نتایج جستجو برای: hemojuvelin mutation

تعداد نتایج: 291556  

Journal: :Journal of Cerebral Blood Flow & Metabolism 2019

Journal: :The Journal of clinical investigation 2007
Jodie L Babitt Franklin W Huang Yin Xia Yisrael Sidis Nancy C Andrews Herbert Y Lin

Systemic iron balance is regulated by hepcidin, a peptide hormone secreted by the liver. By decreasing cell surface expression of the iron exporter ferroportin, hepcidin decreases iron absorption from the intestine and iron release from reticuloendothelial stores. Hepcidin excess has been implicated in the pathogenesis of anemia of chronic disease, while hepcidin deficiency has a key role in th...

Journal: :Blood 2010
Paul J Schmidt Nancy C Andrews Mark D Fleming

Mutations in HFE cause the most common form of hereditary hemochromatosis (HH). We previously showed that liver-specific, transgenic overexpression of murine Hfe stimulates production of the iron regulatory hormone hepcidin. Here, we developed several additional transgenic mouse strains to further interrogate the structural basis of HFE function in the pathophysiology of HH. We hypothesized tha...

2007
Lan Lin Erika V. Valore Elizabeta Nemeth Julia B. Goodnough Victoria Gabayan Tomas Ganz

The peptide hormone hepcidin is the principal regulator of systemic iron homeostasis. We examined the pathway by which iron stimulates the production of hepcidin. In humans who ingested 65 mg of iron, the increase in transferrin saturation preceded by hours the increase in urinary hepcidin excretion. Increases in urinary hepcidin concentrations were proportional to the increment in transferrin ...

Journal: :Human molecular genetics 2015
Benedikt Schaefer David Haschka Armin Finkenstedt Britt-Sabina Petersen Igor Theurl Benjamin Henninger Andreas R Janecke Chia-Yu Wang Herbert Y Lin Lothar Veits Wolfgang Vogel Günter Weiss Andre Franke Heinz Zoller

Liver disease due to alpha-1-antitrypsin deficiency (A1ATD) is associated with hepatic iron overload in a subgroup of patients. The underlying cause for this association is unknown. The aim of the present study was to define the genetics of this correlation and the effect of alpha-1-antitrypsin (A1AT) on the expression of the iron hormone hepcidin. Full exome and candidate gene sequencing were ...

2012
Paulo C. J. L. Santos Jose E. Krieger Alexandre C. Pereira

Hereditary hemochromatosis (HH) is an autosomal recessive disorder characterized by enhanced intestinal absorption of dietary iron. Without therapeutic intervention, iron overload leads to multiple organ damage such as liver cirrhosis, cardiomyopathy, diabetes, arthritis, hypogonadism and skin pigmentation. Most HH patients carry HFE mutant genotypes: homozygosity for p.Cys282Tyr or p.Cys282Tyr...

2015
Marco Rausa Michela Ghitti Alessia Pagani Antonella Nai Alessandro Campanella Giovanna Musco Clara Camaschella Laura Silvestri

Hemojuvelin (HJV), the coreceptor of the BMP-SMAD pathway that up-regulates hepcidin transcription, is a repulsive guidance molecule (RGMc) which undergoes a complex intracellular processing. Following autoproteolysis, it is exported to the cell surface both as a full-length and a heterodimeric protein. In vitro membrane HJV (m-HJV) is cleaved by the transmembrane serine protease TMPRSS6 to att...

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