نتایج جستجو برای: berardinelli

تعداد نتایج: 127  

Journal: :genetics in the 3rd millennium 0
pooneh nikuei kianoosh malekzadeh minoo rajaei yousef shafeghati

congenital generalized lipodystrophies (cgls) are very rare autosomal recessive disorders which have four types.of the four cgl types, bscl2 (berardinelli–seip congenital lipodystrophy type 2) is the result of mutations in the bscl2/seipingene.bscl2 which is the most severe lipodystrophic phenotype is characterized by generalized lipodystrophy, overgrowth,acanthosisnigricans, hepatomegaly, insu...

Journal: :Archives of disease in childhood 1961
B SENIOR

A bizarre disorder was recently encountered in a female child. There was severe lipodystrophy affecting the entire body, generalized muscular hypertrophy, large hands and feet, a markedly protuberant abdomen, hepatomegaly with biochemical and histological evidence of liver dysfunction, a large clitoris, enlarged cystic ovaries and a low fasting blood sugar concentration. This entity is not uniq...

2016
Martin Pagac Daniel E. Cooper Yanfei Qi Ivan E. Lukmantara Hoi Yin Mak Zengying Wu Yuan Tian Zhonghua Liu Mona Lei Ximing Du Charles Ferguson Damian Kotevski Pawel Sadowski Weiqin Chen Salome Boroda Thurl E. Harris George Liu Robert G. Parton Xun Huang Rosalind A. Coleman Hongyuan Yang

Berardinelli-Seip congenital lipodystrophy 2 (BSCL2) is caused by loss-of-function mutations in SEIPIN, a protein implicated in both adipogenesis and lipid droplet expansion but whose molecular function remains obscure. Here, we identify physical and functional interactions between SEIPIN and microsomal isoforms of glycerol-3-phosphate acyltransferase (GPAT) in multiple organisms. Compared to c...

Journal: :Human molecular genetics 2011
Xin Cui Yuhui Wang Yin Tang Yixiao Liu Liping Zhao Jingna Deng Guoheng Xu Xingui Peng Shenghong Ju George Liu Hongyuan Yang

Berardinelli-Seip congenital lipodystrophy type 2 (BSCL2) is an autosomal recessive disorder characterized by an almost complete loss of adipose tissue, insulin resistance and fatty liver. Here, we create the first murine model of BSCL2 by targeted disruption of seipin, the causative gene for BSCL2. Compared with their wild-type littermates, the seipin(-/-) mice are viable and of normal weight ...

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