نتایج جستجو برای: pantothenate kinase associated neurodegeneration

تعداد نتایج: 1714897  

Journal: :Neurology 2005
M T Pellecchia E M Valente L Cif S Salvi A Albanese V Scarano U Bonuccelli A R Bentivoglio A D'Amico C Marelli A Di Giorgio P Coubes P Barone B Dallapiccola

Pantothenate kinase-associated neurodegeneration (PKAN) is a rare autosomal-recessive disorder caused by mutations in the PANK2 gene. The authors report clinical and genetic findings of 16 patients with PKAN. The authors identified 12 mutations in the PANK2 gene, five of which were new. Only nine patients could be classified as classic or atypical PKAN, and intermediate phenotypes are described...

Journal: :Journal of intellectual disability research : JIDR 2007
K Freeman A Gregory A Turner P Blasco P Hogarth S Hayflick

BACKGROUND Pantothenate kinase-associated neurodegeneration (PKAN), an extremely rare autosomal recessive disorder resulting in iron accumulation in the brain, has a diverse phenotypic expression. Based on limited case studies of one or two patients, intellectual impairment is considered part of PKAN. Investigations of cognitive functioning have utilized specific neuropsychological tests, witho...

Journal: :American journal of ophthalmology 2003
Susan J Hayflick

PURPOSE The onset of pantothenate kinase-associated neurodegeneration (PKAN) occurs in the first and second decade of life and a pigmentary retinal degeneration is a feature of the disorder. Since the neuro-ophthalmologic and electroretinographic (ERG) features have never been well delineated, we describe them in 16 patients with PKAN. DESIGN Observational case series. METHODS Sixteen patie...

2016
Jae-Hyeok Lee Jongkyu Park Ho-Sung Ryu Hyeyoung Park Young Eun Kim Jin Yong Hong Sang Ook Nam Young-Hee Sung Seung-Hwan Lee Jee-Young Lee Myung Jun Lee Tae-Hyoung Kim Chul Hyoung Lyoo Sun Ju Chung Seong Beom Koh Phil Hyu Lee Jin Whan Cho Mee Young Park Yun Joong Kim Young H. Sohn Beom Seok Jeon Myung Sik Lee

OBJECTIVE Neurodegeneration with brain iron accumulation (NBIA) represents a group of inherited movement disorders characterized by iron accumulation in the basal ganglia. Recent advances have included the identification of new causative genes and highlighted the wide phenotypic variation between and within the specific NBIA subtypes. This study aimed to investigate the current status of NBIA i...

Journal: :Biochemical Society transactions 2014
Paola Venco Sabrina Dusi Lorella Valletta Valeria Tiranti

NBIA (neurodegeneration with brain iron accumulation) comprises a heterogeneous group of neurodegenerative diseases having as a common denominator, iron overload in specific brain areas, mainly basal ganglia and globus pallidus. In the past decade a bunch of disease genes have been identified, but NBIA pathomechanisms are still not completely clear. PKAN (pantothenate kinase-associated neurodeg...

2005
Paul T. Kotzbauer Adam C. Truax John Q. Trojanowski

Mutations in the pantothenate kinase 2 (PANK2) gene have been identified in patients with neurodegeneration with brain iron accumulation (NBIA; formerly Hallervorden–Spatz disease). However, the mechanisms by which these mutations cause neurodegeneration are unclear, especially given the existence of multiple pantothenate kinase genes in humans and multiple PanK2 transcripts with potentially di...

2016
Daniel Nassif João Santos Pereira Mariana Spitz Cláudia Capitão Alessandra Faria

Pantothenate kinase-associated neurodegeneration (PKAN) is an autosomal recessive disorder caused by mutation in the PANK2 gene. It is characterized by abnormal brain iron accumulation, mainly in the globus pallidus. PKAN is included in a group of disorders known as neurodegeneration with brain iron accumulation (NBIA). We report a case of atypical PKAN with its most characteristic presentation...

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