Complete Currarino syndrome in an adult, presenting as a fecalith obstruction: report of a case.
نویسندگان
چکیده
complaint and is frequently secondary to poor bowel or dietary habits. Organic causes include endocrine or electrolyte abnormalities, colonic neoplasm or other obstructing mass lesions, and neurologic dysfunction such as Hirschsprung’s disease. Constipation that is refractory to treatment or results in complications such as fecal impaction warrants consideration of occult causes. One rare cause of chronic constipation is sacral agenesis. Sacral agenesis in a triad of anorectal malformation, sacral bony abnormality and a presacral mass (which may be a meningocele, a teratoma or an enteric cyst) is known as Currarino syndrome. In most cases, the syndrome (also known as Currarino’s triad) is diagnosed in childhood, with most descriptions being found in the pediatric literature. It is extremely uncommon for the syndrome to present in adulthood. We describe a man who presented with a fecalith and lifelong absence of spontaneous bowel movements as his only indication of Currarino syndrome.
منابع مشابه
Currarino syndrome in an adult presenting with a presacral abscess: a case report
INTRODUCTION Currarino syndrome (Currarino triad) was described in 1981 as a triad syndrome with a common embryogenesis in infants and with three characteristics: anorectal stenosis, a defect in the sacral bone, and a presacral mass. We describe here an unusual case of Currarino syndrome in an adult presenting with a presacral abscess but no meningitis. CASE PRESENTATION A 32-year-old Japanes...
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ورودعنوان ژورنال:
- Canadian journal of surgery. Journal canadien de chirurgie
دوره 46 4 شماره
صفحات -
تاریخ انتشار 2003