نتایج جستجو برای: brain iron accumulation

تعداد نتایج: 749017  

Journal: :Brain : a journal of neurology 2013
Susan J Hayflick Michael C Kruer Allison Gregory Tobias B Haack Manju A Kurian Henry H Houlden James Anderson Nathalie Boddaert Lynn Sanford Sami I Harik Vasuki H Dandu Nardo Nardocci Giovanna Zorzi Todd Dunaway Mark Tarnopolsky Steven Skinner Kenton R Holden Steven Frucht Era Hanspal Connie Schrander-Stumpel Cyril Mignot Delphine Héron Dawn E Saunders Margaret Kaminska Jean-Pierre Lin Karine Lascelles Stephan M Cuno Esther Meyer Barbara Garavaglia Kailash Bhatia Rajith de Silva Sarah Crisp Peter Lunt Martyn Carey John Hardy Thomas Meitinger Holger Prokisch Penelope Hogarth

Neurodegenerative disorders with high iron in the basal ganglia encompass an expanding collection of single gene disorders collectively known as neurodegeneration with brain iron accumulation. These disorders can largely be distinguished from one another by their associated clinical and neuroimaging features. The aim of this study was to define the phenotype that is associated with mutations in...

Journal: :The Biochemical journal 2010
Darius J R Lane Stephen R Robinson Hania Czerwinska Glenda M Bishop Alfons Lawen

Astrocytes are central to iron and ascorbate homoeostasis within the brain. Although NTBI (non-transferrin-bound iron) may be a major form of iron imported by astrocytes in vivo, the mechanisms responsible remain unclear. The present study examines NTBI uptake by cultured astrocytes and the involvement of ascorbate and DMT1 (divalent metal transporter 1). We demonstrate that iron accumulation b...

2016
Daniel Nassif João Santos Pereira Mariana Spitz Cláudia Capitão Alessandra Faria

Pantothenate kinase-associated neurodegeneration (PKAN) is an autosomal recessive disorder caused by mutation in the PANK2 gene. It is characterized by abnormal brain iron accumulation, mainly in the globus pallidus. PKAN is included in a group of disorders known as neurodegeneration with brain iron accumulation (NBIA). We report a case of atypical PKAN with its most characteristic presentation...

2014
Kimberly B. Zumbrennen-Bullough Lore Becker Lillian Garrett Sabine M. Hölter Julia Calzada-Wack Ilona Mossbrugger Leticia Quintanilla-Fend Ildiko Racz Birgit Rathkolb Thomas Klopstock Wolfgang Wurst Andreas Zimmer Eckhard Wolf Helmut Fuchs Valerie Gailus-Durner Martin Hrabě de Angelis Steven J. Romney Elizabeth A. Leibold

Iron Regulatory Protein 2 (Irp2, Ireb2) is a central regulator of cellular iron homeostasis in vertebrates. Two global knockout mouse models have been generated to explore the role of Irp2 in regulating iron metabolism. While both mouse models show that loss of Irp2 results in microcytic anemia and altered body iron distribution, discrepant results have drawn into question the role of Irp2 in r...

2010
L. Timmermann K. A. M. Pauls K. Wieland R. Jech G. Kurlemann N. Sharma S. S. Gill C. A. Haenggeli S. J. Hayflick P. Hogarth K. L. Leenders P. Limousin C. J. Malanga E. Moro J. L. Ostrem F. J. Revilla P. Santens A. Schnitzler S. Tisch F. Valldeoriola J. Vesper J. Volkmann D. Woitalla, S. Peker

Neurodegeneration with brain iron accumulation encompasses a heterogeneous group of rare neurodegenerative disorders that are characterized by iron accumulation in the brain. Severe generalized dystonia is frequently a prominent symptom and can be very disabling, causing gait impairment, difficulty with speech and swallowing, pain and respiratory distress. Several case reports and one case seri...

Journal: :Neurosurgical focus 2003
Takehiro Nakamura Richard F Keep Ya Hua Timothy Schallert Julian T Hoff Guohua Xi

OBJECT Previous studies undertaken by the authors have indicated that iron accumulation and oxidative stress in the brain contribute to secondary brain damage after intracerebral hemorrhage (ICH). In the present study the authors investigate whether deferoxamine, an iron chelator, can reduce ICH-induced brain injury. METHODS Male Sprague-Dawley rats each received an infusion of 100 microl of ...

Journal: :Haematologica 2011
Giovanni Abbruzzese Giovanni Cossu Manuela Balocco Roberta Marchese Daniela Murgia Maurizio Melis Renzo Galanello Susanna Barella Gildo Matta Uberto Ruffinengo Ubaldo Bonuccelli Gian Luca Forni

Deferiprone was shown to reverse iron deposition in Friedreich's ataxia. This multi-center, unblinded, single-arm pilot study evaluated safety and efficacy of deferiprone for reducing cerebral iron accumulation in neurodegeneration with brain iron accumulation. Four patients with genetically-confirmed pantothenate kinase-associated neurodegeneration, and 2 with parkinsonism and focal dystonia, ...

2016
Conceição Bettencourt Paola Forabosco Sarah Wiethoff Moones Heidari Daniel M. Johnstone Juan A. Botía Joanna F. Collingwood John Hardy Elizabeth A. Milward Mina Ryten Henry Houlden

Aberrant brain iron deposition is observed in both common and rare neurodegenerative disorders, including those categorized as Neurodegeneration with Brain Iron Accumulation (NBIA), which are characterized by focal iron accumulation in the basal ganglia. Two NBIA genes are directly involved in iron metabolism, but whether other NBIA-related genes also regulate iron homeostasis in the human brai...

2016
Yorka Muñoz Carlos M Carrasco Joaquín D Campos Pabla Aguirre Marco T Núñez

Mitochondrial dysfunction, iron accumulation, and oxidative damage are conditions often found in damaged brain areas of Parkinson's disease. We propose that a causal link exists between these three events. Mitochondrial dysfunction results not only in increased reactive oxygen species production but also in decreased iron-sulfur cluster synthesis and unorthodox activation of Iron Regulatory Pro...

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