نتایج جستجو برای: hemojuvelin mutation

تعداد نتایج: 291556  

Journal: :Blood 2007
Laura Silvestri Alessia Pagani Claudia Fazi Gianmario Gerardi Sonia Levi Paolo Arosio Clara Camaschella

Hemojuvelin (HJV) positively modulates the iron regulator hepcidin, and its mutations are the major cause of juvenile hemochromatosis (JH), a recessive disease leading to iron overload. Defective HJV reduces hepcidin up-regulation both in humans and in Hjv-deficient mice. To investigate the JH pathogenesis and the functional properties of human HJV we studied the biosynthesis and maturation of ...

Journal: :Blood 2009
Jaroslav Truksa Pauline Lee Ernest Beutler

Hepcidin plays a major role in the regulation of iron homeostasis. Several bone morphogenetic proteins (BMPs) are strong inducers of hepcidin (Hamp1, HAMP) expression. Hemojuvelin, a protein critical for maintaining appropriate levels of hepcidin, acts as a coreceptor for BMP2 and BMP4, thereby providing a link between iron homeostasis and the BMP-signaling pathway. We show that a robust BMP, h...

Journal: :The Journal of clinical investigation 2005
Sophie Vaulont Dan-Qing Lou Lydie Viatte Axel Kahn

Recently, mutations causing juvenile hemochromatosis have been identified in a novel gene, hemojuvelin (HJV), located on chromosome 1. Mouse models of this disease have now been developed by 2 groups, Huang et al. and Niederkofler et al., through targeted disruption of the Hjv gene (see the related articles beginning on pages 2180 and 2187). These mutant mice will allow further investigation in...

Journal: :Journal of Veterinary Internal Medicine 2020

Journal: :Journal of Veterinary Medical Science 2015

Journal: :Journal of immunology 2011
Yin Xia Virna Cortez-Retamozo Vera Niederkofler Rishard Salie Shanzhuo Chen Tarek A Samad Charles C Hong Silvia Arber Jatin M Vyas Ralph Weissleder Mikael J Pittet Herbert Y Lin

Repulsive guidance molecule (RGM) family members RGMa, RGMb/Dragon, and RGMc/hemojuvelin were found recently to act as bone morphogenetic protein (BMP) coreceptors that enhance BMP signaling activity. Although our previous studies have shown that hemojuvelin regulates hepcidin expression and iron metabolism through the BMP pathway, the role of the BMP signaling mediated by Dragon remains largel...

Journal: :Blood 2007
Lan Lin Erika V Valore Elizabeta Nemeth Julia B Goodnough Victoria Gabayan Tomas Ganz

The peptide hormone hepcidin is the principal regulator of systemic iron homeostasis. We examined the pathway by which iron stimulates the production of hepcidin. In humans who ingested 65 mg of iron, the increase in transferrin saturation preceded by hours the increase in urinary hepcidin excretion. Increases in urinary hepcidin concentrations were proportional to the increment in transferrin ...

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