نتایج جستجو برای: جهش های gjb2

تعداد نتایج: 479512  

Journal: :Genetic testing and molecular biomarkers 2009
Mortaza Bonyadi Mohsen Esmaeili Masoumeh Abhari Alireza Lotfi

AIMS Mutations in the GJB2 gene-encoding connexin 26 protein are the main cause for autosomal recessive nonsyndromic hearing loss worldwide. In this study, we assessed the contributions made by GJB2 and del(GJB6-D13S1830) mutations to the autosomal recessive nonsyndromic deafness genetic load in Iranian Azeri Turkish patients. RESULTS Probands from 209 different nuclear families were investig...

Journal: :American journal of human genetics 2003
Ignacio Del Castillo Miguel A Moreno-Pelayo Francisco J Del Castillo Zippora Brownstein Sandrine Marlin Quint Adina David J Cockburn Arti Pandya Kirby R Siemering G Parker Chamberlin Ester Ballana Wim Wuyts Andréa Trevas Maciel-Guerra Araceli Alvarez Manuela Villamar Mordechai Shohat Dvorah Abeliovich Hans-Henrik M Dahl Xavier Estivill Paolo Gasparini Tim Hutchin Walter E Nance Edi L Sartorato Richard J H Smith Guy Van Camp Karen B Avraham Christine Petit Felipe Moreno

Mutations in GJB2, the gene encoding connexin-26 at the DFNB1 locus on 13q12, are found in as many as 50% of subjects with autosomal recessive, nonsyndromic prelingual hearing impairment. However, genetic diagnosis is complicated by the fact that 10%-50% of affected subjects with GJB2 mutations carry only one mutant allele. Recently, a deletion truncating the GJB6 gene (encoding connexin-30), n...

ژورنال: :مجله غدد درون ریز و متابولیسم ایران 0
مرضیه محسنی فریدون عزیزی نیلوفر بزاززادگان عاطفه دهقانی مرتضی سیفتی مریم تقدیری پیمان جمالی

مقدمه: جهش در ژن slc26a4 که در جایگاه کروموزومی dfnb4 قرار دارد، سبب ایجاد کاهش شنوایی ارثی به طور غیرسندرمی و سندرمی (سندرم پندرد) می شود. در جمعیت های زیادی جهش این ژن به عنوان دومین عامل ناشنوایی ارثی گزارش شده است. هدف از این مطالعه بررسی شیوع جهش های ژن slc26a4 در خانواده های مبتلا به ناشنوایی سندرمی(سندرم پندرد) و غیرسندرمی در ناشنوایان جسمی مغلوب همراه با کاهش شنوایی ارثی بود. مواد و روش...

2009
Hamid Galehdari Ali Mohammad Foroughmand Maryam Naderi Soorki Gholamreza Mohammadian

BACKGROUND The common GJB2 gene mutation (35delG) has been previously reported from Iranian patients that were affected with nonsyndromic autosomal recessive deafness. We, therefore, for the first time, investigated the prevalence and frequency of the GJB2 gene mutation in the Iranian deaf population with Arabian origins. MATERIALS AND METHODS We amplified and sequenced the entire coding sequ...

Journal: :JAMA dermatology 2015
Jonathan L Levinsohn Jennifer M McNiff Richard J Antaya Keith A Choate

IMPORTANCE Recent data demonstrated somatic mutations in GJB2 that were present in affected porokeratotic eccrine ostial and dermal duct nevus (PEODDN) tissue but absent in unaffected skin. Recognizing that PEODDN lesions can also appear in individuals with keratitis-ichthyosis-deafness syndrome and finding somatic mutations in their cohort, the authors concluded that somatic GJB2 mutation may ...

2016
Kari L. Green Donald L. Swiderski Diane M. Prieskorn Susan J. DeRemer Lisa A. Beyer Josef M. Miller Glenn E. Green Yehoash Raphael

Dietary supplements consisting of beta-carotene (precursor to vitamin A), vitamins C and E and the mineral magnesium (ACEMg) can be beneficial for reducing hearing loss due to aminoglycosides and overstimulation. This regimen also slowed progression of deafness for a boy with GJB2 (CONNEXIN 26) mutations. To assess the potential for treating GJB2 and other forms of hereditary hearing loss with ...

Journal: :Human molecular genetics 2005
Yukihide Maeda Kunihiro Fukushima Kazunori Nishizaki Richard J H Smith

Mutations in GJB2 (gap junction protein, beta-2) are the major cause of autosomal recessive non-syndromic hearing loss. A few allele variants of this gene also cause autosomal dominant non-syndromic hearing loss as a dominant-negative consequence of expression of the mutant protein. Allele-specific gene suppression by RNA interference (RNAi) is a potentially attractive strategy to prevent heari...

Journal: :The Medical journal of Malaysia 2005
B H I Ruszymah I Farah Wahida Y Zakinah Z Zahari M D Norazlinda L Saim B S Aminuddin

Twenty percent of all childhood deafness is due to mutations in the GJB2 gene (Connexin 26). The aim of our study was to determine the prevalence and spectrum of GJB2 mutations in childhood deafness in Malaysia. We analyzed the GJB2 gene in 51 deaf students from Sekolah Pendidikan Khas Alor Setar, Kedah. Bidirectional sequencing indicates that 25% of our childhood deafness has mutation in their...

Journal: :International journal of molecular medicine 2007
Tímea Tóth Susan Kupka Birgit Haack Ferenc Fazakas Laszló Muszbek Nikolaus Blin Markus Pfister István Sziklai

Mutations in the GJB2 gene are the most common cause of hereditary prelingual sensorineural hearing impairment in Europe. Several studies indicate that different members of the connexin protein family interact to form gap junctions in the inner ear. Mutations in different connexin genes may accumulate and, consequently lead to hearing impairment. Therefore, we screened 47 Hungarian GJB2- hetero...

2017
Francisco J. del Castillo Ignacio del Castillo

The inner ear is a very complex sensory organ whose development and function depend on finely balanced interactions among diverse cell types. The many different kinds of inner ear supporting cells play the essential roles of providing physical and physiological support to sensory hair cells and of maintaining cochlear homeostasis. Appropriately enough, the gene most commonly mutated among subje...

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