نتایج جستجو برای: hyper ige syndrome

تعداد نتایج: 654501  

2017
Tobias Schwerd Stephen R F Twigg Dominik Aschenbrenner Santiago Manrique Kerry A Miller Indira B Taylor Melania Capitani Simon J McGowan Elizabeth Sweeney Astrid Weber Liye Chen Paul Bowness Andrew Riordan Andrew Cant Alexandra F Freeman Joshua D Milner Steven M Holland Natalie Frede Miryam Müller Dirk Schmidt-Arras Bodo Grimbacher Steven A Wall E Yvonne Jones Andrew O M Wilkie Holm H Uhlig

Multiple cytokines, including interleukin 6 (IL-6), IL-11, IL-27, oncostatin M (OSM), and leukemia inhibitory factor (LIF), signal via the common GP130 cytokine receptor subunit. In this study, we describe a patient with a homozygous mutation of IL6ST (encoding GP130 p.N404Y) who presented with recurrent infections, eczema, bronchiectasis, high IgE, eosinophilia, defective B cell memory, and an...

Journal: :Immunity 2006
Yoshiyuki Minegishi Masako Saito Tomohiro Morio Ken Watanabe Kazunaga Agematsu Shigeru Tsuchiya Hidetoshi Takada Toshiro Hara Nobuaki Kawamura Tadashi Ariga Hideo Kaneko Naomi Kondo Ikuya Tsuge Akihiro Yachie Yukio Sakiyama Tsutomu Iwata Fumio Bessho Tsutomu Ohishi Kosuke Joh Kohsuke Imai Kazuhiro Kogawa Miwa Shinohara Mikiya Fujieda Hiroshi Wakiguchi Srdjan Pasic Mario Abinun Hans D Ochs Eleonore D Renner Annette Jansson Bernd H Belohradsky Ayse Metin Norio Shimizu Shuki Mizutani Toshio Miyawaki Shigeaki Nonoyama Hajime Karasuyama

Tyrosine kinase 2 (Tyk2) is a nonreceptor tyrosine kinase that belongs to the Janus kinase (Jak) family. Here we identified a homozygous Tyk2 mutation in a patient who had been clinically diagnosed with hyper-IgE syndrome. This patient showed unusual susceptibility to various microorganisms including virus, fungi, and mycobacteria and suffered from atopic dermatitis with elevated serum IgE. The...

2016
Khaled Z Abd-Elmoniem Nadine Ramos Saami Yazdani Steven Holland Alexandra Freeman Ahmed M Gharib

Background Autosomal dominant hyper-IgE (AD-HIES), also called Job’s syndrome, is a rare primary immunodeficiency caused by dominant mutations in STAT3. AD-HIES is characterized by elevated levels of IgE, an ineffective immune response to several infectious agents, and connective tissue and arterial abnormalities. To date, coronary artery evaluation in AD-HIES patients has been limited to lumen...

Journal: :Journal of medical and dental sciences 2003
Yi Zhu Shigeaki Nonoyama Tomohiro Morio Masamichi Muramatsu Tasuku Honjo Shuki Mizutani

Thirteen Japanese patients with hyper-IgM syndrome but normal CD40 ligand were characterized. All patients had mutations in AID (activation-induced cytidine deaminase) gene. Five of them had a missense mutation of Arg112His. In all patients, serum IgG, IgA and IgE levels were undetectable, B cells failed to produce detectable amounts of IgE even if cultured them with anti-CD40 and IL-4. Somatic...

Journal: :Genes & development 2013
Satyendra Kumar Robert Wuerffel Ikbel Achour Bryan Lajoie Ranjan Sen Job Dekker Ann J Feeney Amy L Kenter

V(D)J joining is mediated by RAG recombinase during early B-lymphocyte development in the bone marrow (BM). Activation-induced deaminase initiates isotype switching in mature B cells of secondary lymphoid structures. Previous studies questioned the strict ontological partitioning of these processes. We show that pro-B cells undergo robust switching to a subset of immunoglobulin H (IgH) isotypes...

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