نتایج جستجو برای: menkes

تعداد نتایج: 1314  

Journal: :Indian Journal of Dermatology 2012

Journal: :Pediatric Neurology Briefs 1994

Journal: :Biochimica et Biophysica Acta (BBA) - Molecular Basis of Disease 2006

2005
Roxana M. Llanos Magali Wright Yolanda Deal

21 The Menkes protein (ATP7A) is defective in the Cu deficiency disorder, Menkes 22 disease and is an important contributor to maintenance of physiological copper homeostasis. To 23 investigate more fully the role of ATP7A, transgenic mice expressing the human Menkes gene 24 ATP7A from chicken β-actin composite promoter (CAG) were produced. The transgenic mice 25 expressed ATP7A in lung, heart,...

Journal: :Human molecular genetics 1997
A Grimes C J Hearn P Lockhart D F Newgreen J F Mercer

The brindled mouse mutant (Mo(br)) is the closest animal model of the human genetic copper deficiency, Menkes disease, which is presumed to be due to a mutation at the X-linked mottled locus (Mo). The mutant mice are hypopigmented and die at around 15 days after birth, but can be saved by treatment with copper before the 10th postnatal day. Menkes disease has been shown to be due to mutations o...

Journal: :Romanian journal of morphology and embryology = Revue roumaine de morphologie et embryologie 2014
Dana Craiu Stephen Kaler Mihai Craiu

We report the case of a male patient with a normal development in the first three months of life, presenting for global regression, central axial hypotonic syndrome, pyramidal syndrome, focal epileptic seizures, and a particular aspect of the hair - almost absent, short, sparse, lightly colored, at age of five months, becoming coarse, twisted (kinky hair) by the age of 21 months. Different dise...

Journal: :American journal of physiology. Regulatory, integrative and comparative physiology 2006
Bi-Xia Ke Roxana M Llanos Magali Wright Yolanda Deal Julian F B Mercer

The Menkes protein (ATP7A) is defective in the Cu deficiency disorder Menkes disease and is an important contributor to the maintenance of physiological Cu homeostasis. To investigate more fully the role of ATP7A, transgenic mice expressing the human Menkes gene ATP7A from chicken beta-actin composite promoter (CAG) were produced. The transgenic mice expressed ATP7A in lung, heart, liver, kidne...

Journal: :AJNR. American journal of neuroradiology 2017
R Manara L D'Agata M C Rocco R Cusmai E Freri L Pinelli F Darra E Procopio R Mardari C Zanus G Di Rosa C Soddu M Severino M Ermani D Longo S Sartori

Menkes disease is a rare multisystem X-linked disorder of copper metabolism. Despite an early, severe, and progressive neurologic involvement, our knowledge of brain involvement remains unsatisfactory. The first part of this retrospective and review MR imaging study aims to define the frequency rate, timing, imaging features, and evolution of intracranial vascular and white matter changes. Acco...

Journal: :Pediatric Neurology Briefs 1997

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