نتایج جستجو برای: bethlem myopathy

تعداد نتایج: 12325  

2016
Matthew P. Wicklund

The limb-girdle muscular dystrophies (LGMDs) encompass a collection of genetic muscle diseases with proximal-predominant weakness of the limbs. Thirty-two of these disorders are named via the common nomenclature, including 8 autosomal-dominant (LGMD1A-H) and 24 autosomal-recessive (LGMD2A-X) disorders.(1) In addition, numerous other genetic muscle diseases, including Bethlem myopathy, dystrophi...

2012
P Sabatelli E Palma A Angelin S Squarzoni A Urciuolo C Pellegrini T Tiepolo P Bonaldo F Gualandi L Merlini P Bernardi NM Maraldi

Collagen VI myopathies (Ullrich congenital muscular dystrophy (UCMD), Bethlem myopathy (BM), and myosclerosis myopathy) share a common pathogenesis, that is, mitochondrial dysfunction due to deregulation of the permeability transition pore (PTP). This effect was first identified in the Col6a1(-/-) mouse model and then in muscle cell cultures from UCMD and BM patients; the normalizing effect of ...

Journal: :Human molecular genetics 2014
Alessandra Zulian Erika Rizzo Marco Schiavone Elena Palma Francesca Tagliavini Bert Blaauw Luciano Merlini Nadir Mario Maraldi Patrizia Sabatelli Paola Braghetta Paolo Bonaldo Francesco Argenton Paolo Bernardi

Ullrich congenital muscular dystrophy (UCMD) and Bethlem myopathy (BM) are inherited muscle diseases due to mutations in the genes encoding the extracellular matrix protein collagen (Col) VI. Opening of the cyclosporin A-sensitive mitochondrial permeability transition pore (PTP) is a causative event in disease pathogenesis, and a potential target for therapy. Here, we have tested the effect of ...

2014
A Reghan Foley Robert D S Pitceathly Jie He Jihee Kim Nathaniel M Pearson Francesco Muntoni Michael G Hanna

BACKGROUND Clinicians are faced with unprecedented opportunities to identify the genetic aetiologies of hitherto molecularly uncharacterised conditions via the use of high-throughput sequencing. Access to genomic technology and resultant data is no longer limited to clinicians, geneticists and bioinformaticians, however; ongoing commercialisation gives patients themselves ever greater access to...

Journal: :The Lancet 1841

Journal: :Journal of neurology, neurosurgery, and psychiatry 1967
W C Hulsmann J Bethlem A E Meijer P Fleury J P Schellens

When the rate of respiration of mitochrondria in the presence of inorganic phosphate cannot be increased by adding adenosine diphosphate (A.D.P.) but these particles can still couple respiration to phosphorylation of A.D.P. to adenosine triphosphate (A.T.P.), the state of respiration is called 'loosely coupled'. The first patient in whom such a loosely coupled state of oxidative phosphorylation...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید