نتایج جستجو برای: glucocerebrosidase

تعداد نتایج: 825  

Journal: :iranian journal of pediatric hematology and oncology 0
f binesh associate professor of pathology,shahid sadoughi university of medical sciences,yazd,iran. a yousefi assistant professor of pediateric disease, shahid sadoughi university of medical sciences,yazd,iran.سازمان اصلی تایید شده: دانشگاه علوم پزشکی شهید صدوقی یزد (shahid sadooghi university of medical sciences) m ordooei assistant professor of pediateric disease, shahid sadoughi university of medical sciences,yazd,iran.سازمان اصلی تایید شده: دانشگاه علوم پزشکی شهید صدوقی یزد (shahid sadooghi university of medical sciences) ma bagherinasab general practitioner, shahid sadoughi university of medical sciences,yazd,iran.سازمان اصلی تایید شده: دانشگاه علوم پزشکی شهید صدوقی یزد (shahid sadooghi university of medical sciences)

background gaucher’s disease (g.d.) is an autosomal recessive disorder resulting from the accumulation of glucocerebrosidase in the cells of macrophage-monocyte system as a result of a deficiency in lysosomal glucocerebrosidase. this enzyme is encoded by a gene on chromosome-1. here we report a case of gaucher’s disease .g.d is rare in yazd. case reports we reported a patient that presented wit...

2015
James M. Gruschus Philipp J. Kahle

Mutations in the GBA1 gene are associated with increased risk of Parkinson's disease, and the protein produced by the gene, glucocerebrosidase, interacts with α-synuclein, the protein at the center of the disease etiology. One possibility is that the mutations disrupt a beneficial interaction between the proteins, and a beneficial interaction would imply that the proteins have coevolved. To exp...

Journal: :The Journal of neuroscience : the official journal of the Society for Neuroscience 2016
Elma Aflaki Daniel K Borger Nima Moaven Barbara K Stubblefield Steven A Rogers Samarjit Patnaik Frank J Schoenen Wendy Westbroek Wei Zheng Patricia Sullivan Hideji Fujiwara Rohini Sidhu Zayd M Khaliq Grisel J Lopez David S Goldstein Daniel S Ory Juan Marugan Ellen Sidransky

UNLABELLED Among the known genetic risk factors for Parkinson disease, mutations in GBA1, the gene responsible for the lysosomal disorder Gaucher disease, are the most common. This genetic link has directed attention to the role of the lysosome in the pathogenesis of parkinsonism. To study how glucocerebrosidase impacts parkinsonism and to evaluate new therapeutics, we generated induced human p...

Journal: :Neurobiology of aging 2009
Jose Bras Coro Paisan-Ruiz Rita Guerreiro Maria Helena Ribeiro Ana Morgadinho Cristina Januario Ellen Sidransky Catarina Oliveira Andrew Singleton

Mutations in the gene encoding beta-glucocerebrosidase, a lysosomal degrading enzyme, have recently been associated with the development of Parkinson disease. Here we report the results found in a cohort of Portuguese Parkinson disease patients and healthy age-matched controls for mutations in the aforementioned gene. This screening was accomplished by sequencing the complete open-reading frame...

Journal: :GSC Advanced Research and Reviews 2022

Gaucher disease is an autosomal recessive genetic caused by a deficiency in lysosomal enzyme, beta glucocerebrosidase. This characterized deposits of glucosylceramide liver, spleen and bone marrow cells. The presentation MG very heterogeneous, ranging from the asymptomatic form to lethal form. Neurological forms (types 2 3) are present only 5% patients with less frequent than non-neurological (...

Journal: :Brain : a journal of neurology 2015
Roy N Alcalay Oren A Levy Cheryl C Waters Stanley Fahn Blair Ford Sheng-Han Kuo Pietro Mazzoni Michael W Pauciulo William C Nichols Ziv Gan-Or Guy A Rouleau Wendy K Chung Pavlina Wolf Petra Oliva Joan Keutzer Karen Marder Xiaokui Zhang

Glucocerebrosidase (GBA) mutations have been associated with Parkinson's disease in numerous studies. However, it is unknown whether the increased risk of Parkinson's disease in GBA carriers is due to a loss of glucocerebrosidase enzymatic activity. We measured glucocerebrosidase enzymatic activity in dried blood spots in patients with Parkinson's disease (n = 517) and controls (n = 252) with a...

Journal: :Movement Disorders 2021

Background With pathway-specific trials in PD associated with variants the glucocerebrosidase gene (PDGBA) under way, we need markers that confirm impact of genetic patient-derived biofluids order to allow patient stratification merely based on genetics and might serve as biochemical read-out for target engagement. Objective To explore GBA-pathway-specific biomarker profiles cross-sectionally (...

2016
Wendy Westbroek Matthew Nguyen Marina Siebert Taylor Lindstrom Robert A Burnett Elma Aflaki Olive Jung Rafael Tamargo Jorge L Rodriguez-Gil Walter Acosta An Hendrix Bahafta Behre Nahid Tayebi Hideji Fujiwara Rohini Sidhu Benoit Renvoise Edward I Ginns Amalia Dutra Evgenia Pak Carole Cramer Daniel S Ory William J Pavan Ellen Sidransky

Glucocerebrosidase is a lysosomal hydrolase involved in the breakdown of glucosylceramide. Gaucher disease, a recessive lysosomal storage disorder, is caused by mutations in the gene GBA1 Dysfunctional glucocerebrosidase leads to accumulation of glucosylceramide and glycosylsphingosine in various cell types and organs. Mutations in GBA1 are also a common genetic risk factor for Parkinson diseas...

Journal: :Human molecular genetics 1997
M Pasmanik-Chor L Madar-Shapiro E O Stein H Aerts S Gatt M Horowitz

Gaucher disease is a heterogeneous disease characterized by impaired activity of the lysosomal enzyme glucocerebrosidase. This heterogeneity is attributed to a large number of mutations in the corresponding gene. In order to test the biochemical properties of some mutations prevalent among Israeli populations, the normal human glucocerebrosidase cDNA and cDNAs carrying mutations N370S, L444P, D...

Journal: :Proceedings of the National Academy of Sciences of the United States of America 1985
J Sorge C West B Westwood E Beutler

Mutations in the human glucocerebrosidase gene cause Gaucher disease. A cDNA clone containing the entire human glucocerebrosidase coding region from normal cells has been isolated using lambda gt11 expression libraries. The complete nucleotide sequence, a restriction map, and a hydropathy profile are presented. Hybridization to chromosome-specific DNA localizes the human glucocerebrosidase gene...

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