نتایج جستجو برای: col6a2

تعداد نتایج: 61  

Journal: :American journal of human genetics 2012
Christine Ackerman Adam E Locke Eleanor Feingold Benjamin Reshey Karina Espana Janita Thusberg Sean Mooney Lora J H Bean Kenneth J Dooley Clifford L Cua Roger H Reeves Stephanie L Sherman Cheryl L Maslen

About half of people with trisomy 21 have a congenital heart defect (CHD), whereas the remainder have a structurally normal heart, demonstrating that trisomy 21 is a significant risk factor but is not causal for abnormal heart development. Atrioventricular septal defects (AVSD) are the most commonly occurring heart defects in Down syndrome (DS), and ∼65% of all AVSD is associated with DS. We us...

2011
Jong Hui Suh Jeong-Seob Yoon Jong-Bum Kwon Hwan Wook Kim Young-Pil Wang

BACKGROUND The aim of the present study was to identify chromosomal loci that contribute to the pathogenesis of aortic dissection (AD) in a Korean population using array comparative genomic hybridization (CGH) and to confirm the results using real-time polymerase chain reaction (PCR). MATERIALS AND METHODS Eighteen patients with ADs were enrolled in this study. Genomic DNA was extracted from ...

Journal: :Molecular medicine reports 2015
Xiang-Dong Kong Ning Liu Xue-Ju Xu Zhen-Hua Zhao Miao Jiang

The aim of the current study was to identify the genes on human chromosome 21 (HC21) that may serve important functions in the pathogenesis of Down syndrome (DS). The microarray data GSE5390 were obtained from the Gene Expression Omnibus database, which contained 7 DS and 8 healthy normal samples. The data were then normalized and the differentially expressed genes (DEGs) were identified using ...

Journal: :Clinical cancer research : an official journal of the American Association for Cancer Research 2007
Anil Vachani Michael Nebozhyn Sunil Singhal Linda Alila Elliot Wakeam Ruth Muschel Charles A Powell Patrick Gaffney Bhuvanesh Singh Marcia S Brose Leslie A Litzky John Kucharczuk Larry R Kaiser J Stephen Marron Michael K Showe Steven M Albelda Louise C Showe

PURPOSE The risk of developing metastatic squamous cell carcinoma for patients with head and neck squamous cell carcinoma (HNSCC) is very high. Because these patients are often heavy tobacco users, they are also at risk for developing a second primary cancer, with squamous cell carcinoma of the lung (LSCC) being the most common. The distinction between a lung metastasis and a primary LSCC is cu...

2014
Partha Sen Avinash V. Dharmadhikari Tadeusz Majewski Mahmoud A. Mohammad Tanya V. Kalin Joanna Zabielska Xiaomeng Ren Molly Bray Hannah M. Brown Stephen Welty Sundararajah Thevananther Claire Langston Przemyslaw Szafranski Monica J. Justice Vladimir V. Kalinichenko Anna Gambin John Belmont Pawel Stankiewicz

Alveolar Capillary Dysplasia with Misalignment of Pulmonary Veins (ACDMPV) is a developmental disorder of the lungs, primarily affecting their vasculature. FOXF1 haploinsufficiency due to heterozygous genomic deletions and point mutations have been reported in most patients with ACDMPV. The majority of mice with heterozygous loss-of-function of Foxf1 exhibit neonatal lethality with evidence of ...

Journal: :Human molecular genetics 2015
Laetitia Ramanoudjame Claire Rocancourt Jeanne Lainé Arnaud Klein Lucette Joassard Corine Gartioux Marjory Fleury Laura Lyphout Edor Kabashi Sorana Ciura Xavier Cousin Valérie Allamand

Collagen VI (COLVI), a protein ubiquitously expressed in connective tissues, is crucial for structural integrity, cellular adhesion, migration and survival. Six different genes are recognized in mammalians, encoding six COLVI-chains that assemble as two 'short' (α1, α2) and one 'long' chain (theoretically any one of α3-6). In humans, defects in the most widely expressed heterotrimer (α123), due...

2017
Kristin L. Fraser Scott Wong A. Reghan Foley Sameer Chhibber Carsten G. Bönnemann Daniel J. Lesser Carla Grosmann Anne Rutkowski

Collagen VI-related dystrophy (collagen VI-RD) is a rare neuromuscular condition caused by mutations in the COL6A1, COL6A2 or COL6A3 genes. The phenotypic spectrum includes early-onset Ullrich congenital muscular dystrophy, adult-onset Bethlem myopathy and an intermediate phenotype. The disorder is characterised by distal hyperlaxity and progressive muscle weakness, joint contractures and respi...

Journal: :BMJ case reports 2013
Jasper M Morrow Robert D S Pitceathly Ros M Quinlivan Tarek A Yousry

To cite: Morrow JM, Pitceathly RDS, Quinlivan RM, et al. BMJ Case Rep Published online: [please include Day Month Year] doi:10.1136/bcr-2013008596 DESCRIPTION A 44-year-old man presented with progressive limb girdle weakness from 10 years of age. The inheritance pattern was autosomal dominant; two siblings, his mother and maternal grandfather were similarly affected. On examination there was an...

2013
Arpita Dey Krishnendu Bhowmik Arpita Chatterjee Pit Baran Chakrabarty Swagata Sinha Kanchan Mukhopadhyay

Down syndrome (DS), the principal cause for intellectual disability, is also associated with hormonal, immunological, and gastrointestinal abnormalities. Muscle hypotonia (MH) and congenital heart diseases (CHD) are also frequently observed. Collagen molecules are essential components for maintaining muscle integrity and are formed by the assembly of three chains, alpha 1-3. The type VI collage...

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