نتایج جستجو برای: r117h

تعداد نتایج: 90  

Journal: :Gut 2001
N Howes W Greenhalf S Rutherford M O'Donnell R Mountford I Ellis D Whitcomb C Imrie B Drumm J P Neoptolemos

BACKGROUND AND AIMS Hereditary pancreatitis (HP) is a rare form of recurrent acute and chronic pancreatitis. Mutations in the cationic trypsinogen (protease serine 1, PRSS1) gene have been identified as causing HP. The R122H (previously known as R117H) mutation is the commonest and can be detected by a single and rapid polymerase chain reaction/restriction fragment length polymorphism (PCR/RFLP...

2010
Danjun Fang Richard H West Mary E Manson Jennifer Ruddy Dechen Jiang Stephen F Previs Nitin D Sonawane James D Burgess Thomas J Kelley

BACKGROUND Previous observations demonstrate that Cftr-null cells and tissues exhibit alterations in cholesterol processing including perinuclear cholesterol accumulation, increased de novo synthesis, and an increase in plasma membrane cholesterol accessibility compared to wild type controls. The hypothesis of this study is that membrane cholesterol accessibility correlates with CFTR genotype a...

Journal: :Archivio italiano di urologia, andrologia : organo ufficiale [di] Societa italiana di ecografia urologica e nefrologica 2014
Jlenia Elia Rossella Mazzilli Michele Delfino Maria Piane Cristina Bozzao Vincenzo Spinosa Luciana Chessa Fernando Mazzilli

Objective. The aim of this study was to evaluate the prevalence of most common mutations and intron 8 5T (IVS8-5T) polymorphism of CFTR gene in Italian: a) azoospermic males; b) non azoospermic subjects, male partners of infertile couples enrolled in assisted reproductive technology (ART) programs. Material and methods. We studied 242 subjects attending our Andrology Unit (44 azoospermic subjec...

2014
Jessica LaRusch Jinsei Jung Ignacio J. General Michele D. Lewis Hyun Woo Park Randall E. Brand Andres Gelrud Michelle A. Anderson Peter A. Banks Darwin Conwell Christopher Lawrence Joseph Romagnuolo John Baillie Samer Alkaade Gregory Cote Timothy B. Gardner Stephen T. Amann Adam Slivka Bimaljit Sandhu Amy Aloe Michelle L. Kienholz Dhiraj Yadav M. Michael Barmada Ivet Bahar Min Goo Lee David C. Whitcomb

CFTR is a dynamically regulated anion channel. Intracellular WNK1-SPAK activation causes CFTR to change permeability and conductance characteristics from a chloride-preferring to bicarbonate-preferring channel through unknown mechanisms. Two severe CFTR mutations (CFTRsev) cause complete loss of CFTR function and result in cystic fibrosis (CF), a severe genetic disorder affecting sweat glands, ...

Journal: :American journal of physiology. Lung cellular and molecular physiology 2004
Anna M van Heeckeren Mark D Schluchter Mitchell L Drumm Pamela B Davis

Patients with cystic fibrosis have a lesion in the cystic fibrosis transmembrane conductance regulator gene (CFTR), which is associated with abnormal regulation of other ion channels, abnormal glycosylation of secreted and cell surface molecules, and vulnerability to bacterial infection and inflammation in the lung usually leading to the death of these patients. The exact mechanism(s) by which ...

Journal: :Pediatrics 2002
Vidya Raman Randall Clary Karen L Siegrist Barbara Zehnbauer Talal A Chatila

OBJECTIVE Chronic rhinosinusitis results in significant morbidity in the pediatric population; however, no predisposing factor is found in many cases. Cystic fibrosis (CF) is a recognized cause of chronic rhinosinusitis. Although the carrier frequency for CF ranges from 3% to 4% in the general white population, the prevalence of mutations in the CF transmembrane conductance regulator (CFTR) amo...

2014
Guiying Cui Kazi S. Rahman Daniel T. Infield Christopher Kuang Chengyu Z. Prince Nael A. McCarty

The cystic fibrosis (CF) transmembrane conductance regulator (CFTR) bears six extracellular loops (ECL1-6); ECL1 is the site of several mutations associated with CF. Mutation R117H has been reported to reduce current amplitude, whereas D110H, E116K, and R117C/L/P may impair channel stability. We hypothesized that these amino acids might not be directly involved in ion conduction and permeation ...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید