نتایج جستجو برای: cartilage hair hypoplasia

تعداد نتایج: 77284  

Journal: :Cell 2001
Maaret Ridanpää Hans van Eenennaam Katarina Pelin Robert Chadwick Cheryl Johnson Bo Yuan Walther vanVenrooij Ger Pruijn Riika Salmela Susanna Rockas Outi Mäkitie Ilkka Kaitila Albert de la Chapelle

The recessively inherited developmental disorder, cartilage-hair hypoplasia (CHH) is highly pleiotropic with manifestations including short stature, defective cellular immunity, and predisposition to several cancers. The endoribonuclease RNase MRP consists of an RNA molecule bound to several proteins. It has at least two functions, namely, cleavage of RNA in mitochondrial DNA synthesis and nucl...

Journal: :Turkish journal of haematology : official journal of Turkish Society of Haematology 2009
Namık Özbek

Several congenital disorders may cause neutropenia. The recent advances in the field of molecular biology have facilitated our knowledge concerning pathophysiological mechanisms leading to these disorders. The molecular basis of disorders with defective myelopoiesis (severe congenital neutropenia and cyclic neutropenia) and disorders due to defective RNA processing (Shwachman Diamond syndrome a...

2011
Joseph Rosenbluh Deepak Nijhawan Zhao Chen Kwok-Kin Wong Kenkichi Masutomi William C. Hahn

RMRP is a non-coding RNA that is ubiquitously expressed in both humans and mice. RMRP mutations that lead to decreased RMRP levels are found in the pleiotropic syndrome Cartilage Hair Hypoplasia. To assess the effects of deleting RMRP, we engineered a targeting vector that contains loxP sequences flanking RMRP and created hemizygous mice harboring this engineered allele (RMRP conditional). We f...

Journal: :The Turkish journal of pediatrics 2009
Gülten Türkkani-Asal Yasemin Alanay Tuba Turul-Ozgür Martin Zenker Christian Thiel Anita Rauch Sule Unal Aytemiz Gürgey Ilhan Tezcan

Cartilage-hair hypoplasia (CHH) is one of the well-known immuno-osseous dysplasias (IOD), which are a combination of skeletal dysplasia and immunodeficiency. It is characterized by disproportionate short stature, fine sparse hair, ligamentous laxity, hematological abnormalities with anemia, a predisposition to malignant tumors, and recurrent infections usually due to cellular and/or humoral imm...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید