نتایج جستجو برای: anophthalmos

تعداد نتایج: 207  

2016
Mohamed Fetohi Abderrahmane El Mazghi

Basal cell carcinoma is a type of skin cancer and rare, aggressive forms of basal cell carcinoma can invade and destroy nearby muscles, nerves and bone. Very rarely, basal cell carcinoma can spread to other areas of the body. We report the case of a 70-yearold woman who present 3 years ago a small nodule in the right upper eyelid neglected until a very important increase in its volume what moti...

Journal: :Journal of medical genetics 2011
Anne M Slavotinek Sergio E Baranzini Denny Schanze Cassandre Labelle-Dumais Kieran M Short Ryan Chao Mani Yahyavi Emilia K Bijlsma Catherine Chu Stacey Musone Ashleigh Wheatley Pui-Yan Kwok Sandra Marles Jean-Pierre Fryns A Murat Maga Mohamed G Hassan Douglas B Gould Lohith Madireddy Chumei Li Timothy C Cox Ian Smyth Albert E Chudley Martin Zenker

BACKGROUND Manitoba-oculo-tricho-anal (MOTA) syndrome is a rare condition defined by eyelid colobomas, cryptophthalmos and anophthalmia/microphthalmia, an aberrant hairline, a bifid or broad nasal tip, and gastrointestinal anomalies such as omphalocele and anal stenosis. Autosomal recessive inheritance had been assumed because of consanguinity in the Oji-Cre population of Manitoba and reports o...

2014
Vanessa A van Rahden Isabella Rau Sigrid Fuchs Friederike K Kosyna Hiram Larangeira de Almeida Helen Fryssira Bertrand Isidor Anna Jauch Madeleine Joubert Augusta M A Lachmeijer Christiane Zweier Ute Moog Kerstin Kutsche

BACKGROUND Segmental Xp22.2 monosomy or a heterozygous HCCS mutation is associated with the microphthalmia with linear skin defects (MLS) or MIDAS (microphthalmia, dermal aplasia, and sclerocornea) syndrome, an X-linked disorder with male lethality. HCCS encodes the holocytochrome c-type synthase involved in mitochondrial oxidative phosphorylation (OXPHOS) and programmed cell death. METHODS W...

Journal: :The American journal of pathology 2015
Elizabeth J Bankhead Mary P Colasanto Kayla M Dyorich Milan Jamrich L Charles Murtaugh Sabine Fuhrmann

Wnt glycoproteins control key processes during development and disease by activating various downstream pathways. Wnt secretion requires post-translational modification mediated by the O-acyltransferase encoded by the Drosophila porcupine homolog gene (PORCN). In humans, PORCN mutations cause focal dermal hypoplasia (FDH, or Goltz syndrome), an X-linked dominant multisystem birth defect that is...

2014
E. Mosbah

The present study was carried out between November 2004 and April ,2008 on 184 animals( 122 cattle, 27 buffaloes, 12 horses, 7 donkeys ,11 sheep, 2 goats ,and 3 dogs)suffered from different ocular affections . The animals were examined at private farm stations at Dakahlia Province, during field training trips beside those animals admitted to the surgery clinic of the Mansoura Teaching Hospital ...

Journal: :Ophthalmic & physiological optics : the journal of the British College of Ophthalmic Opticians 2016
Benjamin Thompson Scott A Read Serge O Dumoulin Ann E Elsner Jason Porter Austin Roorda

Imaging technologies have revolutionized the study of human anatomy and physiology. Nowhere is this more evident than in the vision sciences, where imaging has provided unprecedented insights into the structure and function of the entire visual pathway in vivo. Ocular and retinal imaging techniques such as optical coherence tomography (OCT) have become established clinical tools, providing high...

2012
Hana Abouzeid Mohamed A. Youssef Nader Bayoumi Nihal ElShakankiri Iman Marzouk Philippe Hauser Daniel F. Schorderet

PURPOSE To report the clinical and genetic study of two families of Egyptian origin with clinical anophthalmia. To further determine the role of the retina and anterior neural fold homeobox gene (RAX) in anophthalmia and associated cerebral malformations. METHODS Three patients with clinical anophthalmia and first-degree relatives from two consanguineous families of Egyptian origin underwent ...

2013
Omar Abdel-Wahab Jie Gao Mazhar Adli Anwesha Dey Thomas Trimarchi Young Rock Chung Cem Kuscu Todd Hricik Delphine Ndiaye-Lobry Lindsay M. LaFave Richard Koche Alan H. Shih Olga A. Guryanova Eunhee Kim Sheng Li Suveg Pandey Joseph Y. Shin Leon Telis Jinfeng Liu Parva K. Bhatt Sebastien Monette Xinyang Zhao Christopher E. Mason Christopher Y. Park Bradley E. Bernstein Iannis Aifantis Ross L. Levine

Somatic Addition of Sex Combs Like 1 (ASXL1) mutations occur in 10-30% of patients with myeloid malignancies, most commonly in myelodysplastic syndromes (MDSs), and are associated with adverse outcome. Germline ASXL1 mutations occur in patients with Bohring-Opitz syndrome. Here, we show that constitutive loss of Asxl1 results in developmental abnormalities, including anophthalmia, microcephaly,...

Journal: :Blood 2014
Jiapeng Wang Zhaomin Li Yongzheng He Feng Pan Shi Chen Steven Rhodes Lihn Nguyen Jin Yuan Li Jiang Xianlin Yang Ophelia Weeks Ziyue Liu Jiehao Zhou Hongyu Ni Chen-Leng Cai Mingjiang Xu Feng-Chun Yang

ASXL1 is mutated/deleted with high frequencies in multiple forms of myeloid malignancies, and its alterations are associated with poor prognosis. De novo ASXL1 mutations cause Bohring-Opitz syndrome characterized by multiple congenital malformations. We show that Asxl1 deletion in mice led to developmental abnormalities including dwarfism, anophthalmia, and 80% embryonic lethality. Surviving As...

Journal: :Clinical genetics 2013
N K Ragge G Quaghebeur H Stewart

To the Editor : Heterozygous, loss of function mutations in the high mobility group (HMG) gene, SOX2 , encoding the sex-determining region Y-box 2 (MIM 184429) protein, lead to severe developmental eye and brain malformations, and some anophthalmos-esophagealgenital syndrome cases (1). However, the fate of these cases into adulthood is unknown. We report an adult with SOX2 anophthalmia syndrome...

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