نتایج جستجو برای: fshd

تعداد نتایج: 347  

Journal: :Human molecular genetics 2015
Richard J L F Lemmers Jelle J Goeman Patrick J van der Vliet Merlijn P van Nieuwenhuizen Judit Balog Marianne Vos-Versteeg Pilar Camano Maria Antonia Ramos Arroyo Ivonne Jerico Mark T Rogers Daniel G Miller Meena Upadhyaya Jan J G M Verschuuren Adolfo Lopez de Munain Arregui Baziel G M van Engelen George W Padberg Sabrina Sacconi Rabi Tawil Stephen J Tapscott Bert Bakker Silvère M van der Maarel

Facioscapulohumeral muscular dystrophy (FSHD: MIM#158900) is a common myopathy with marked but largely unexplained clinical inter- and intra-familial variability. It is caused by contractions of the D4Z4 repeat array on chromosome 4 to 1-10 units (FSHD1), or by mutations in the D4Z4-binding chromatin modifier SMCHD1 (FSHD2). Both situations lead to a partial opening of the D4Z4 chromatin struct...

2015
Yuling Zhu Huili Zhang Yiming Sun Yaqin Li Langhui Deng Xingxuan Wen Huaqiao Wang Cheng Zhang

BACKGROUND Differentiation among types of muscular dystrophy (MD) has remained challenging. In this retrospective study, we sought to develop a methodology for differentiation of MD types using analysis of serum enzyme profiles. METHODS The serum levels of enzymes from 232 patients, including 120 with DMD, 36 with BMD, 36 with FSHD, 46 with LGMD, and 11 with EDMD, were evaluated. RESULTS Th...

Journal: :Epigenetics 2015
Judit Balog Peter E Thijssen Sean Shadle Kirsten R Straasheijm Patrick J van der Vliet Yvonne D Krom Marlinde L van den Boogaard Annika de Jong Richard J L F Lemmers Rabi Tawil Stephen J Tapscott Silvère M van der Maarel

Facioscapulohumeral muscular dystrophy is caused by incomplete epigenetic repression of the transcription factor DUX4 in skeletal muscle. A copy of DUX4 is located within each unit of the D4Z4 macrosatellite repeat array and its derepression in somatic cells is caused by either repeat array contraction (FSHD1) or by mutations in the chromatin repressor SMCHD1 (FSHD2). While DUX4 expression has ...

2015
Feng Lin Zhi-Qiang Wang Min-Ting Lin Shen-Xing Murong Ning Wang

BACKGROUND Facioscapulohumeral muscular dystrophy (FSHD), a common autosomal dominant muscular disorder, is caused by contraction of the D4Z4 repeats on 4q35. The complicated genotype-phenotype correlation among different ethnic population remains a controversial subject. We aimed to refine this correlation in order to provide new information for genetic counseling. METHODS Here, a cohort of ...

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