نتایج جستجو برای: fanconi anemia patients

تعداد نتایج: 2119640  

Journal: :Blood 2011
Jean E Sanders Ann E Woolfrey Paul A Carpenter Barry E Storer Paul A Hoffmeister H Joachim Deeg Mary E D Flowers Rainer F Storb

Aplastic anemia (AA), a potentially fatal disease, may be cured with marrow transplantation. Survival in pediatric patients has been excellent early after transplantation, but only limited data are available regarding late effects. This study evaluates late effects among 152 patients followed 1-38 years (median, 21.8 years). Transplantation-preparative regimes were mostly cyclophosphamide with ...

Journal: :The Journal of Clinical Endocrinology & Metabolism 2007

2012
Terrie Flatt Kathleen Neville Karen Lewing Jignesh Dalal

Fanconi anemia is associated with an increased risk of malignancy. Patients are sensitive to the toxic effects of chemotherapy. We report the case of a patient with Fanconi anemia who developed T-cell acute lymphoblastic leukemia. He experienced chemotherapy-related complications including prolonged neutropenia, grade IV vincristine neuropathy, and disseminated aspergillosis. He was successfull...

Journal: :Cancer research 2006
Tanja Pejovic Jane E Yates Hong Y Liu Laura E Hays Yassmine Akkari Yumi Torimaru Winifred Keeble R Keaney Rathbun William H Rodgers Allen E Bale Najim Ameziane C Michael Zwaan Abdellatif Errami Philippe Thuillier Fabio Cappuccini Susan B Olson Joanna M Cain Grover C Bagby

Fanconi anemia is an inherited cancer predisposition disease characterized by cytogenetic and cellular hypersensitivity to cross-linking agents. Seeking evidence of Fanconi anemia protein dysfunction in women at risk of ovarian cancer, we screened ovarian surface epithelial cells from 25 primary cultures established from 22 patients using cross-linker hypersensitivity assays. Samples were obtai...

2018
Roberta Bottega Elena Nicchia Enrico Cappelli Silvia Ravera Daniela De Rocco Michela Faleschini Fabio Corsolini Filomena Pierri Michaela Calvillo Giovanna Russo Gabriella Casazza Ugo Ramenghi Piero Farruggia Carlo Dufour Anna Savoia

Fanconi anemia is a rare disease characterized by congenital malformations, aplastic anemia, and predisposition to cancer. Despite the consolidated role of the Fanconi anemia proteins in DNA repair, their involvement in mitochondrial function is emerging. The purpose of this work was to assess whether the mitochondrial phenotype, independent of genomic integrity, could correlate with patient ph...

Journal: :Molecular cancer research : MCR 2012
Younghoon Kee Min Huang Sophia Chang Lisa A Moreau Eunmi Park Peter G Smith Alan D D'Andrea

The Fanconi anemia pathway is required for repair of DNA interstrand cross-links (ICL). Fanconi anemia pathway-deficient cells are hypersensitive to DNA ICL-inducing drugs such as cisplatin. Conversely, hyperactivation of the Fanconi anemia pathway is a mechanism that may underlie cellular resistance to DNA ICL agents. Modulating FANCD2 monoubiquitination, a key step in the Fanconi anemia pathw...

Journal: :Cancer discovery 2015
Sarah L Sawyer Lei Tian Marketta Kähkönen Jeremy Schwartzentruber Martin Kircher Jacek Majewski David A Dyment A Micheil Innes Kym M Boycott Lisa A Moreau Jukka S Moilanen Roger A Greenberg

UNLABELLED Deficiency in BRCA-dependent DNA interstrand crosslink (ICL) repair is intimately connected to breast cancer susceptibility and to the rare developmental syndrome Fanconi anemia. Bona fide Fanconi anemia proteins, BRCA2 (FANCD1), PALB2 (FANCN), and BRIP1 (FANCJ), interact with BRCA1 during ICL repair. However, the lack of detailed phenotypic and cellular characterization of a patient...

2012
Younghoon Kee Min Huang Sophia Chang Lisa A. Moreau Eunmi Park Peter G. Smith Alan D. D'Andrea

The Fanconi anemia pathway is required for repair of DNA interstrand cross-links (ICL). Fanconi anemia pathway–deficient cells are hypersensitive to DNA ICL–inducing drugs such as cisplatin. Conversely, hyperactivation of the Fanconi anemia pathway is a mechanism that may underlie cellular resistance to DNA ICL agents. Modulating FANCD2 monoubiquitination, a key step in the Fanconi anemia pathw...

Journal: :Clinical genetics 2011
M H Kang

SLX4, a coordinator of structure-specific endo-nucleases, is mutated in a new Fanconi anemia subtype Stoepker et al. (2011) Nature Genetics 43:138-141. Mutations of the SLX4 gene in Fanconi anemia Kim et al. (2011) Nature Genetics 43:142-146.

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