نتایج جستجو برای: duane syndrome

تعداد نتایج: 622107  

Journal: :Neuropsychologia 2010
Shai Gabay Avishai Henik Libe Gradstein

Is orienting of spatial attention dependent on normal functioning of the ocular motor system? We investigated the role of motor pathways in covert orienting (attentional orienting without performing eye movements) by studying three patients suffering from Duane Retraction Syndrome-a congenital impairment in executing horizontal eye movements restricted to specific gaze directions. Patients show...

2011
Arif O. Khan Jameela Shinwari Nada Abu Dhaim Dania Khalil Latifa Al Sharif Nada Al Tassan

PURPOSE To perform linkage analysis on an inbred family with members who exhibit different phenotypic forms of childhood strabismus. METHODS Prospective clinical examination and linkage analysis. RESULTS three of the ten siblings and their cousin each had a different phenotypic form of childhood strabismus: infantile esotropia with convergence excess, esotropia associated with anisometropic...

2015
Ayşe Gül Altıntaş Hasan Basri Arifoğlu Şükrü Gültekin Köklü

OBJECTIVES To present the outcomes of modified lateral rectus Y-splitting combined with either unilateral or bilateral horizontal rectus recession in Duane Retraction Syndrome (DRS) with significant upshoot or downshoot. MA­TE­RI­ALS AND MET­HODS A total of 12 patients including 10 patients with Type I DRS and 2 with Type III DRS underwent modified Y-splitting surgery. Amount of additional re...

Journal: :American journal of human genetics 2016
Jong G Park Max A Tischfield Alicia A Nugent Long Cheng Silvio Alessandro Di Gioia Wai-Man Chan Gail Maconachie Thomas M Bosley C Gail Summers David G Hunter Caroline D Robson Irene Gottlob Elizabeth C Engle

Duane retraction syndrome (DRS) is a congenital eye-movement disorder defined by limited outward gaze and retraction of the eye on attempted inward gaze. Here, we report on three heterozygous loss-of-function MAFB mutations causing DRS and a dominant-negative MAFB mutation causing DRS and deafness. Using genotype-phenotype correlations in humans and Mafb-knockout mice, we propose a threshold mo...

2007

Disease characteristics. Townes-Brocks syndrome (TBS) is characterized by the triad of imperforate anus (82%), dysplastic ears (88%) (overfolded superior helices and preauricular tags) frequently associated with sensorineural and/or conductive hearing impairment (65%), and thumb malformations (89%) (triphalangeal thumbs, duplication of the thumb (preaxial polydactyly), and rarely hypoplasia of ...

2009
Craig N. Jenne Anselm Enders Richard Rivera Susan R. Watson Alexander J. Bankovich Joao P. Pereira Ying Xu Carla M. Roots Joshua N. Beilke Arnob Banerjee Steven L. Reiner Sara A. Miller Amy S. Weinmann Chris C. Goodnow Lewis L. Lanier Jason G. Cyster Jerold Chun

During a screen for ethylnitrosourea-induced mutations in mice affecting blood natural killer (NK) cells, we identified a strain, designated Duane, in which NK cells were reduced in blood and spleen but increased in lymph nodes (LNs) and bone marrow (BM). The accumulation of NK cells in LNs reflected a decreased ability to exit into lymph. This strain carries a point mutation within Tbx21 (T-be...

2011
Patrick Yu-Wai-Man Patrick F. Chinnery

Sir, Pretegiani et al. (2011) describe a 28-year-old female with early-onset optic atrophy who subsequently developed slowly progressive spastic paraplegia. Electrophysiological studies did not suggest a peripheral neuropathy and additional investigations excluded a primary demyelinating process as the cause of her neurological deficits. Interestingly, this patient was eventually found to harbo...

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