نتایج جستجو برای: juvenile hemochromatosis

تعداد نتایج: 48167  

Journal: :Hematology. American Society of Hematology. Education Program 2006
Pierre Brissot Frédéric de Bels

The term hemochromatosis encompasses at least four types of genetic iron overload conditions, most of them recently distinguished from one another as a result of the identification of a series of genes related to iron metabolism. At least three of these entities (HFE hemochromatosis, juvenile hemochromatosis and transferrin receptor 2 hemochromatosis) involve systemic hepcidin deficiency as a k...

Journal: :Haematologica 2007
Alexandra Rideau Bastien Mangeat Thomas Matthes Didier Trono Photis Beris

We describe a point mutation creating an additional ATG codon in the 5' untranslated region (UTR) of the HAMP gene, in a patient with juvenile hemochromatosis. By transient in vitro transfection studies, we provide evidence that the additional ATG is functional and prevents normal hepcidin production by inducing an aberrant translation initiation of the pre-hepcidin mRNA.

Journal: :The Journal of clinical investigation 2005
Sophie Vaulont Dan-Qing Lou Lydie Viatte Axel Kahn

Recently, mutations causing juvenile hemochromatosis have been identified in a novel gene, hemojuvelin (HJV), located on chromosome 1. Mouse models of this disease have now been developed by 2 groups, Huang et al. and Niederkofler et al., through targeted disruption of the Hjv gene (see the related articles beginning on pages 2180 and 2187). These mutant mice will allow further investigation in...

Journal: :Blood 2005
Lan Lin Y Paul Goldberg Tomas Ganz

Mutations in a recently identified gene HJV (also called HFE2, or repulsive guidance molecule C, RgmC) are the major cause of juvenile hemochromatosis (JH). The protein product of HJV, hemojuvelin, contains a C-terminal glycosylphosphatidylinositol anchor, suggesting that it can be present in either a soluble or a cell-associated form. Patients with HJV hemochromatosis have low urinary levels o...

Journal: :The Journal of biological chemistry 2005
An-Sheng Zhang Anthony P West Anne E Wyman Pamela J Bjorkman Caroline A Enns

Type 2 hereditary hemochromatosis (HH) or juvenile hemochromatosis is an early onset, genetically heterogeneous, autosomal recessive disorder of iron overload. Type 2A HH is caused by mutations in the recently cloned hemojuvelin gene (HJV; also called HFE2) (Papanikolaou, G., Samuels, M. E., Ludwig, E. H., MacDonald, M. L., Franchini, P. L., Dube, M. P., Andres, L., MacFarlane, J., Sakellaropou...

Journal: :Clinical chemistry 2007
Séverine Cunat Muriel Giansily-Blaizot Michael Bismuth François Blanc Olivier Dereure Dominique Larrey Alain Le Quellec Philippe Pouderoux Christian Rose Isabelle Raingeard Eric Renard Jean-François Schved Patricia Aguilar-Martinez

BACKGROUND New genetic forms of hereditary hemochromatosis (HH) or hereditary hyperferritinemia (HF) have been identified over the last few years, and abnormalities of various genes may interact in a single patient. This study aimed to develop a rapid automated method for sequencing the main genes involved. METHODS We used a standard 96-well microplate with a single PCR condition in an adapta...

2014
Masoud M. Malekzadeh Amir Reza Radmard Alireza Nouroozi Mohammad Reza Akbari Marzie Amini Behrooz Navabakhsh Angela Caleffi Antonello Pietrangelo Reza Malekzadeh

BACKGROUND Hereditary hemochromatosis (HH) is a very rare disease in Iran and reported cases are all negative for HFE mutation. We report a family affected by severe juvenile hemochromatosis (JH) with a detailed molecular study of the family members. METHODS We studied a pedigree with siblings affected by juvenile HH and followed them for 3 years. Microsatellite and gene sequencing analysis was...

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