نتایج جستجو برای: apert syndrome

تعداد نتایج: 621953  

Journal: :International Journal of Research in Medical Sciences 2013

Journal: :Development 2005
Yingli Wang Ran Xiao Fan Yang Baktiar O Karim Anthony J Iacovelli Juanliang Cai Charles P Lerner Joan T Richtsmeier Jen M Leszl Cheryl A Hill Kai Yu David M Ornitz Jennifer Elisseeff David L Huso Ethylin Wang Jabs

Apert syndrome is an autosomal dominant disorder characterized by malformations of the skull, limbs and viscera. Two-thirds of affected individuals have a S252W mutation in fibroblast growth factor receptor 2 (FGFR2). To study the pathogenesis of this condition, we generated a knock-in mouse model with this mutation. The Fgfr2(+/S252W) mutant mice have abnormalities of the skeleton, as well as ...

Journal: :IP international journal of ocular oncology and oculoplasty 2023

Apert syndrome is a congenital type 1 acrocephalosyndactyly characterized by craniosynostosis, dysmorphic facial features and symmetrical syndactyly. There premature fusion of cranial sutures which leads to restriction intracranial orbital space expansion giving characteristic appearance. We are reporting two cases different age groups from ophthalmic point view, with sets ocular manifestation....

Journal: :Journal of medical genetics 1998
M R Passos-Bueno A Richieri-Costa A L Sertié A Kneppers

Apert syndrome, characterised by craniosynostosis, craniofacial anomalies, and symmetrical syndactyly of the digits (cutaneous and bony fusion), has been associated with two canonical mutations in the FGFR2 gene (S252W, P253R) in the great majority of cases. Since these two alterations have been observed exclusively among these patients, it has been suggested that the S252W and P253R changes ma...

Journal: :Bone 2008
Fan Yang Yingli Wang Zijun Zhang Bryan Hsu Ethylin Wang Jabs Jennifer H Elisseeff

Apert syndrome is caused by mutations in fibroblast growth factor receptor 2 (Fgfr2) and is characterized by craniosynostosis and other skeletal abnormalities. The Apert syndrome Fgfr2+/S252W mouse model exhibits perinatal lethality. A 3D hydrogel culture model, derived from tissue engineering strategies, was used to extend the study of the effect of the Fgfr2+/S252W mutation in differentiating...

2010
Elena G Bochukova Shamit Soneji Steven A Wall Andrew O M Wilkie

BACKGROUND Craniosynostosis can be caused by both genetic and environmental factors, the relative contributions of which vary between patients. Genetic testing identifies a pathogenic mutation or chromosomal abnormality in ∼ 21% of cases, but it is likely that further causative mutations remain to be discovered. OBJECTIVE To identify a shared signature of genetically determined craniosynostos...

Journal: :Medical Journal of Dr. D.Y. Patil University 2014

Journal: :Egyptian Journal of Anaesthesia 2015

2010

Apert syndrome is a birth defect caused by mutation of either of two specific base pairs. The syndrome occurs at a rate of about 1 in 200,000 live births, much higher than the estimated 1 in 100,000,000 expected from the average estimated human mutation rate. Mutation rates do vary significantly across the genome (e.g. “hot spots”); but such a large variation is still very unexpected. It has al...

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