نتایج جستجو برای: monogenic diseases

تعداد نتایج: 852089  

2014
Henner Morbach Greta Meyers Yen-Shing Ng Jean-Nicolas Schickel Laurence Menard Sergei Rudchenko Jessica Rojas Charlotte Cunningham-Rundles Mary Conley Ismail Reisli Jose Franco Eric Meffre

Introduction B cells play a central role in the pathogenesis of many autoimmune diseases. Therefore, understanding the mechanisms that regulate B-cell tolerance in humans is important for the development of new therapeutic strategies. Patients with monogenic diseases provide rare opportunities to study the impact of specific gene mutations on the regulation of human B cell tolerance. By this, w...

Journal: :iranian journal of allergy, asthma and immunology 0
gholamreza azizi department of laboratory medicine, imam hassan mojtaba hospital, alborz university of medical sciences, karaj, iran and research centre for immunodeficiencies, pediatrics centre of excellence, children's medical centre, tehran university of medical sciences, tehran, iran shahin khadem azarian department of immunology, school of public health, tehran university of medical sciences, tehran, iran sepideh nazeri department of immunology, school of public health, tehran university of medical sciences, tehran, iran ali mosayebian department of immunology, school of medicine, mazandaran university of medical sciences, sari, iran saleh ghiasy research centre for immunodeficiencies, pediatrics centre of excellence, children's medical centre, tehran university of medical sciences, tehran, iran ghazal sadri research centre for immunodeficiencies, pediatrics centre of excellence, children's medical centre, tehran university of medical sciences, tehran, iran

auto-inflammatory syndromes are a new group of distinct hereditable disorders characterized by episodes of seemingly unprovoked inflammation (most commonly in skin, joints, gut, and eye), the absence of a high titer of auto-antibodies or auto-reactive t cells, and an inborn error of innate immunity. a narrative literature review was carried out of studies related to auto-inflammatory syndromes ...

Journal: :South African medical journal = Suid-Afrikaanse tydskrif vir geneeskunde 1978
A E Retief

The current status of our knowledge of genetic diseases is reviewed. The incidence of monogenic, multifactorial and chromosomal disorders, according to the literature to date, is given, and the possibilities of mass screening programmes are discussed. The prospects for antenatal diagnosis of genetic diseases are reviewed, with emphasis on the indications for amniocentesis and the safety of the ...

Journal: :Physiological reviews 2006
Elina Ikonen

This review summarizes the mechanisms of cellular cholesterol transport and monogenic human diseases caused by defects in intracellular cholesterol processing. In addition, selected mouse models of disturbed cholesterol trafficking are discussed. Current pharmacological strategies to prevent atherosclerosis are largely based on altering cellular cholesterol balance and are introduced in this co...

2012
Tomasz Klupa Jan Skupien Maciej T. Malecki

Monogenic diabetes constitutes a heterogeneous group of single gene disorders. The molecular background and clinical picture of many of these diseases have been described. While each of these forms is much less prevalent than multifactorial type 1 and type 2 diabetes mellitus (T2DM), together they affect millions of patients worldwide. Genetic diagnosis, which has become widely available, is of...

2017
Carlo Vermeulen Geert Geeven Elzo de Wit Marjon J.A.M. Verstegen Rumo P.M. Jansen Melissa van Kranenburg Ewart de Bruijn Sara L. Pulit Evelien Kruisselbrink Zahra Shahsavari Davood Omrani Fatemeh Zeinali Hossein Najmabadi Theodora Katsila Christina Vrettou George P. Patrinos Joanne Traeger-Synodinos Erik Splinter Jeffrey M. Beekman Sima Kheradmand Kia Gerard J. te Meerman Hans Kristian Ploos van Amstel Wouter de Laat

During pregnancy, cell-free DNA (cfDNA) in maternal blood encompasses a small percentage of cell-free fetal DNA (cffDNA), an easily accessible source for determination of fetal disease status in risk families through non-invasive procedures. In case of monogenic heritable disease, background maternal cfDNA prohibits direct observation of the maternally inherited allele. Non-invasive prenatal di...

Journal: :Medizinische Genetik 2022

Abstract Reduced penetrance is an important but underreported aspect in monogenic diseases. It refers to the phenomenon that carriers of pathogenic variants do not manifest with overt disease. Clinical expressivity, on other hand, describes degree which certain disease characteristics are present. In this article, we discuss implications reduced genetic testing and counseling, outline how can b...

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