نتایج جستجو برای: hereditary periodic fever syndromes

تعداد نتایج: 337589  

2013
SO Salugina E Fedorov N Kuzmina E Zaharova

Introduction Cryopyrin-associated periodic syndromes (CAPS) are the rare hereditary autoinflammatory diseases. CAPS include three similar conditions are distinguished which lie along a phenotypical continuum with increasing levels of severity: familial cold autoinflammatory syndrome (FCAS), Muckle-Wells syndrome (MWS) and CINCA/ NOMID. Distinguishing features include cutaneous, neurological, op...

2013
V Messia M Pardeo R Nicolai C Bracaglia F De Benedetti A Insalaco

Introduction The term CAPS (Cryopyrin-Associated Periodic Syndromes) identifies a spectrum of autoinflammatory diseases caused by heterozygous mutations of the CIAS1/NLRP3. Affected individuals may present three different phenotypes: Familial Cold Autoinflammatory Syndrome (FCAS), Muckle-Wells Syndrome (MWS) and CINCA syndrome, the most severe form of the clinical spectrum. Clinical manifestati...

Journal: :Cell 1999
Michael F McDermott Ivona Aksentijevich Jérôme Galon Elizabeth M McDermott B.William Ogunkolade Michael Centola Elizabeth Mansfield Massimo Gadina Leena Karenko Tom Pettersson John McCarthy David M Frucht Martin Aringer Yelizaveta Torosyan Anna-Maija Teppo Meredith Wilson H.Mehmet Karaarslan Ying Wan Ian Todd Geryl Wood Ryan Schlimgen Thisum R Kumarajeewa Sheldon M Cooper John P Vella Christopher I Amos John Mulley Kathleen A Quane Michael G Molloy Annamari Ranki Richard J Powell Graham A Hitman John J O’Shea Daniel L Kastner

Autosomal dominant periodic fever syndromes are characterized by unexplained episodes of fever and severe localized inflammation. In seven affected families, we found six different missense mutations of the 55 kDa tumor necrosis factor receptor (TNFR1), five of which disrupt conserved extracellular disulfide bonds. Soluble plasma TNFR1 levels in patients were approximately half normal. Leukocyt...

2015
Yasemin Bozkurt Alper Demir Burak Erman Ahmet Gül

Familial mediterranean fever (FMF) and Cryopyrin associated periodic syndromes (CAPS) are two prototypical hereditary autoinflammatory diseases, characterized by recurrent episodes of fever and inflammation as a result of mutations in MEFV and NLRP3 genes encoding Pyrin and Cryopyrin proteins, respectively. Pyrin and Cryopyrin play key roles in the multiprotein inflammasome complex assembly, wh...

2013
E Demirkaya S Ozen C Saglam T Turker A Duzova P Woo I Konè-Paut M Doglio G Amaryan J Frenkel Y Uziel A Insalaco L Cantarini M Hofer S Boiu C Modesto A Bryant D Rigante E Papadopoulou-Alataki S Guillaume-Czitrom N Ruperto M Gattorno

Methods The study group consisted of 339 FMF patients diagnosed according to Tel Hashomer criteria. A control group of 377 patients were diagnosed other periodic fever syndromes including MKD, TRAPS, CAPS and PFAPA syndromes. Both groups were evaluated according to the Tel Hashomer criteria and the new set of diagnostic criteria proposed to use in childhood FMF. The diagnostic performance of bo...

Journal: :Rheumatology 2014
Michaël Hofer Pascal Pillet Marie-Madeleine Cochard Stefan Berg Petra Krol Isabelle Kone-Paut Donato Rigante Véronique Hentgen Jordi Anton Riva Brik Bénédicte Neven Isabelle Touitou Daniela Kaiser Agnès Duquesne Carine Wouters Marco Gattorno

OBJECTIVES The aims of this study were to describe the clinical features of periodic fever, aphthous stomatitis, pharyngitis and cervical adenitis (PFAPA) and identify distinct phenotypes in a large cohort of patients from different countries. METHODS We established a web-based multicentre cohort through an international collaboration within the periodic fevers working party of the Pediatric ...

2015
E Schuh P Lohse J Havla I Meinl L-A Gerdes R Hohlfeld T Kümpfel

Introduction Cryopyrin-associated periodic syndrome (CAPS), familial mediterranean fever (FMF) and tumor necrosis factor receptor-associated periodic syndromes (TRAPS) are rare systemic, monogenetic inherited autoinflammatory diseases. The clinical significance of low penetrance mutations in TRAPS and CAPS as well as heterozygosity in FMF is still under debate. The frequency and clinical patter...

2006
Sarah M. Churchman Michael F. McDermott

The term auto-inflammatory disorders has been coined to describe a group of conditions characterized by spontaneously relapsing and remitting bouts of systemic inflammation without apparent involvement of antigen-specific T cells or significant production of auto-antibodies. The hereditary periodic fever syndromes are considered as the prototypic auto-inflammatory diseases, and genetic studies ...

2015
K Hohenstein-Scheibenecker A Schmidt

Objectives The identification of genes involved in the modulation of inflammatory processes has allowed the delineation of a new group of diseases called “Monogenetic Autoinflammatory Syndromes MAISs”. At the moment, 25 syndromes and their gene-disorders are known. Some of them are well known (eg Familial Mediterranean Fever), most of them are rare diseases (eg FCAS-Familial Cold-Autoinflammato...

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