نتایج جستجو برای: fabry disease

تعداد نتایج: 1493456  

Journal: :Kidney & blood pressure research 2016
Kultigin Turkmen Aydın Guclu Garip Sahin Ismail Kocyigit Levent Demirtas Fatih Mehmet Erdur Erkan Sengül Oktay Ozkan Habib Emre Faruk Turgut Hilmi Unal Murat Karaman Cengiz Acıkel Hasan Esen Ebru Balli Gulfidan Bıtırgen Halil Zeki Tonbul Mahmut Ilker Yılmaz Alberto Ortiz

BACKGROUND/AIMS Fabry disease is a treatable cause of chronic kidney disease (CKD) characterized by a genetic deficiency of α-galactosidase A. European Renal Best Practice (ERBP) recommends screening for Fabry disease in CKD patients. However, this is based on expert opinion and there are no reports of the prevalence of Fabry disease in stage 1-5 CKD. Hence, we investigated the prevalence of Fa...

2016
Brent Fall C. Ronald Scott Michael Mauer Stuart Shankland Jeffrey Pippin Jonathan A. Jefferson Eric Wallace David Warnock Behzad Najafian

Chronic kidney disease is a major complication of Fabry disease. Podocytes accumulate globotriaosylceramide inclusions more than other kidney cell types in Fabry patients. Podocyte injury occurs early in age, and is progressive. Since injured podocytes detach into the urine (podocyturia), we hypothesized that podocyturia would increase in Fabry patients and correlate with clinical severity of F...

2017
Jin-Ho Choi Beom Hee Lee Sun Hee Heo Gu-Hwan Kim Yoo-Mi Kim Dae-Seong Kim Jung Min Ko Young Bae Sohn Yong Hee Hong Dong-Hwan Lee Hoon Kook Han Hyuk Lim Kyung Hee Kim Woo-Shik Kim Geu-Ru Hong Su-Hyun Kim Sang Hyun Park Chan-Duck Kim So Mi Kim Jeong-Sook Seo Han-Wook Yoo

Fabry disease is a rare X-linked lysosomal storage disorder caused by an α-galactosidase A deficiency. The progressive accumulation of globotriaosylceramide (GL-3) results in life-threatening complications, including renal, cardiac, and cerebrovascular diseases. This study investigated the phenotypic and molecular spectra of GLA mutations in Korean patients with Fabry disease using a nationwide...

Journal: :European heart journal 2010
Noureddine Brakch Olivier Dormond Soumeya Bekri Dela Golshayan Magali Correvon Lucia Mazzolai Beat Steinmann Frédéric Barbey

AIMS A hallmark of Fabry disease is the concomitant development of left-ventricular hypertrophy and arterial intima-media thickening, the pathogenesis of which is thought to be related to the presence of a plasmatic circulating growth-promoting factor. We therefore characterized the plasma of patients with Fabry disease in order to identify this factor. METHODS AND RESULTS Using a classical b...

2016
Yu-pin Chang Jyh-wen Chai Yun-ching Fu Yi-Ying Wu Ying-xiang Liao John Wang Clayton Chi-Chang Chen

Background Fabry disease is a rare X-linked disorder characterized by deficiency ofa-galactosidase A, leading to progressive accumulation of glycosphingolipid in various organs, including the heart. Several studies have pointed out the unique pre-contrast T1 value character of classic Fabry cardiomyopathy, which is lower than the normal myocardium. In Taiwan, several recent studies pointed out ...

2013
Sachie Nakano Yoshihito Morizane Noriko Makisaka Toshihiro Suzuki Tadayasu Togawa Takahiro Tsukimura Ikuo Kawashima Hitoshi Sakuraba Futoshi Shibasaki

Fabry disease is an X-linked genetic disorder caused by defects in the α-galactosidase A (GLA) gene, and heterogeneous mutations lead to quantitative and/or qualitative defects in GLA protein in male patients with Fabry disease. Random X-chromosomal inactivation modifies the clinical and biochemical features of female patients with Fabry disease. Functional polymorphisms have been frequently re...

2012
MI HEE LEE EUN NAM CHOI YEO JIN JEON SUNG-CHUL JUNG

Fabry disease is a lysosomal storage disorder (LSD) caused by deficiency of α-galactosidase A (α-gal A), resulting in deposition of globotriaosylceramide (Gb3; also known as ceramide trihexoside) in the vascular endothelium of many organs. A gradual accumulation of Gb3 leads to cardiovascular, cerebrovascular and renal dysfunction. Endothelial cel...

Journal: :Revista portuguesa de cardiologia : orgao oficial da Sociedade Portuguesa de Cardiologia = Portuguese journal of cardiology : an official journal of the Portuguese Society of Cardiology 2014
Elisabete Martins Teresa Pinho Stirling Carpenter Sérgio Leite Raquel Garcia António Madureira João Paulo Oliveira

Fabry disease is a rare X-linked lysosomal storage disorder caused by mutations in the alpha-galactosidase gene. The most frequent cardiac presentation of Fabry disease is cardiomyopathy characterized by left ventricular (LV) hypertrophy, usually concentric. Heart disease in affected females tends to be clinically recognized later than in males and cardiac complications are the most frequently ...

2009
Maryam Banikazemi

of various cells, such as in the vascular endothelium of multiple organs (1). The accumulation of GL-3 in the lysosomes causes lysosomal and cellular dysfunction and this in turn, triggers the cascade of cellular and tissue ischemia and fibrosis. The estimated prevalence of Fabry disease is about one in every 117000 live born males. The classic phenotype of Fabry disease is seen Introduction Fa...

2010
Dominique P Germain

Fabry disease (FD) is a progressive, X-linked inherited disorder of glycosphingolipid metabolism due to deficient or absent lysosomal α-galactosidase A activity. FD is pan-ethnic and the reported annual incidence of 1 in 100,000 may underestimate the true prevalence of the disease. Classically affected hemizygous males, with no residual α-galactosidase A activity may display all the characteris...

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