نتایج جستجو برای: acute infantile gaucher disease

تعداد نتایج: 1877238  

Journal: :Journal of Applied Hematology 2020

Journal: :Molecular Genetics and Metabolism 2018

2017
Grazia Devigili Michele De Filippo Giovanni Ciana Andrea Dardis Christian Lettieri Sara Rinaldo Daniela Macor Alessandro Moro Roberto Eleopra Bruno Bembi

BACKGOUND Pain is one of the most disabling symptoms of Gaucher disease. It is referred by the majority of Gaucher patients and often persists despite long-term enzyme replacement treatment. It has been mainly considered as nociceptive pain secondary to skeletal involvement but it is described even in the absence of bone disease without a clear explanation. In the last years an increasing numbe...

2016
A.A. Mhanni M. Kozenko J.N. Hartley M. Deneau W. El-Matary C. Rockman-Greenberg

Gaucher disease (OMIM #230800) is caused by β-glucosidase deficiency and primarily involves the mononuclear phagocyte system (also called Reticuloendothelial System or Macrophage System). The disease is classified into three main phenotypes based on the presence or absence of neurological manifestations: non-neuronopathic (type 1), acute neuronopathic (type 2) and chronic neuronopathic (type 3)...

Journal: :Anais brasileiros de dermatologia 2011
Fernanda Razera Gislaine Silveira Olm Renan Rangel Bonamigo

This article addresses neutrophilic dermatoses, thus complementing the previous article (part I). The following dermatoses are introduced and discussed: subcorneal pustular dermatosis (Sneddon-Wilkinson disease), dermatitis cruris pustulosa et atrophicans, acute generalized exanthematous pustulosis, continuous Hallopeau acrodermatitis, palmoplantar pustulosis, infantile acropustulosis, Andrews'...

2014
Aya Narita Kentarou Shirai Norika Kubota Rumiko Takayama Yukitoshi Takahashi Takanori Onuki Chikahiko Numakura Mitsuhiro Kato Yusuke Hamada Norio Sakai Atsuko Ohno Maya Asami Shoko Matsushita Anri Hayashi Tomohiro Kumada Tatsuya Fujii Asako Horino Takeshi Inoue Ichiro Kuki Ken Asakawa Hitoshi Ishikawa Koyo Ohno Yoko Nishimura Akiko Tamasaki Yoshihiro Maegaki Kousaku Ohno

The hallmark of neuronopathic Gaucher disease (GD) is oculomotor abnormalities, but ophthalmological assessment is difficult in uncooperative patients. Chromatic pupillometry is a quantitative method to assess the pupillary light reflex (PLR) with minimal patient cooperation. Thus, we investigated whether chromatic pupillometry could be useful for neurological evaluations in GD. In our neuronop...

Journal: :Clinical investigation 2011
Thomas A Burrow Gregory A Grabowski

Gaucher disease is an autosomal recessively inherited lysosomal storage disease that results from the defective activity of the enzyme acid β-glucosidase (glucocerebrosidase). Velaglucerase alfa was recently developed and approved as an alternative form to imiglucerase enzyme therapy. Despite differences in primary structure and glycosylation patterns, recent preclinical and clinical trials of ...

2013
K Wyatt W Henley L Anderson R Anderson V Nikolaou K Stein L Klinger D Hughes S Waldek R Lachmann A Mehta A Vellodi S Logan

List of abbreviations Executive summary Background Objectives Methods Results Conclusions Recommendations for research Funding Chapter 1 Background Lysosomal storage disorders Summary of lysosomal storage disorders investigated in this study Patterns of treatment in England Rationale for the cohort study Background and objectives Chapter 2 Methods Study procedures Data collection Methods used i...

Journal: :The Journal of biological chemistry 2010
Marc N Offman Marcin Krol Israel Silman Joel L Sussman Anthony H Futerman

Gaucher disease is caused by the defective activity of the lysosomal hydrolase, glucosylceramidase. Although the x-ray structure of wild type glucosylceramidase has been resolved, little is known about the structural features of any of the >200 mutations. Various treatments for Gaucher disease are available, including enzyme replacement and chaperone therapies. The latter involves binding of co...

Journal: :Therapeutics and Clinical Risk Management 2010

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