نتایج جستجو برای: s ataxia frda

تعداد نتایج: 727598  

2017
Vijayendran Chandran Kun Gao Vivek Swarup Revital Versano Hongmei Dong Maria C Jordan Daniel H Geschwind

Friedreich's ataxia (FRDA), the most common inherited ataxia, is caused by recessive mutations that reduce the levels of frataxin (FXN), a mitochondrial iron binding protein. We developed an inducible mouse model of Fxn deficiency that enabled us to control the onset and progression of disease phenotypes by the modulation of Fxn levels. Systemic knockdown of Fxn in adult mice led to multiple ph...

2012
Tracey A. Rouault

Iron-sulfur (Fe-S) clusters are ubiquitous cofactors composed of iron and inorganic sulfur. They are required for the function of proteins involved in a wide range of activities, including electron transport in respiratory chain complexes, regulatory sensing, photosynthesis and DNA repair. The proteins involved in the biogenesis of Fe-S clusters are evolutionarily conserved from bacteria to hum...

Journal: :The Biochemical journal 2010
Ana R Correia Tao Wang Elizabeth A Craig Cláudio M Gomes

Frataxin is a highly conserved mitochondrial protein whose deficiency in humans results in Friedreich's ataxia (FRDA), an autosomal recessive disorder characterized by progressive ataxia and cardiomyopathy. Although its cellular function is still not fully clear, the fact that frataxin plays a crucial role in Fe-S assembly on the scaffold protein Isu is well accepted. In the present paper, we r...

Journal: :F1000Research 2023

A major cause of death in the elderly worldwide is attributed to neurodegenerative diseases, such as AD (Alzheimer’s disease), PD (Parkinson’s ALS (Amyotrophic lateral sclerosis), FRDA (Friedreich’s ataxia), VaD (Vascular dementia) etc. These can be caused due multiple factors genetic, physiological problems like stroke or tumor, even external causes viruses, toxins, chemicals. T3s (toco...

2015
Michael Lazaropoulos Yina Dong Elisia Clark Nathaniel R Greeley Lauren A Seyer Karlla W Brigatti Carlton Christie Susan L Perlman George R Wilmot Christoper M Gomez Katherine D Mathews Grace Yoon Theresa Zesiewicz Chad Hoyle Sub H Subramony Alicia F Brocht Jennifer M Farmer Robert B Wilson Eric C Deutsch David R Lynch

OBJECTIVE Friedreich ataxia (FRDA) is an autosomal recessive ataxia resulting from mutations in the frataxin gene (FXN). Such mutations, usually expanded guanine-adenine-adenine (GAA) repeats, give rise to decreased levels of frataxin protein in both affected and unaffected tissues. The goal was to understand the relationship of frataxin levels in peripheral tissues to disease status. METHODS...

2016
Maya Patel Charles J. Isaacs Lauren Seyer Karlla Brigatti Sarah Gelbard Cassandra Strawser Debbie Foerster Julianna Shinnick Kimberly Schadt Eppie M. Yiu Martin B. Delatycki Susan Perlman George R. Wilmot Theresa Zesiewicz Katherine Mathews Christopher M. Gomez Grace Yoon Sub H. Subramony Alicia Brocht Jennifer Farmer David R. Lynch

OBJECTIVE Friedreich ataxia (FRDA) is a progressive neurodegenerative disorder of adults and children. This study analyzed neurological outcomes and changes to identify predictors of progression and generate power calculations for clinical trials. METHODS Eight hundred and twelve subjects in a natural history study were evaluated annually across 12 sites using the Friedreich Ataxia Rating Sca...

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