نتایج جستجو برای: merosin

تعداد نتایج: 173  

Journal: :Physiological genomics 2006
Erik van Lunteren Michelle Moyer Patrick Leahy

Deficiency of alpha2-laminin (merosin) underlies classical congenital muscular dystrophy in humans and dy/dy muscular dystrophy in mice and causes severe muscle dysfunction in both species. To gain greater insight into the biochemical and molecular events that link alpha2-laminin deficiency with muscle fiber necrosis, and the associated compensatory responses, gene expression profiles were char...

Journal: :Seizure-european Journal of Epilepsy 2021

Epilepsy is a common, often severe, feature of LAMA2-related muscular dystrophy (LAMA2-RD) and could represent its onset main manifestation, even in the absence overt muscle involvement. To date, there no systematic characterization epilepsy LAMA2-RD, impact on neurodevelopment clinical course remains poorly established. In view this knowledge gap, we conducted review literature and, as an illu...

Journal: :Journal of medical genetics 2001
K J Jones G Morgan H Johnston V Tobias R A Ouvrier I Wilkinson K N North

Initial reports of patients with laminin alpha2 chain (merosin) deficiency had a relatively homogeneous phenotype, with classical congenital muscular dystrophy (CMD) characterised by severe muscle weakness, inability to achieve independent ambulation, markedly raised creatine kinase, and characteristic white matter hypodensity on cerebral magnetic resonance imaging. We report a series of five p...

2012
Vandana A. Gupta Genri Kawahara Jennifer A. Myers Aye T. Chen Thomas E. Hall M. Chiara Manzini Peter D. Currie Yi Zhou Leonard I. Zon Louis M. Kunkel Alan H. Beggs

Congenital muscular dystrophy (CMD) is a clinically and genetically heterogeneous group of inherited muscle disorders. In patients, muscle weakness is usually present at or shortly after birth and is progressive in nature. Merosin deficient congenital muscular dystrophy (MDC1A) is a form of CMD caused by a defect in the laminin-α2 gene (LAMA2). Laminin-α2 is an extracellular matrix protein that...

Journal: :Journal of cell science 2008
Bruce L Patton Bing Wang Yukie S Tarumi Kevin L Seburn Robert W Burgess

Mutations in the gene encoding the basal lamina (BL) component laminin alpha2 (LAMA2) cause merosin-deficient congenital muscular dystrophy 1A (MDC1A), a complex disorder that includes hypomyelination and myodegeneration. In dystrophia muscularis (dy) mice bearing Lama2 mutations, myofibers and Schwann cells fail to assemble stable BLs, which are thought to be crucial for myofiber survival and ...

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