نتایج جستجو برای: fshd

تعداد نتایج: 347  

Journal: :Human molecular genetics 2013
Natacha Broucqsault Julia Morere Marie-Cécile Gaillard Julie Dumonceaux Julia Torrents Emmanuelle Salort-Campana André Maues De Paula Marc Bartoli Carla Fernandez Anne Laure Chesnais Maxime Ferreboeuf Laure Sarda Henry Dufour Claude Desnuelle Shahram Attarian Nicolas Levy Karine Nguyen Frédérique Magdinier Stéphane Roche

Facio-scapulo-humeral dystrophy (FSHD) results from deletions in the subtelomeric macrosatellite D4Z4 array on the 4q35 region. Upregulation of the DUX4 retrogene from the last D4Z4 repeated unit is thought to underlie FSHD pathophysiology. However, no one knows what triggers muscle defect and when alteration arises. To gain further insights into the molecular mechanisms of the disease, we eval...

2013
Naoe Harafuji Peter Schneiderat Maggie C Walter Yi-Wen Chen

BACKGROUND Facioscapulohumeral muscular dystrophy (FSHD) is an autosomal dominant muscle disorder, which is linked to the contraction of the D4Z4 array at chromosome 4q35. Recent studies suggest that this shortening of the D4Z4 array leads to aberrant expression of double homeobox protein 4 (DUX4) and causes FSHD. In addition, misregulation of microRNAs (miRNAs) has been reported in muscular dy...

Journal: :Human molecular genetics 2003
Guanchao Jiang Fan Yang Petra G M van Overveld Vettaikorumakankav Vedanarayanan Silvere van der Maarel Melanie Ehrlich

Facioscapulohumeral muscular dystrophy (FSHD) is a unique dominant disorder involving shortening of an array of tandem 3.3 kb repeats. This copy-number polymorphic repeat, D4Z4, is present in arrays at both 4q35 and 10q26, but only 4q35 arrays with one to 10 copies of the repeat are linked to FSHD. The most popular model for how the 4q35 array-shortening causes FSHD is that it results in a loss...

2016
Sabrina Giacoppo Thangavelu Soundara Rajan Rocco Salvatore Calabrò Placido Bramanti Emanuela Mazzon

Facioscapulohumeral dystrophy (FSHD) is the third most common type of muscular dystrophy after Duchenne and myotonic dystrophy with an incidence of 12 per 100,000 worldwide [1,2]. FSHD is an autosomal dominant disease with an insidious onset and development, characterized by progressive weakness and atrophy of facial, shoulder girdle and upper arm muscles [1]. Currently FSHD diagnosis is mainly...

ژورنال: کومش 2000
ادوارد, ریچارد, بختیاری, امیرهوشنگ, فراستیک, سایمون, فینیکس, جوان,

مقدمه: عمده مشکل بیماران دیستروفی انجام فعالیتهای روزمره می باشد که به دلیل ضعف عضلات اندام فوقانی موجب وابستگی آنها می گردد. هدف توانبخشی این بیماران افزایش کارایی اندام فوقانی در جهت ایجاد استقلال در زندگی شخصی است. در این مطالعه اثر یادگیری حرکتی روی کارایی اندام فوقانی بررسی شد. روش کار: دو مطالعه مختلف برای بررسی اثر یادگیری حرکتی و پیچیدگی مدل یادگیری روی عملکرد اندام فوقانی طراحی و دو مد...

2014
Valery Kazakov

In the present time there is the opinion that FSHD is a disease genetically heterogeneous, but homogeneous from a clinical point of view: “...clinical, genetic and epigenetic features of facioscapulohumeral muscular dystrophy (FSHD) allowed the identification of two forms of FSHD, the classical autosomal dominant FSHD type 1, and the FSHD type 2 characterized by an identical clinical phenotype ...

2010
Lauren Snider Linda N. Geng Richard J. L. F. Lemmers Michael Kyba Carol B. Ware Angelique M. Nelson Rabi Tawil Galina N. Filippova Silvère M. van der Maarel Stephen J. Tapscott Daniel G. Miller

Each unit of the D4Z4 macrosatellite repeat contains a retrotransposed gene encoding the DUX4 double-homeobox transcription factor. Facioscapulohumeral dystrophy (FSHD) is caused by deletion of a subset of the D4Z4 units in the subtelomeric region of chromosome 4. Although it has been reported that the deletion of D4Z4 units induces the pathological expression of DUX4 mRNA, the association of D...

2014
Veronica Colangelo Stéphanie François Giulia Soldà Raffaella Picco Francesca Roma Enrico Ginelli Raffaella Meneveri Atsushi Asakura

Emerging evidence has demonstrated that miRNA sequences can regulate skeletal myogenesis by controlling the process of myoblast proliferation and differentiation. However, at present a deep analysis of miRNA expression in control and FSHD myoblasts during differentiation has not yet been derived. To close this gap, we used a next-generation sequencing (NGS) approach applied to in vitro myogenes...

2009
Weihua Zeng Jessica C. de Greef Yen-Yun Chen Richard Chien Xiangduo Kong Heather C. Gregson Sara T. Winokur April Pyle Keith D. Robertson John A. Schmiesing Virginia E. Kimonis Judit Balog Rune R. Frants Alexander R. Ball Leslie F. Lock Peter J. Donovan Silvère M. van der Maarel Kyoko Yokomori

Facioscapulohumeral dystrophy (FSHD) is an autosomal dominant muscular dystrophy in which no mutation of pathogenic gene(s) has been identified. Instead, the disease is, in most cases, genetically linked to a contraction in the number of 3.3 kb D4Z4 repeats on chromosome 4q. How contraction of the 4qter D4Z4 repeats causes muscular dystrophy is not understood. In addition, a smaller group of FS...

2013
Félix F. González-Navarro Lluís A. Belanche-Muñoz Karen A. Silva-Colón

The Facioscapulohumeral Muscular Dystrophy (FSHD) is an autosomal dominant neuromuscular disorder whose incidence is estimated in about one in 400,000 to one in 20,000. No effective therapeutic strategies are known to halt progression or reverse muscle weakness and atrophy. It is known that the FSHD is caused by modifications located within a D4ZA repeat array in the chromosome 4q, while recent...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید