نتایج جستجو برای: vsx1

تعداد نتایج: 79  

Journal: :Journal of medical genetics 2004
F Brancati E M Valente A Sarkozy J Fehèr M Castori P Del Duca R Mingarelli A Pizzuti B Dallapiccola

K eratoconus (OMIM148300) is a bilateral, non-inflammatory, slowly progressive, corneal ectasia that is a major cause of corneal transplant. Characteristically, the cornea becomes thin and conical, with myopia and irregular astigmatism that leads to vision impairment. The incidence of keratoconus is between 50 and 230 per 100 000, with remarkable differences between ethnic groups. Although the ...

Journal: :American journal of human genetics 2005
Charles M Krafchak Hemant Pawar Sayoko E Moroi Alan Sugar Paul R Lichter David A Mackey Shahzad Mian Theresa Nairus Victor Elner Miriam T Schteingart Catherine A Downs Theresa Guckian Kijek Jenae M Johnson Edward H Trager Frank W Rozsa Md Nawajes Ali Mandal Michael P Epstein Douglas Vollrath Radha Ayyagari Michael Boehnke Julia E Richards

Posterior polymorphous corneal dystrophy (PPCD, also known as PPMD) is a rare disease involving metaplasia and overgrowth of corneal endothelial cells. In patients with PPCD, these cells manifest in an epithelial morphology and gene expression pattern, produce an aberrant basement membrane, and, sometimes, spread over the iris and nearby structures in a way that increases the risk for glaucoma....

2009
Andrea L. Vincent David M. Markie Betina De Karolyi Catherine E. Wheeldon Dipika V. Patel Christina N. Grupcheva Charles N.J. McGhee

PURPOSE With advances in phenotyping tools and availability of molecular characterization, an increasing number of phenotypically and genotypically diverse inherited corneal dystrophies are described. We aimed to determine the underlying causative genetic mechanism in a three-generation pedigree affected with a unique anterior membrane corneal dystrophy characterized by early onset recurrent co...

2017
Doug D Chung Ricardo F Frausto Aleck E Cervantes Katherine M Gee Marina Zakharevich Evelyn M Hanser Edwin M Stone Elise Heon Anthony J Aldave

PURPOSE To identify the genetic basis of posterior polymorphous corneal dystrophy (PPCD) in families mapped to the PPCD1 locus and in affected individuals without ZEB1 coding region mutations. METHODS The promoter, 5' UTR, and coding regions of OVOL2 was screened in the PPCD family in which linkage analysis established the PPCD1 locus and in 26 PPCD probands who did not harbor a ZEB1 mutation...

2012
Petra Liskova Rhian Gwilliam Martin Filipec Katerina Jirsova Stanislava Reinstein Merjava Panos Deloukas Tom R. Webb Shomi S. Bhattacharya Neil D. Ebenezer Alex G. Morris Alison J. Hardcastle

Posterior polymorphous corneal dystrophy (PPCD) is a rare autosomal dominant genetically heterogeneous disorder. Nineteen Czech PPCD pedigrees with 113 affected family members were identified, and 17 of these kindreds were genotyped for markers on chromosome 20p12.1- 20q12. Comparison of haplotypes in 81 affected members, 20 unaffected first degree relatives and 13 spouses, as well as 55 unrela...

2016
Derek J. Le Duk-Won D. Chung Ricardo F. Frausto Michelle J. Kim Anthony J. Aldave

Posterior polymorphous corneal dystrophy 1 (PPCD1) is a genetic disorder that affects corneal endothelial cell function and leads to loss of visual acuity. PPCD1 has been linked to a locus on chromosome 20 in multiple families; however, Sanger sequencing of protein-coding genes in the consensus region failed to identify any causative missense mutations. In this study, custom capture probes were...

2016
Anna L. Shen Susan A. Moran Edward A. Glover Norman R. Drinkwater Rebecca E. Swearingen Leandro B. Teixeira Christopher A. Bradfield

We have previously described a mouse model of human posterior polymorphous corneal dystrophy (PPCD) and localized the causative mutation to a 6.2 Mbp region of chromosome 2, termed Ppcd1. We now show that the gene rearrangement linked to mouse Ppcd1 is a 3.9 Mbp chromosomal inversion flanked by 81 Kbp and 542 bp deletions. This recombination event leads to deletion of Csrp2bp Exons 8 through 11...

2015
Jianqin Shen Du Chixin Yangshun GU Heiko Pult.

Posterior polymorphous corneal dystrophy (PPCD) is an extremely rare, bilateral, and inherited disorder, which affects the corneal endothelium and Descemet’s membrane. Few PPCD cases in Chinese patients have been published so far. As far as we know, there are few studies which focused on the associations between PPCD and high myopia either. Here we report a rare case of coexistence of posterior...

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