج: 843  

Journal: :European Journal of Human Genetics 2011

Journal: :Acta Pediátrica Hondureña 2019

Journal: :Sovremennye problemy nauki i obrazovaniâ 2022

2014
Andrew F Malone Paul J Phelan Gentzon Hall Umran Cetincelik Alison Homstad Andrea Alonso Ruiji Jiang Thomas Lindsey Guanghong Wu Matthew A Sparks Stephen R Smith Nicholas J A Webb Philip Kalra Adebowale Adeyemo Andrey S Shaw Peter J Conlon J Charles Jennette David N Howell Michelle P Winn Rasheed A Gbadegesin

Focal segmental glomerulosclerosis (FSGS) is a histological lesion with many causes, including inherited genetic defects, with significant proteinuria being the predominant clinical finding at presentation. Mutations in COL4A3 and COL4A4 are known to cause Alport syndrome (AS), thin basement membrane nephropathy, and to result in pathognomonic glomerular basement membrane (GBM) findings. Second...

Journal: :The Journal of clinical investigation 1995
C Guo B Van Damme Y Vanrenterghem K Devriendt J J Cassiman P Marynen

The X-linked form of Alport disease, caused by mutations in the COL4A5 or the COL4A6 gene, usually leads to terminal renal failure in males, while affected females have a more variable and moderate phenotype. We detected in a female patient, with a severe Alport phenotype, two new missense mutations. One mutation (G289V) occurred in exon 15 and converted a glycine in a collagenous domain of COL...

Journal: :Genetics research 2013
Jane Gibson Rodney D Gilbert David J Bunyan Elizabeth M Angus Darren J Fowler Sarah Ennis

A girl aged 6 presented with haematuria and her sister (aged 5) presented with haematuria and proteinuria. Family history showed multiple individuals suffering from end stage renal failure from the paternal side of the pedigree. Following kidney biopsy in the father and paternal grandmother, the pathological diagnosis was of focal segmental glomerulosclerosis (FSGS). Exome sequencing was undert...

2017
C. Cervera-Acedo A. Coloma E. Huarte-Loza M. Sierra-Carpio E. Domínguez-Garrido

BACKGROUND Alport syndrome is an inherited renal disorder characterized by glomerular basement membrane lesions with hematuria, proteinuria and frequent hearing defects and ocular abnormalities. The disease is associated with mutations in genes encoding α3, α4, or α5 chains of type IV collagen, namely COL4A3 and COL4A4 in chromosome 2 and COL4A5 in chromosome X. In contrast to the well-known X-...

2017
Tomohiko Yamamura Kandai Nozu Xue Jun Fu Yoshimi Nozu Ming Juan Ye Akemi Shono Satoko Yamanouchi Shogo Minamikawa Naoya Morisada Koichi Nakanishi Yuko Shima Norishige Yoshikawa Takeshi Ninchoji Ichiro Morioka Hiroshi Kaito Kazumoto Iijima

Introduction X-linked Alport syndrome (XLAS) is a hereditary disease characterized by progressive nephritis, hearing loss, and ocular abnormalities. Affected male patients usually progress to end-stage renal disease in early or middle adulthood, and disease severity is strongly correlated with genotype. However, the clinical course in female patients has rarely been reported. Methods We condu...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 2006
Hikaru Sugimoto Thomas M Mundel Malin Sund Liang Xie Dominic Cosgrove Raghu Kalluri

Type IV collagen is a predominant component of basement membranes, and glomeruli of a kidney filter approximately 70-90 liters of plasma every day through a specialized glomerular basement membrane (GBM). In Alport syndrome, a progressive disease primarily affecting kidneys, mutations in GBM-associated type IV collagen genes (COL4A3, COL4A4, or COL4A5) lead to basement membrane structural defec...

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