نتایج جستجو برای: familial mds

تعداد نتایج: 63422  

2017
Nahla A M Hamed

The morphologic dysplasia manifested in any lineage(s) frequently does not correlate with the specific cytopenia(s) in individual MDS cases. For this reason, WHO revision for adult MDS classification in 2016 removes terms such as “refractory anemia” and “refractory cytopenia” and replaces them with “myelodysplastic syndrome” followed by the appropriate modifiers: single vs multilineage dysplasi...

2014
Fabrizio Vianello Silvia Vettore Fabiana Tezza Luca De Toni Raffaella Scandellari Luisa Sambado Martina Treleani Fabrizio Fabris

The relationship between thrombopoietin (TPO) and its receptor cMpl in thrombocytopenic conditions has not been entirely clarified. To elucidate this interplay may expand the spectrum of indications of TPO mimetics. In this study we have explored the relationship between TPO and cMpl in platelets and megakaryocytes of 43 patients with thrombocytopenia due to idiopathic thrombocytopenic purpura ...

2011
Paula G Heller Ana C Glembotsky

Other names Familial platelet disorder with predisposition to myeloid malignancy FPD/AML Inheritance Familial platelet disorder with predisposition to acute myelogenous leukemia (FPD/AML) is an autosomal dominant disorder caused by germline heterozygous mutations in the hematopoietic transcription factor RUNX1. Thirty-six pedigrees have been reported to date. Although rare, the frequency of thi...

2014
Rafael Bejar David P. Steensma

The myelodysplastic syndromes (MDS) represent the most common class of acquired bonemarrow failure syndromes in adults. Although MDSs are increasinglywell understood from a biological standpoint, including discovery of .40 MDS-associated recurrently mutated genes in the last 7 years, improved pathological insight has not yet translated into highly effective or curative therapies for most patien...

Journal: :Blood 2012
Jan Kazenwadel Genevieve A Secker Yajuan J Liu Jill A Rosenfeld Robert S Wildin Jennifer Cuellar-Rodriguez Amy P Hsu Sarah Dyack Conrad V Fernandez Chan-Eng Chong Milena Babic Peter G Bardy Akiko Shimamura Michael Y Zhang Tom Walsh Steven M Holland Dennis D Hickstein Marshall S Horwitz Christopher N Hahn Hamish S Scott Natasha L Harvey

Recent work has established that heterozygous germline GATA2 mutations predispose carriers to familial myelodysplastic syndrome (MDS)/acute myeloid leukemia (AML), "MonoMAC" syndrome, and DCML deficiency. Here, we describe a previously unreported MDS family carrying a missense GATA2 mutation (p.Thr354Met), one patient with MDS/AML carrying a frameshift GATA2 mutation (p.Leu332Thrfs*53), another...

Journal: :Biochimie 2003
Peter Karran Judith Offman Margherita Bignami

DNA mismatch repair (MMR) is an important replication error avoidance mechanism that prevents mutation. The association of defective MMR with familial and sporadic gastrointestinal and endometrial cancer has been acknowledged for some years. More recently, it has become apparent that MMR defects are common in acute myeloid leukaemia/myelodysplastic syndrome (AML/MDS) that follows successful che...

Journal: :Journal of medical genetics 1996
H M Kingston D H Ledbetter P I Tomlin K L Gaunt

We report a case of Miller-Dieker syndrome (MDS) owing to an unbalanced rearrangement of a familial pericentric inversion of chromosome 17 (inv(17) (p13.3q25.1)). In addition to lissencephaly and the facial features of MDS, the affected child had other congenital malformations consistent with distal 17q duplication. Initial cytogenetic analysis failed to show any abnormality and fluorescence in...

2015
Matthew Collin Rachel Dickinson Venetia Bigley

Heterozygous familial or sporadic GATA2 mutations cause a multifaceted disorder, encompassing susceptibility to infection, pulmonary dysfunction, autoimmunity, lymphoedema and malignancy. Although often healthy in childhood, carriers of defective GATA2 alleles develop progressive loss of mononuclear cells (dendritic cells, monocytes, B and Natural Killer lymphocytes), elevated FLT3 ligand, and ...

Journal: :Cancer research 2006
Robert C Briggs Keith E Shults Leanne A Flye Sara A McClintock-Treep Madan H Jagasia Stacey A Goodman Fouad I Boulos James W Jacobberger Greg T Stelzer David R Head

Reduced levels of human myeloid nuclear differentiation antigen (MNDA) gene transcripts have been detected in both familial and sporadic cases of myelodysplastic syndromes (MDS). Numerous reports implicate elevated apoptosis/programmed cell death and death ligands and their receptors in the pathogenesis of MDS. MNDA and related proteins contain the pyrin domain that functions in signaling assoc...

Journal: :Clinical genetics 2014
T Requena J M Espinosa-Sanchez S Cabrera G Trinidad A Soto-Varela S Santos-Perez R Teggi P Perez A Batuecas-Caletrio J Fraile I Aran E Martin J Benitez N Pérez-Fernández J A Lopez-Escamez

The aims of this study were to estimate the prevalence of familial cases in patients with Meniere's disease (MD) and to identify clinical differences between sporadic and familial MD. We recruited 1375 patients with definite MD according to the American Academy of Otolaryngology-Head and Neck Surgery criteria, obtaining the familial history of hearing loss or episodic vertigo by direct intervie...

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