نتایج جستجو برای: cysteamine

تعداد نتایج: 950  

2011
Ammar Kutiyanawalla Alvin V. Terry Anilkumar Pillai

OBJECTIVE Stress and glucocorticoid hormones, which are released into the circulation following stressful experiences, have been shown to contribute significantly to the manifestation of anxiety-like behaviors observed in many neuropsychiatric disorders. Brain-derived neurotrophic factor (BDNF) signaling through its receptor TrkB plays an important role in stress-mediated changes in structural ...

Journal: :The Journal of pediatrics 2011
Martine T P Besouw Richard Bowker Jean-Paul Dutertre Francesco Emma William A Gahl Marcella Greco Marc R Lilien John McKiernan François Nobili Jerry A Schneider Flemming Skovby Lambertus P van den Heuvel William G Van't Hoff Elena N Levtchenko

OBJECTIVE To report new adverse effects of cysteamine. STUDY DESIGN Detailed clinical information was obtained from the patients' physicians. RESULTS New adverse events were reported in 8 of 550 patients with cystinosis treated with cysteamine in Europe during the last 5 years. Detailed clinical information was not available for 2 of these patients, 1 of whom died from cerebral ischemia. Th...

2014
Daniela De Stefano Valeria R Villella Speranza Esposito Antonella Tosco Angela Sepe Fabiola De Gregorio Laura Salvadori Rosa Grassia Carlo A Leone Giuseppe De Rosa Maria C Maiuri Massimo Pettoello-Mantovani Stefano Guido Anna Bossi Anna Zolin Andrea Venerando Lorenzo A Pinna Anil Mehta Gianni Bona Guido Kroemer Luigi Maiuri Valeria Raia

Restoration of BECN1/Beclin 1-dependent autophagy and depletion of SQSTM1/p62 by genetic manipulation or autophagy-stimulatory proteostasis regulators, such as cystamine, have positive effects on mouse models of human cystic fibrosis (CF). These measures rescue the functional expression of the most frequent pathogenic CFTR mutant, F508del, at the respiratory epithelial surface and reduce lung i...

Journal: :Human molecular genetics 2015
Marisa I S Mendes Desirée E C Smith João B Vicente Isabel Tavares De Almeida Tawfeg Ben-Omran Gajja S Salomons Isabel A Rivera Paula Leandro Henk J Blom

The key regulatory point of L-methionine (Met) and L-homocysteine (Hcy) degradation is catalyzed by cystathionine beta-synthase (CBS). CBS deficiency is caused by mutations in CBS gene, often resulting in protein misfolding. The prevalence of CBS deficiency in Qatar is 1/1800, ∼200-fold higher than the worldwide prevalence of 1/344 000. Almost all patients bear the CBS p.R336C variant. More tha...

Journal: :The Journal of pediatrics 2003
Ranjan Dohil Robert O Newbury Zachary M Sellers Reena Deutsch Jerry A Schneider

OBJECTIVES Cysteamine prevents organ damage in children with cystinosis, but may cause gastrointestinal (GI) symptoms. In this study we evaluated the nature of GI disease, and the value of omeprazole in controlling GI symptoms in these children. STUDY DESIGN Upper GI disease was evaluated with endoscopy, gastrin levels, and acid secretion studies after oral administration of cysteamine, befor...

Journal: :Medical decision making : an international journal of the Society for Medical Decision Making 1997
N Soohoo J A Schneider R M Kaplan

OBJECTIVE Cysteamine is a recently licensed orphan drug used to treat the inherited metabolic disease cystinosis. The drug delays the onset of renal failure in cystinotic patients and may provide many other significant health benefits. This study examined the cost-effectiveness of the administration of cysteamine to cystinotic patients prior to end-stage renal disease (ESRD). METHOD Decision-...

Journal: :Molecular genetics and metabolism 1998
F Iwata E M Kuehl G F Reed L M McCain W A Gahl M I Kaiser-Kupfer

In nephropathic cystinosis, corneal cystine crystals cause severe photophobia and corneal erosions. Topical cysteamine dissolves these crystals, but cannot be marketed because it rapidly oxidizes to the disulfide form, cystamine, at room temperature. Since cystamine itself could be used commercially, we compared the efficacy of cystamine and cysteamine with respect to cystine crystal dissolutio...

Journal: :American journal of physiology. Gastrointestinal and liver physiology 2009
Tetyana Khomenko Sandor Szabo Xiaoming Deng Hideki Ishikawa Gregory J Anderson Gordon D McLaren

Cysteamine induces perforating duodenal ulcers in rats within 24-48 h. This reducing aminothiol generates hydrogen peroxide in the presence of transition metals (e.g., ferric iron), producing oxidative stress, which may contribute to organ-specific tissue damage. Since most intestinal iron absorption takes place in the proximal duodenum, we hypothesized that cysteamine may disrupt regulation of...

Journal: :Contact dermatitis 2007
Marléne Isaksson Henk van der Walle

Journal: :The Journal of biological chemistry 1967
H Neumann L Boross E Katchalski

Alkaline phosphatase from Escherichia coli catalyzes the hydrolysis of S-substituted monoesters of phosphorothioic acid of the type RSP03Naz (R = -CH2CH2NH2,-CH2CHzNHCOCH3,-CH,COOH, or -CH2CHzCOOCzH~), at the S-P bond, to yield orthophosphate and the corresponding thioalcohols. The rate of enzymic hydrolysis of cysteamine S-phosphate was measured at different pH values and substrate concentrati...

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