نتایج جستجو برای: smn2 protein

تعداد نتایج: 1234838  

Journal: :Science 2014
Nikolai A Naryshkin Marla Weetall Amal Dakka Jana Narasimhan Xin Zhao Zhihua Feng Karen K Y Ling Gary M Karp Hongyan Qi Matthew G Woll Guangming Chen Nanjing Zhang Vijayalakshmi Gabbeta Priya Vazirani Anuradha Bhattacharyya Bansri Furia Nicole Risher Josephine Sheedy Ronald Kong Jiyuan Ma Anthony Turpoff Chang-Sun Lee Xiaoyan Zhang Young-Choon Moon Panayiota Trifillis Ellen M Welch Joseph M Colacino John Babiak Neil G Almstead Stuart W Peltz Loren A Eng Karen S Chen Jesse L Mull Maureen S Lynes Lee L Rubin Paulo Fontoura Luca Santarelli Daniel Haehnke Kathleen D McCarthy Roland Schmucki Martin Ebeling Manaswini Sivaramakrishnan Chien-Ping Ko Sergey V Paushkin Hasane Ratni Irene Gerlach Anirvan Ghosh Friedrich Metzger

Spinal muscular atrophy (SMA) is a genetic disease caused by mutation or deletion of the survival of motor neuron 1 (SMN1) gene. A paralogous gene in humans, SMN2, produces low, insufficient levels of functional SMN protein due to alternative splicing that truncates the transcript. The decreased levels of SMN protein lead to progressive neuromuscular degeneration and high rates of mortality. Th...

2013
Chalermchai Mitrpant Paul Porensky Haiyan Zhou Loren Price Francesco Muntoni Sue Fletcher Steve D. Wilton Arthur H. M. Burghes

Spinal muscular atrophy (SMA) is caused by loss of the Survival Motor Neuron 1 (SMN1) gene, resulting in reduced SMN protein. Humans possess the additional SMN2 gene (or genes) that does produce low level of full length SMN, but cannot adequately compensate for loss of SMN1 due to aberrant splicing. The majority of SMN2 gene transcripts lack exon 7 and the resultant SMNΔ7 mRNA is translated int...

Journal: :Human molecular genetics 2012
Paul N Porensky Chalermchai Mitrpant Vicki L McGovern Adam K Bevan Kevin D Foust Brain K Kaspar Stephen D Wilton Arthur H M Burghes

Spinal muscular atrophy (SMA) is an autosomal-recessive disorder characterized by α-motor neuron loss in the spinal cord anterior horn. SMA results from deletion or mutation of the Survival Motor Neuron 1 gene (SMN1) and retention of SMN2. A single nucleotide difference between SMN1 and SMN2 results in exclusion of exon 7 from the majority of SMN2 transcripts, leading to decreased SMN protein l...

Journal: :The Journal of neuroscience : the official journal of the Society for Neuroscience 2010
Tristan H Coady Christian L Lorson

Spinal muscular atrophy is a leading genetic cause of infantile death and occurs in approximately 1/6000 live births. SMA is caused by the loss of Survival Motor Neuron-1 (SMN1), however, all patients retain at least one copy of a nearly identical gene called SMN2. While SMN2 and SMN1 are comprised of identical coding sequences, the majority of SMN2 transcripts are alternatively spliced, encodi...

2016
Joonbae Seo Natalia N. Singh Eric W. Ottesen Senthilkumar Sivanesan Maria Shishimorova Ravindra N. Singh

Humans carry two nearly identical copies of Survival Motor Neuron gene: SMN1 and SMN2. Loss of SMN1 leads to spinal muscular atrophy (SMA), the most frequent genetic cause of infant mortality. While SMN2 cannot compensate for the loss of SMN1 due to predominant skipping of exon 7, correction of SMN2 exon 7 splicing holds the promise of a cure for SMA. Previously, we used cell-based models coupl...

Journal: :The New England Journal of Medicine 2021

Type 1 spinal muscular atrophy (SMA) is a progressive neuromuscular disease characterized by an onset at 6 months of age or younger, inability to sit without support, and deficient levels survival motor neuron (SMN) protein. Risdiplam orally administered small molecule that modifies SMN2 pre–messenger RNA splicing increases functional SMN protein in blood.

Journal: :Human molecular genetics 2009
Lutz Garbes Markus Riessland Irmgard Hölker Raoul Heller Jan Hauke Christian Tränkle Roland Coras Ingmar Blümcke Eric Hahnen Brunhilde Wirth

Histone deacetylase inhibitors (HDACi) are potential candidates for therapeutic approaches in cancer and neurodegenerative diseases such as spinal muscular atrophy (SMA)--a common autosomal recessive disorder and frequent cause of early childhood death. SMA is caused by homozygous absence of SMN1. Importantly, all SMA patients carry a nearly identical copy gene, SMN2, that produces only minor l...

Journal: :Molecular and cellular biology 2006
Nirmal K Singh Natalia N Singh Elliot J Androphy Ravindra N Singh

Humans have two nearly identical copies of the Survival Motor Neuron (SMN) gene, SMN1 and SMN2. In spinal muscular atrophy (SMA), SMN2 is not able to compensate for the loss of SMN1 due to exclusion of exon 7. Here we describe a novel inhibitory element located immediately downstream of the 5' splice site in intron 7. We call this element intronic splicing silencer N1 (ISS-N1). Deletion of ISS-...

Journal: :The EMBO journal 2010
Simona Pedrotti Pamela Bielli Maria Paola Paronetto Fabiola Ciccosanti Gian Maria Fimia Stefan Stamm James L Manley Claudio Sette

Spinal muscular atrophy (SMA) is a neurodegenerative disease caused by loss of motor neurons in patients with null mutations in the SMN1 gene. An almost identical SMN2 gene is unable to compensate for this deficiency because a single C-to-T transition at position +6 in exon-7 causes skipping of the exon by a mechanism not yet fully elucidated. We observed that the C-to-T transition in SMN2 crea...

Journal: :Journal of medical genetics 2008
C Angelozzi F Borgo F D Tiziano A Martella G Neri C Brahe

Spinal muscular atrophy (SMA) is an inherited neuromuscular disorder caused by homozygous absence of the survival motor neuron gene (SMN1). All patients have at least one, usually two to four copies of the related SMN2 gene which, however, produce insufficient levels of functional SMN protein due to the exclusion of exon 7 in the majority of SMN2 transcripts. Here, we show that salbutamol, a be...

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