نتایج جستجو برای: merosin

تعداد نتایج: 173  

2017
MK Thong

We report the first known ethnic Malay patient with laminin alpha-2 (merosin) deficiency (MDC1A), a subtype of congenital muscular dystrophy (CMD)as a result of novel LAMA2 gene mutations. The 21-month-old female presented with hypotonia at birth and gross motor delay of her distal lower limbs. Physical examination showed generalised hypotonia, hyporeflexia and myopathic facies but good cogniti...

2017
Sarah J. Smith Jeffrey C. Wang Vandana A. Gupta James J. Dowling

Merosin deficient congenital muscular dystrophy (MDC1A) is a severe neuromuscular disorder with onset in infancy that is associated with severe morbidities (particularly wheelchair dependence) and early mortality. It is caused by recessive mutations in the LAMA2 gene that encodes a subunit of the extracellular matrix protein laminin 211. At present, there are no treatments for this disabling di...

Journal: :Polish journal of pathology : official journal of the Polish Society of Pathologists 2009
Mariusz Gajda Olaf Zagólski Agnieszka Jasztal Grzegorz J Lis Dariusz Adamek Jan A Litwin

Schwannoma is a benign tumour originating from Schwann cells forming sheaths of peripheral nerves. Its location in the oral cavity, and particularly in the cheek, is very rare. A large tumour (5 cm) was surgically removed from the left cheek of a fifty-five-year-old man and pathological examination revealed schwannoma with Antoni A and B patterns. The tumour was investigated using immunofluores...

Journal: :The Journal of Cell Biology 2002
M. Laura Feltri Diana Graus Porta Stefano C. Previtali Alessandro Nodari Barbara Migliavacca Arianna Cassetti Amanda Littlewood-Evans Louis F. Reichardt Albee Messing Angelo Quattrini Ulrich Mueller Lawrence Wrabetz

In dystrophic mice, a model of merosin-deficient congenital muscular dystrophy, laminin-2 mutations produce peripheral nerve dysmyelination and render Schwann cells unable to sort bundles of axons. The laminin receptor and the mechanism through which dysmyelination and impaired sorting occur are unknown. We describe mice in which Schwann cell-specific disruption of beta1 integrin, a component o...

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