نتایج جستجو برای: severe congenital neutropenia

تعداد نتایج: 443969  

Journal: :Blood 2007
Carsten U Niemann Magnus Abrink Gunnar Pejler Rikke L Fischer Erik I Christensen Stefan D Knight Niels Borregaard

Granule proteins play a major role in bacterial killing by neutrophils. Serglycin proteoglycan, the major intracellular proteoglycan of hematopoietic cells, has been proposed to play a role in sorting and packing of granule proteins. We examined the content of major neutrophil granule proteins in serglycin knockout mice and found neutrophil elastase absent from mature neutrophils as shown by ac...

Journal: :Haematologica 2009
Karolien Beel Peter Vandenberghe

X-linked neutropenia (XLN) is a rare form of Congenital Neutropenia (CN) caused by inherited gain-of-function mutations of WAS. Here we report 2 cases of the original L270P X-linked neutropenia kindred that evolved to MDS or AML, with acquisition of G-CSFR (CSF3R) mutations and monosomy 7. Thus, leukemic transformation with acquisition of CSF3R mutations and monosomy 7 is not restricted to clas...

Journal: :Blood 2004
Christine Bellanné-Chantelot Séverine Clauin Thierry Leblanc Bruno Cassinat Fernando Rodrigues-Lima Sandrine Beaufils Christelle Vaury Mohamed Barkaoui Odile Fenneteau Micheline Maier-Redelsperger Christine Chomienne Jean Donadieu

Heterozygous mutations of the gene encoding neutrophil elastase (ELA2) have been associated with cyclic neutropenia (CN) and severe congenital neutropenia (SCN). To date, 30 different mutations have been reported, but no correlation has been found with the degree of neutropenia. To address this issue, we analyzed the clinical, hematologic, and molecular characteristics of 81 unrelated patients ...

Journal: :Haematologica 2005
Yasuhiko Sera Hiroshi Kawaguchi Kazuhiro Nakamura Takashi Sato Masakazu Habara Satoshi Okada Nobutsune Ishikawa Seiji Kojima Osamu Katoh Masao Kobayashi

BACKGROUND AND OBJECTIVES Cyclic neutropenia (CyN) in childhood and severe congenital neutropenia (SCN) are congenital disorders that cause chronic neutropenia. Mutations in the neutrophil elastase gene, ELA2, have been reported in patients with CyN and in those with SCN. We examined granulopoietic defects in CyN patients with those in SCN patients. DESIGN AND METHODS Three patients with CyN ...

Faranoush M, Ghahramanfard F, Ghorbani R, Rahbar M,

Background:Chemotherapy-induced neutropenia as a major toxicity of systemic chemotherapy is commonly associated with substantial mortality and morbidity, and thus identifying its determinants is necessary. This study was undertaken to identify main risk factors of severe neutropenia following adjuvant chemotherapy treatment in a community-based population of patients with cancer in Semnan, I...

2015
Quang Van Vu Taizo Wada Tham Thi Tran Duc Ngoc Ngo Thuc Van Dinh Cuong Hung Nguyen Huong Thi Minh Le Akihiro Yachie Sang Ngoc Nguyen

BACKGROUND Severe congenital neutropenia (SCN) is an immunodeficiency disease characterized low blood neutrophil counts, early bacterial infections, and risk of leukaemia development. Heterozygous mutations in the ELANE gene coding neutrophil elastase are associated with SCN. Patients with SCN suffer from recurrent bacterial infections and often succumb them. To our knowledge, this is the first...

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