نتایج جستجو برای: fmr1

تعداد نتایج: 1591  

پایان نامه :وزارت علوم، تحقیقات و فناوری - دانشگاه گیلان - دانشکده علوم پایه 1392

یکی از مهمترین نگرانی ها در زنان باردار، سقط مکرر با شیوع 1 در هر 300 بارداری بوده که عامل آن گاهی اوقات اختلالات خودایمنی می باشد. سقط مکرر در زنان باردار با آنتی بادی هایی مانند آنتی فسفولیپید و آنتیtpoمشاهده میشود. تعداد تکرارهای cgg در 5utr-fmr1با خودایمنی در ارتباط می باشد. افزایش در تعداد تکرارهای fmr1 با سندرم فراژیل x مرتبط است. محدوده نرمال بین 5-54 تکرار می باشد. عملکرد نرمال تخمدان ب...

Journal: :Journal of medical genetics 2000
R Willemsen R Olmer Y De Diego Otero B A Oostra

The absence of the fragile X mental retardation protein (FMRP) results in fragile X syndrome. All males with a full mutation in the FMR1 gene and an inactive FMR1 gene are mentally retarded while 60% of the females with a full mutation are affected. Here we describe monozygotic twin sisters who both have a full mutation in their FMR1 gene, one of whom is normal while the other is affected. Usin...

2013
Stella Lanni Martina Goracci Loredana Borrelli Giorgia Mancano Pietro Chiurazzi Umberto Moscato Fabrizio Ferrè Manuela Helmer-Citterich Elisabetta Tabolacci Giovanni Neri

Fragile X syndrome (FXS), the leading cause of inherited intellectual disability, is caused by epigenetic silencing of the FMR1 gene, through expansion and methylation of a CGG triplet repeat (methylated full mutation). An antisense transcript (FMR1-AS1), starting from both promoter and intron 2 of the FMR1 gene, was demonstrated in transcriptionally active alleles, but not in silent FXS allele...

Journal: :Development 2003
Alan Lee Wenjun Li Kanyan Xu Brigitte A Bogert Kimmy Su Fen-Biao Gao

Fragile X syndrome is caused by loss-of-function mutations in the fragile X mental retardation 1 gene. How these mutations affect neuronal development and function remains largely elusive. We generated specific point mutations or small deletions in the Drosophila fragile X-related (Fmr1) gene and examined the roles of Fmr1 in dendritic development of dendritic arborization (DA) neurons in Droso...

Journal: :Neuron 2007
Rhiannon M. Meredith Carl D. Holmgren Meredith Weidum Nail Burnashev Huibert D. Mansvelder

Fragile X syndrome, caused by a mutation in the Fmr1 gene, is characterized by mental retardation. Several studies reported the absence of long-term potentiation (LTP) at neocortical synapses in Fmr1 knockout (FMR1-KO) mice, but underlying cellular mechanisms are unknown. We find that in the prefrontal cortex (PFC) of FMR1-KO mice, spike-timing-dependent LTP (tLTP) is not so much absent, but ra...

2010
Peter K. Todd Seok Yoon Oh Amy Krans Udai B. Pandey Nicholas A. Di Prospero Kyung-Tai Min J. Paul Taylor Henry L. Paulson

Fragile X Tremor Ataxia Syndrome (FXTAS) is a common inherited neurodegenerative disorder caused by expansion of a CGG trinucleotide repeat in the 5'UTR of the fragile X syndrome (FXS) gene, FMR1. The expanded CGG repeat is thought to induce toxicity as RNA, and in FXTAS patients mRNA levels for FMR1 are markedly increased. Despite the critical role of FMR1 mRNA in disease pathogenesis, the bas...

Journal: :Molecular pharmacology 2009
Laura K K Pacey Scott P Heximer David R Hampson

Mice lacking the gene encoding fragile X mental retardation protein (FMR1) are susceptible to audiogenic seizures, and antagonists of the group I metabotropic glutamate receptors (mGluRs) have been shown to block seizures in FMR1 knockout mice. We investigated whether the G-protein-inhibitory activity of the regulator of G-protein signaling protein, RGS4, could also alter the susceptibility to ...

Journal: :Molecular syndromology 2014
A M Zink E Wohlleber H Engels O K Rødningen K Ravn S Heilmann J Rehnitz N Katzorke C Kraus S Blichfeldt P Hoffmann H Reutter F F Brockschmidt M Kreiß-Nachtsheim P H Vogt T E Prescott Z Tümer J A Lee

Fragile X syndrome (FXS) is one of the most common causes of intellectual disability/developmental delay (ID/DD), especially in males. It is caused most often by CGG trinucleotide repeat expansions, and less frequently by point mutations and partial or full deletions of the FMR1 gene. The wide clinical spectrum of affected females partly depends on their X-inactivation status. Only few female I...

2008
Marie-Cécile Didiot Zhaoxia Tian Céline Schaeffer Murugan Subramanian Jean-Louis Mandel Hervé Moine

The fragile X mental retardation protein (FMRP) is a RNA-binding protein proposed to post-transcriptionally regulate the expression of genes important for neuronal development and synaptic plasticity. We previously demonstrated that FMRP binds to its own FMR1 mRNA via a guanine-quartet (G-quartet) RNA motif. However, the functional effect of this binding on FMR1 expression was not established. ...

2016
Lu Wang Yan Wang Shimeng Zhou Liukun Yang Qixin Shi Yujiao Li Kun Zhang Le Yang Minggao Zhao Qi Yang

Fragile X syndrome (FXS) is a form of inherited mental retardation that results from the absence of the fragile X mental retardation protein (FMRP), the product of the Fmr1 gene. Numerous studies have shown that FMRP expression in astrocytes is important in the development of FXS. Although astrocytes affect neuronal dendrite development in Fmr1 knockout (KO) mice, the factors released by astroc...

نمودار تعداد نتایج جستجو در هر سال

با کلیک روی نمودار نتایج را به سال انتشار فیلتر کنید