نتایج جستجو برای: autosomal recessive primary microcephaly

تعداد نتایج: 682552  

2011
Saqib Mahmood Wasim Ahmad Muhammad J Hassan

Autosomal Recessive Primary Microcephaly (MCPH) is a rare disorder of neurogenic mitosis characterized by reduced head circumference at birth with variable degree of mental retardation. In MCPH patients, brain size reduced to almost one-third of its original volume due to reduced number of generated cerebral cortical neurons during embryonic neurogensis. So far, seven genetic loci (MCPH1-7) for...

2013
Lina Issa Katrin Mueller Katja Seufert Nadine Kraemer Henning Rosenkotter Olaf Ninnemann Michael Buob Angela M Kaindl Deborah J Morris-Rosendahl

BACKGROUND Primary autosomal recessive microcephaly (MCPH) is a rare neurodevelopmental disorder that results in severe microcephaly at birth with pronounced reduction in brain volume, particularly of the neocortex, simplified cortical gyration and intellectual disability. Homozygous mutations in the Cyclin-dependent kinase 5 regulatory subunit-associated protein 2 gene CDK5RAP2 are the cause o...

Journal: :Molecular biology of the cell 2008
Ka-Wing Fong Yuk-Kwan Choi Jerome B Rattner Robert Z Qi

Microtubule nucleation and organization by the centrosome require gamma-tubulin, a protein that exists in a macromolecular complex called the gamma-tubulin ring complex (gammaTuRC). We report characterization of CDK5RAP2, a novel centrosomal protein whose mutations have been linked to autosomal recessive primary microcephaly. In somatic cells, CDK5RAP2 localizes throughout the pericentriolar ma...

Journal: :genetics in the 3rd millennium 0
فاطمه هادی پور fatemeh hadipour medical genetics department, sarem women’s hospital. tehran, iran یوسف شفقتی yousof shafeghati 1- medical genetics department, sarem women’s hospital. tehran, iran 2-genetics research center, university of welfare science and rehabilitation, tehran. iran زهرا هادی پور zahra hadipour medical genetics department, sarem women’s hospital. tehran, iran مهرداد نوروزی نیا mehrdad noruzinia medical genetics department, sarem women’s hospital. tehran, iran.department of medical genetics, school of medical sciences, tarbiat modares university, tehran, iran فرخنده بهجتی farkhondeh behjati genetics research center, university of welfare science and rehabilitation, tehran. iran

cockayne syndrome is a very rare genetic disorder with a recessive autosomal mode of inheritance characterized by dwarfism, microcephaly, mental retardation, deafness, photosensive dermatitis and a peculiar form of retinal pigmentation. we report an iranian family with one affected child who suffers from cockayne syndrome. cardinal features are failure to thrive, short stature, premature aging,...

2015
Sandrine Floriot Christine Vesque Sabrina Rodriguez Florence Bourgain-Guglielmetti Anthi Karaiskou Mathieu Gautier Amandine Duchesne Sarah Barbey Sébastien Fritz Alexandre Vasilescu Maud Bertaud Mohammed Moudjou Sophie Halliez Valérie Cormier-Daire Joyce E L Hokayem Erich A Nigg Luc Manciaux Raphaël Guatteo Nora Cesbron Geraldine Toutirais André Eggen Sylvie Schneider-Maunoury Didier Boichard Joelle Sobczak-Thépot Laurent Schibler

Caprine-like Generalized Hypoplasia Syndrome (SHGC) is an autosomal-recessive disorder in Montbéliarde cattle. Affected animals present a wide range of clinical features that include the following: delayed development with low birth weight, hind limb muscular hypoplasia, caprine-like thin head and partial coat depigmentation. Here we show that SHGC is caused by a truncating mutation in the CEP2...

2013
Manèl Chograni Myriam Chaabouni Faouzi Maazoul Habiba Chaabouni Bouhamed

Purpose: To identify the causative gene for phenotypes associating autosomal recessive congenital cataract, mental retardation and congenital cataract, mental retardation and microcephaly in four unrelated Tunisian families. Methods: Four genes (EPHA2, GALK1, GCNT2, and CRYBB1) were selected based on their expression in human brain and their known or putative function. Linkage analysis were per...

Journal: :Turkish Journal of Pediatrics 2021

BACKGROUND Isolated sulfite oxidase deficiency (ISOD), caused by mutations in SUOX gene, is an autosomal recessive disease manifesting with early onset seizures, developmental delay, microcephaly, and spasticity. It mimics hypoxic-ischemic encephalopathy (HIE) the neonatal period characterized progressive severe neurological impairment due to accumulation of toxic metabolites. CASE This report ...

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