نتایج جستجو برای: exome sequencing

تعداد نتایج: 127939  

Journal: :Internal medicine 2013
Hiroshi Doi Chihiro Ohba Yoshinori Tsurusaki Satoko Miyatake Noriko Miyake Hirotomo Saitsu Yuko Kawamoto Tamaki Yoshida Shigeru Koyano Yume Suzuki Yoshiyuki Kuroiwa Fumiaki Tanaka Naomichi Matsumoto

Autosomal recessive cerebellar ataxias and autosomal recessive hereditary spastic paraplegias are clinically and genetically heterogeneous disorders with diverse neurological and non-neurological features. We herein describe a Japanese patient with a slowly progressive form of ataxia and spastic paraplegia. Using whole exome sequencing, we identified a novel homozygous frameshift mutation in SP...

2017
Imane Boudellioua Rozaimi B. Mahamad Razali Maxat Kulmanov Yasmeen Hashish Vladimir B. Bajic Eva Goncalves-Serra Nadia Schoenmakers Georgios V. Gkoutos Paul N. Schofield Robert Hoehndorf

Discriminating the causative disease variant(s) for individuals with inherited or de novo mutations presents one of the main challenges faced by the clinical genetics community today. Computational approaches for variant prioritization include machine learning methods utilizing a large number of features, including molecular information, interaction networks, or phenotypes. Here, we demonstrate...

2015
Sigmund Brabrand Bjarne Johannessen Ulrika Axcrona Sigrid M. Kraggerud Kaja G. Berg Anne C. Bakken Jarle Bruun Sophie D. Fosså Ragnhild A. Lothe Gustav Lehne Rolf I. Skotheim

Intratubular germ cell neoplasia, the precursor of testicular germ cell tumors (TGCTs), is hypothesized to arise during embryogenesis from developmentally arrested primordial germ cells (PGCs) or gonocytes. In early embryonal life, the PGCs migrate from the yolk sac to the dorsal body wall where the cell population separates before colonizing the genital ridges. However, whether the malignant t...

2012
Philippe Chouvarine Amanda M. Cooksey Fiona M. McCarthy David A. Ray Brian S. Baldwin Shane C. Burgess Daniel G. Peterson

BACKGROUND Distinguishing between individuals is critical to those conducting animal/plant breeding, food safety/quality research, diagnostic and clinical testing, and evolutionary biology studies. Classical genetic identification studies are based on marker polymorphisms, but polymorphism-based techniques are time and labor intensive and often cannot distinguish between closely related individ...

2014
Sarah L Sawyer Jeremy Schwartzentruber Chandree L Beaulieu David Dyment Amanda Smith Jodi Warman Chardon Grace Yoon Guy A Rouleau Oksana Suchowersky Victoria Siu Lisa Murphy Robert A Hegele Christian R Marshall Dennis E Bulman Jacek Majewski Mark Tarnopolsky Kym M Boycott

Ataxia demonstrates substantial phenotypic and genetic heterogeneity. We set out to determine the diagnostic yield of exome sequencing in pediatric patients with ataxia without a molecular diagnosis after standard-of-care assessment in Canada. FORGE (Finding Of Rare disease GEnes) Canada is a nation-wide project focused on identifying novel disease genes for rare pediatric diseases using whole-...

2013
Nadine Norton Ana Morales Stephan Zuchner Shengru Guo Peggy D. Robertson Deborah A. Nickerson

Nadine Norton, PhD1, Duanxiang Li, MD, MS1, Evadnie Rampersaud, PhD2, Ana Morales, MS, CGC1, Eden R. Martin, PhD2, Stephan Zuchner, MD2, Shengru Guo, MS2, Michael Gonzalez, BSc2, Dale J. Hedges, PhD2, Peggy D. Robertson, PhD3, Niklas Krumm, BA3, Deborah A. Nickerson, PhD3, and Ray E. Hershberger, MD1 on behalf of the National Heart Lung and Blood Institute GO Exome Sequencing Project & the Exom...

2015
Sarah L. Nickerson Renate Marquis-Nicholson Karen Claxton Fern Ashton Ivone U. S. Leong Debra O. Prosser Jennifer M. Love Alice M. George Graham Taylor Callum Wilson R. J. McKinlay Gardner Donald R. Love

Autosomal recessive cerebellar ataxia encompasses a large and heterogeneous group of neurodegenerative disorders. We employed single nucleotide polymorphism (SNP) analysis and whole exome sequencing to investigate a consanguineous Maori pedigree segregating ataxia. We identified a novel mutation in exon 10 of the SACS gene: c.7962T>G p.(Tyr2654*), establishing the diagnosis of autosomal recessi...

Journal: :Clinical genetics 2016
N Gupta S Shastri P K Singh M Jana A Mridha G Verma M Kabra

An association of congenital diaphragmatic hernia, dandy walker malformation and nasopharyngeal teratoma is very rare. Here, we report a fourth case with this association where chromosomal microarray and whole exome sequencing (WES) was performed to understand the underlying genetic basis. Findings of few variants especially a novel variation in HIRA provided some insights. An association of co...

Journal: :Cold Spring Harbor protocols 2015
Rui Chen Hogune Im Michael Snyder

Multiple platforms are available for whole-exome enrichment and sequencing (WES). This protocol is based on the Illumina TruSeq Exome Enrichment platform, which captures ∼62 Mb of the human exonic regions using 95-base DNA probes. In addition to covering the RefSeq and Ensembl coding sequences, the enriched sequences also include ∼28 Mb of RefSeq untranslated regions (UTR). The protocol can be ...

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