نتایج جستجو برای: mucopolysaccharidosis type i

تعداد نتایج: 2218703  

2006
P Mueller A Moeckel I Daehnert

A neonate presented with mucopolysaccharidosis-like phenotypic expression and typical signs of dysostosis multiplex but without urinary excretion of glycosaminoglycans. Investigations of lysosomal enzymes in cultured fibroblasts revealed a mucolipidosis type 2, known as I-cell disease. We describe the fatal course of the patient due to complications of an uncommon dilated cardiomyopathy in this...

Journal: :Human mutation 2011
Francesca Bertola Mirella Filocamo Giorgio Casati Matthew Mort Camillo Rosano Anna Tylki-Szymanska Beyhan Tüysüz Orazio Gabrielli Serena Grossi Maurizio Scarpa Giancarlo Parenti Daniela Antuzzi Jaime Dalmau Maja Di Rocco Carlo Dionisi Vici Ilyas Okur Jordi Rosell Attilio Rovelli Francesca Furlan Miriam Rigoldi Andrea Biondi David N Cooper Rossella Parini

Mutational analysis of the IDUA gene was performed in a cohort of 102 European patients with mucopolysaccharidosis type I. A total of 54 distinct mutant IDUA alleles were identified, 34 of which were novel including 12 missense mutations, 2 nonsense mutations, 12 splicing mutations, 5 micro-deletions, 1 micro-duplication 1 translational initiation site mutation, and 1 'no-stop' change (p.X654Re...

Journal: :Blood 2015
Michael A Pulsipher

After a herculean data-gathering effort, in this issue of Blood, Aldenhoven and colleagues from Europe and North America provide an eye-opening assessment of long-term neurocognitive, organ, joint, and tissue function after allogeneic transplantation of children with mucopolysaccharidosis type I–Hurler syndrome (MPS-IH), along with an analysis defining a path to better these outcomes.

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