نتایج جستجو برای: trna mitochondrial mutation repeated pregnancy loss

تعداد نتایج: 1060873  

Journal: :Molecular biology and evolution 1998
J R Macey J A Schulte A Larson T J Papenfuss

A tandem duplication of the mitochondrial tRNA(Thr) and tRNA(Pro) genes in the amphisbaenian reptile Bipes biporus is the first case reported of a tandem duplication restricted to a single pair of tRNA genes in a vertebrate mitochondrial genome. Such duplications have been predicted, however, as intermediate steps in the evolution of observed mitochondrial genomic rearrangements through errors ...

Journal: :Human molecular genetics 2016
Pingping Jiang Xiaofen Jin Yanyan Peng Meng Wang Hao Liu Xiaoling Liu Zengjun Zhang Yanchun Ji Juanjuan Zhang Min Liang Fuxin Zhao Yan-Hong Sun Minglian Zhang Xiangtian Zhou Ye Chen Jun Qin Mo Taosheng Huang Jia Qu Min-Xin Guan

Leber's hereditary optic neuropathy (LHON) is the most common mitochondrial disorder. Nuclear modifier genes are proposed to modify the phenotypic expression of LHON-associated mitochondrial DNA (mtDNA) mutations. By using an exome sequencing approach, we identified a LHON susceptibility allele (c.572G>T, p.191Gly>Val) in YARS2 gene encoding mitochondrial tyrosyl-tRNA synthetase, which interact...

Journal: :Nucleic acids research 2003
Lisa M Wittenhagen Marc D Roy Shana O Kelley

The U3271C mutation affecting the human mitochondrial transfer RNA(Leu(UUR)) (hs mt tRNA) is correlated with diabetes and mitochondrial encephalopathies. We have explored the relationship between the structural effects of this mutation and its impact on function using chemical probing experiments and in vitro aminoacylation assays to investigate a series of tRNA constructs. Chemical probing exp...

Journal: :Trends in genetics : TIG 2001
A Schneider

The importation of cytosolic tRNAs is required for protein synthesis in the mitochondria of the wide variety of eukaryotes that lack a complete set of mitochondrial tRNA genes. The evolutionary history of the process, however, is still enigmatic. The analysis presented here suggests that the loss of distinct mitochondrial tRNA genes was not random and that it might be explained by the different...

2013
Veronika Boczonadi Paul M. Smith Angela Pyle Aurora Gomez-Duran Ulrike Schara Mar Tulinius Patrick F. Chinnery Rita Horvath

Childhood-onset mitochondrial encephalomyopathies are severe, relentlessly progressive conditions. However, reversible infantile respiratory chain deficiency (RIRCD), due to a homoplasmic mt-tRNA(Glu) mutation, and reversible infantile hepatopathy, due to tRNA 5-methylaminomethyl-2-thiouridylate methyltransferase (TRMU) deficiency, stand out by showing spontaneous recovery, and provide the key ...

Journal: :Kidney and dialysis 2023

HUPRA syndrome is a rare autosomal recessive mitochondrial disorder caused by mutation in the SARS2 gene encoding seryl-tRNA synthetase (mtSerRS). It includes hyperuricemia, pulmonary hypertension, renal failure, and alkalosis. We present case report of boy aged 1 year 2 months with premature anemia, alkalosis diagnosed syndrome. This disease known to be progressive fatal. A genetic test reveal...

Journal: :Nucleic acids research 2001
K Szuhai J Ouweland R Dirks M Lemaître J Truffert G Janssen H Tanke E Holme J Maassen A Raap

The association of a particular mitochondrial DNA (mtDNA) mutation with different clinical phenotypes is a well-known feature of mitochondrial diseases. A simple genotype-phenotype correlation has not been found between mutation load and disease expression. Tissue and intercellular mosaicism as well as mtDNA copy number are thought to be responsible for the different clinical phenotypes. As dis...

2007
Takahiro Chihara David Luginbuhl Liqun Luo

We identified a mutation in Aats-gly (also known as gars or glycyl-tRNA synthetase), the Drosophila melanogaster ortholog of the human GARS gene that is associated with Charcot-Marie-Tooth neuropathy type 2D (CMT2D), from a mosaic genetic screen. Loss of gars in Drosophila neurons preferentially affects the elaboration and stability of terminal arborization of axons and dendrites. The human and...

2000
Anne Chomyn José Antonio Enriquez Vicente Micol Patricio Fernandez-Silva Giuseppe Attardi

The pathogenetic mechanism of the mitochondrial tRNA A3243G transition associated with the mitochondrial myopathy, encephalopathy, lactic acidosis, and stroke-like episodes (MELAS) syndrome has been investigated in transmitochondrial cell lines constructed by transfer of mutant mitochondrial DNA (mtDNA)-carrying mitochondria from three genetically unrelated MELAS patients or of isogenic wild-ty...

Journal: :Human molecular genetics 1998
F Degoul H Brulé C Cepanec M Helm C Marsac J Leroux R Giegé C Florentz

A growing number of mutated mitochondrial tRNA genes have been found associated with severe human diseases. To investigate the potential interference of such mutations with the primordial function of tRNAs, i.e. their aminoacylation by cognate aminoacyl-tRNA synthetases, a human mitochondrial in vitro aminoacylation system specific for isoleucine has been established. Both native tRNAIleand iso...

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