نتایج جستجو برای: pkhd1

تعداد نتایج: 158  

Journal: :Disease models & mechanisms 2010
Renee M Miller Douglas S Portman

Autosomal dominant polycystic kidney disease (ADPKD) results from loss-of-function mutations in PKD1 or PKD2. The products of these genes, the polycystins PC-1 and PC-2, form a transmembrane channel that is necessary for flow sensing by renal cilia. In C. elegans, the polycystin orthologs LOV-1 and PKD-2 function in sensory neurons that mediate male mating behavior. Here, we report that the nov...

Journal: :Anatomical record 2010
Stephen B Mason Yun Liang Rachel M Sinders Caroline A Miller Tracy Eggleston-Gulyas Robin Crisler-Roberts Peter C Harris Vincent H Gattone

The rat Pck gene is orthologous to the human PKHD1 gene responsible for autosomal recessive polycystic kidney disease (ARPKD). Both renal and hepatic fibrocystic pathology occur in ARPKD. Affected humans have a variable rate of progression, from morbidly affected infants to those surviving into adulthood. This study evaluated the PCK rat, a model of slowly progressive ARPKD. This model originat...

Journal: :Journal of the American Society of Nephrology : JASN 2017
Asaf Vivante Daw-Yang Hwang Stefan Kohl Jing Chen Shirlee Shril Julian Schulz Amelie van der Ven Ghaleb Daouk Neveen A Soliman Aravind Selvin Kumar Prabha Senguttuvan Elijah O Kehinde Velibor Tasic Friedhelm Hildebrandt

Congenital anomalies of the kidneys and urinary tract (CAKUT) are the leading cause of CKD in children, featuring a broad variety of malformations. A monogenic cause can be detected in around 12% of patients. However, the morphologic clinical phenotype of CAKUT frequently does not indicate specific genes to be examined. To determine the likelihood of detecting causative recessive mutations by w...

Journal: :Journal of the American Society of Nephrology : JASN 2011
Anil Karihaloo Farrukh Koraishy Sarah C Huen Yashang Lee David Merrick Michael J Caplan Stefan Somlo Lloyd G Cantley

Polycystic kidney disease (PKD) exhibits an inflammatory component, but the contribution of inflammation to cyst progression is unknown. Macrophages promote the proliferation of tubular cells following ischemic injury, suggesting that they may have a role in cystogenesis. Furthermore, cultured Pkd1-deficient cells express the macrophage chemoattractants Mcp1 and Cxcl16 and stimulate macrophage ...

2009
Sadaf Ahmad Ray Choi Quincy Roberts Jennillee Wallace

Polycystic kidney disease is the most common genetic, life-threatening disease, affecting more than 12.5 million people worldwide. Fluid-filled renal cysts that eventually destroy renal tissue and renal function altogether are characteristic of polycystic kidney disease. The autosomal dominant form of the disease which is also the most common form, ADPKD, is linked to mutations in the genes PKD...

Journal: :Molecular and cellular biology 2007
Shixuan Wang Jingjing Zhang Surya M Nauli Xiaogang Li Patrick G Starremans Ying Luo Kristina A Roberts Jing Zhou

Recent evidence suggests that fibrocystin/polyductin (FPC), polycystin-1 (PC1), and polycystin-2 (PC2) are all localized at the plasma membrane and the primary cilium, where PC1 and PC2 contribute to fluid flow sensation and may function in the same mechanotransduction pathways. To further define the exact subcellular localization of FPC, the protein product encoded by the PKHD1 gene responsibl...

Journal: :Kidney diseases 2016
Ming Wu Shengqiang Yu

BACKGROUND Autosomal dominant polycystic kidney disease (PKD) or autosomal recessive PKD is caused by a mutation in the PKD1, PKD2 or PKHD1 gene, which encodes polycystin-1, polycystin-2 or fibrocystin, respectively. Embryonic and postnatal mutation studies show that transport or channel function is dysregulated before the initiation of cystogenesis, suggesting that the abnormality of transport...

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