نتایج جستجو برای: survival motor neuron gene

تعداد نتایج: 1595196  

Journal: :IP international journal of comprehensive and advanced pharmacology 2023

Spinal muscular atrophy is an inherited neurodegenerative illness characterized by muscle wasting and loss of spinal cord motor neurons. It results from homozygous loss, translation, or mutation the survival neuron 1 (SMN1) gene. Despite lack a cure, research has revealed potential processes explaining disease’s molecular etiology. The SMN1 gene region’s distinctive genomic structure been used ...

2018
Francesca Magri Fiammetta Vanoli Stefania Corti

Spinal muscular atrophy (SMA) is an autosomal recessive neurodegenerative disease characterized by the selective death of lower motor neurons in the brain stem and spinal cord. SMA is caused by mutations in the survival motor neuron 1 gene (SMN1), leading to the reduced expression of the full-length SMN protein. microRNAs (miRNAs) are small RNAs that regulate post-transcriptional gene expressio...

Journal: :Cell 1995
Thomas M. DeChiara Richard Vejsada William T. Poueymirou Ann Acheson Chitra Suri Joanne C. Conover Beth Friedman Joyce McClain Li Pan Neil Stahl Nancy Y. Ip Ann Kato George D. Yancopoulos

Ciliary neurotrophic factor (CNTF) supports motor neuron survival in vitro and in mouse models of motor neuron degeneration and was considered a candidate for the muscle-derived neurotrophic activity that regulates motor neuron survival during development. However, CNTF expression is very low in the embryo, and CNTF gene mutations in mice or human do not result in notable abnormalities of the d...

Journal: :Science 2005
Meenakshi Rao Shanthini Sockanathan

During neural development, coordinate regulation of cell-cycle exit and differentiation is essential for cell-fate specification, cell survival, and proper wiring of neuronal circuits. However, the molecules that direct these events remain poorly defined. In the developing spinal cord, the differentiation of motor neuron progenitors into postmitotic motor neurons is regulated by retinoid signal...

Journal: :Muscle & nerve 2015
W David Arnold Darine Kassar John T Kissel

Spinal muscular atrophy (SMA) describes a group of disorders associated with spinal motor neuron loss. In this review we provide an update regarding the most common form of SMA, proximal or 5q-SMA, and discuss the contemporary approach to diagnosis and treatment. Electromyography and muscle biopsy features of denervation were once the basis for diagnosis, but molecular testing for homozygous de...

Journal: :Human molecular genetics 2000
T Frugier F D Tiziano C Cifuentes-Diaz P Miniou N Roblot A Dierich M Le Meur J Melki

Deletion of the murine survival of motor neuron gene (SMN) exon 7, the most frequent mutation found in spinal muscular atrophy (SMA) patients, directed to neurons but not to skeletal muscle, enabled generation of a mouse model of SMA providing evidence that motor neurons are the primary target of the gene defect. Moreover, the mutated SMN protein (SMNDeltaC15) is dramatically reduced in the mot...

Journal: :Neuron 2005
Umrao R. Monani

Spinal muscular atrophy (SMA) is a neurodegenerative disease in humans and the most common genetic cause of infant mortality. The disease results in motor neuron loss and skeletal muscle atrophy. Despite a range of disease phenotypes, SMA is caused by mutations in a single gene, the Survival of Motor Neuron 1 (SMN1) gene. Recent advances have shed light on functions of the protein product of th...

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